Technical Considerations for Lung Transplantation in Kartagener's Syndrome.


Journal

The Annals of thoracic surgery
ISSN: 1552-6259
Titre abrégé: Ann Thorac Surg
Pays: Netherlands
ID NLM: 15030100R

Informations de publication

Date de publication:
05 2019
Historique:
received: 20 07 2018
revised: 29 08 2018
accepted: 30 08 2018
pubmed: 8 1 2019
medline: 20 12 2019
entrez: 8 1 2019
Statut: ppublish

Résumé

Kartagener's syndrome is a rare genetic disorder of ciliated epithelial cells associated with recurrent respiratory tract infections, bronchiectasis, and situs inversus. In some patients, the accumulation of airway secretions and recurrent infections lead to end-stage lung disease, for which lung transplantation is the only effective treatment. Anatomical variations, such as dextrocardia and pulmonary situs inversus, make the procedure challenging, yet feasible with certain technical modifications and careful preparation of donor lungs. We report a case of bilateral lung transplantation without the use of cardiopulmonary bypass in a patient with Kartagener's syndrome while describing important technical details of the operation.

Identifiants

pubmed: 30612988
pii: S0003-4975(18)31528-5
doi: 10.1016/j.athoracsur.2018.08.095
pii:
doi:

Types de publication

Case Reports Journal Article Research Support, N.I.H., Extramural

Langues

eng

Sous-ensembles de citation

IM

Pagination

e337-e339

Subventions

Organisme : NHLBI NIH HHS
ID : F32 HL143950
Pays : United States
Organisme : NCI NIH HHS
ID : K07 CA178120
Pays : United States

Informations de copyright

Copyright © 2019 The Society of Thoracic Surgeons. Published by Elsevier Inc. All rights reserved.

Auteurs

Jason M Gauthier (JM)

Division of Cardiothoracic Surgery, Department of Surgery, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Tsuyoshi Takahashi (T)

Division of Cardiothoracic Surgery, Department of Surgery, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Andrew J Bierhals (AJ)

Division of Diagnostic Radiology, Mallinckrodt Institute of Radiology, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Steven L Brody (SL)

Division of Pulmonary and Critical Care Medicine, Department of Medicine, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Ramsey R Hachem (RR)

Division of Pulmonary and Critical Care Medicine, Department of Medicine, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Chad A Witt (CA)

Division of Pulmonary and Critical Care Medicine, Department of Medicine, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Derek E Byers (DE)

Division of Pulmonary and Critical Care Medicine, Department of Medicine, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Roger D Yusen (RD)

Division of Pulmonary and Critical Care Medicine, Department of Medicine, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Elbert P Trulock (EP)

Division of Pulmonary and Critical Care Medicine, Department of Medicine, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Patrick R Aguilar (PR)

Division of Pulmonary and Critical Care Medicine, Department of Medicine, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Ruben G Nava (RG)

Division of Cardiothoracic Surgery, Department of Surgery, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Benjamin D Kozower (BD)

Division of Cardiothoracic Surgery, Department of Surgery, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Bryan F Meyers (BF)

Division of Cardiothoracic Surgery, Department of Surgery, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

G Alexander Patterson (GA)

Division of Cardiothoracic Surgery, Department of Surgery, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Daniel Kreisel (D)

Division of Cardiothoracic Surgery, Department of Surgery, Washington University School of Medicine in St. Louis, St. Louis, Missouri; Department of Pathology & Immunology, Washington University School of Medicine in St. Louis, St. Louis, Missouri.

Varun Puri (V)

Division of Cardiothoracic Surgery, Department of Surgery, Washington University School of Medicine in St. Louis, St. Louis, Missouri. Electronic address: varunpuri@wustl.edu.

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Classifications MeSH