Novel compound heterozygous


Journal

Human genome variation
ISSN: 2054-345X
Titre abrégé: Hum Genome Var
Pays: England
ID NLM: 101652445

Informations de publication

Date de publication:
2019
Historique:
received: 11 06 2018
revised: 10 11 2018
accepted: 09 12 2018
entrez: 19 2 2019
pubmed: 19 2 2019
medline: 19 2 2019
Statut: epublish

Résumé

Usher syndrome type I (USH1) is characterized by congenital, bilateral, profound sensorineural hearing loss, vestibular areflexia, and adolescent-onset retinitis pigmentosa. Here, we report a 12-year-old female patient with typical USH1. Targeted panel sequencing revealed compound heterozygous variants of the

Identifiants

pubmed: 30774966
doi: 10.1038/s41439-019-0037-y
pii: 37
pmc: PMC6348282
doi:

Types de publication

Case Reports

Langues

eng

Pagination

8

Déclaration de conflit d'intérêts

The authors declare no competing interests.

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Auteurs

Satomi Okano (S)

Hokkaido Asahikawa Habilitation Center for Disabled Children, Asahikawa, Japan.

Yoshio Makita (Y)

2Education Center, Asahikawa Medical University, Asahikawa, Japan.

Akihiro Katada (A)

3Department of Otolaryngology-Head and Neck Surgery, Asahikawa Medical University, Asahikawa, Japan.

Yasuaki Harabuchi (Y)

3Department of Otolaryngology-Head and Neck Surgery, Asahikawa Medical University, Asahikawa, Japan.

Tomohiro Kohmoto (T)

4Department of Human Genetics, Graduate School of Biomedical Sciences, Tokushima University, Tokushima, Japan.

Takuya Naruto (T)

4Department of Human Genetics, Graduate School of Biomedical Sciences, Tokushima University, Tokushima, Japan.

Kiyoshi Masuda (K)

4Department of Human Genetics, Graduate School of Biomedical Sciences, Tokushima University, Tokushima, Japan.

Issei Imoto (I)

4Department of Human Genetics, Graduate School of Biomedical Sciences, Tokushima University, Tokushima, Japan.
5Risk Assessment Center, Aichi Cancer Center Hospital, Nagoya, Japan.

Classifications MeSH