Pure Red Cell Aplasia (PRCA) and Cerebellar Hypoplasia as Atypical Features of Polyglandular Autoimmune Syndrome Type I (APS-1): Two Sisters With the Same AIRE Mutation but Different Phenotypes.

acute disseminated encephalomyelitis (ADEM) cerebellar hypoplasia hematopoietic stem cell transplantation (HCT) polyglandular autoimmune syndrome type I pure red cell aplasia (PRCA)

Journal

Frontiers in pediatrics
ISSN: 2296-2360
Titre abrégé: Front Pediatr
Pays: Switzerland
ID NLM: 101615492

Informations de publication

Date de publication:
2019
Historique:
received: 07 12 2018
accepted: 07 02 2019
entrez: 14 3 2019
pubmed: 14 3 2019
medline: 14 3 2019
Statut: epublish

Résumé

The polyglandular autoimmune syndrome type I is a rare hereditary autosomal recessive disease. We describe a child with the classic triad of the disease and her sister with pure red cell aplasia and cerebellar hypoplasia. The latter received two haematopoietic stem cell transplantations, complicated by an acute disseminated encephalomyelitis.

Identifiants

pubmed: 30863741
doi: 10.3389/fped.2019.00051
pmc: PMC6399394
doi:

Types de publication

Case Reports

Langues

eng

Pagination

51

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Auteurs

Matteo Chinello (M)

Pediatric Hematology Oncology, Azienda Ospedaliera Universitaria Integrata, Verona, Italy.

Margherita Mauro (M)

Mother and Child Department, University of Verona, Verona, Italy.

Gaetano Cantalupo (G)

Child Neuropsychiatry, University of Verona, Verona, Italy.

Rita Balter (R)

Pediatric Hematology Oncology, Azienda Ospedaliera Universitaria Integrata, Verona, Italy.

Massimiliano De Bortoli (M)

Pediatric Hematology Oncology, Azienda Ospedaliera Universitaria Integrata, Verona, Italy.

Virginia Vitale (V)

Pediatric Hematology Oncology, Azienda Ospedaliera Universitaria Integrata, Verona, Italy.

Ada Zaccaron (A)

Pediatric Hematology Oncology, Azienda Ospedaliera Universitaria Integrata, Verona, Italy.

Elisa Bonetti (E)

Pediatric Hematology Oncology, Azienda Ospedaliera Universitaria Integrata, Verona, Italy.

Rossella Gaudino (R)

Pediatric Division, Department of Pediatrics, University Hospital of Verona, Verona, Italy.

Elena Fiorini (E)

Child Neuropsychiatry, University of Verona, Verona, Italy.

Simone Cesaro (S)

Pediatric Hematology Oncology, Azienda Ospedaliera Universitaria Integrata, Verona, Italy.

Classifications MeSH