Mutation-Proved Clouston Syndrome in a Large Indian Family with a Variant Phenotype.

Clouston syndrome gjb6 hidrotic ectodermal dysplasia hypotrichosis keratoderma

Journal

Indian journal of dermatology
ISSN: 1998-3611
Titre abrégé: Indian J Dermatol
Pays: India
ID NLM: 0370750

Informations de publication

Date de publication:
Historique:
entrez: 16 4 2019
pubmed: 16 4 2019
medline: 16 4 2019
Statut: ppublish

Résumé

Hereditary ectodermal dysplasias, a group of disorders affecting skin, hair, nails, and teeth, consist of two main clinical forms - hypohidrotic and hidrotic. Clouston syndrome is a hidrotic ectodermal dysplasia characterized by a triad of generalized hypotrichosis, palmoplantar hyperkeratosis, and nail dystrophy. This paper reports a large Indian family with Clouston syndrome but with the absence of palmoplantar keratoderma, one of the features of the typical triad, thus representing phenotypic heterogeneity, in spite of the presence of a common known mutation in GJB6 gene (p.Gly11Arg).

Identifiants

pubmed: 30983611
doi: 10.4103/ijd.IJD_510_17
pii: IJD-64-143
pmc: PMC6440177
doi:

Types de publication

Case Reports

Langues

eng

Pagination

143-145

Déclaration de conflit d'intérêts

There are no conflicts of interest.

Références

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Auteurs

Sangeeta Khatter (S)

Department of Medical Genetics, Institute of Genomics and Medical Genetics, Sir Ganga Ram Hospital, New Delhi, India.

Ratna Dua Puri (RD)

Department of Medical Genetics, Institute of Genomics and Medical Genetics, Sir Ganga Ram Hospital, New Delhi, India.

Sunita Bijarnia Mahay (SB)

Department of Medical Genetics, Institute of Genomics and Medical Genetics, Sir Ganga Ram Hospital, New Delhi, India.

Pratibha Bhai (P)

Department of Medical Genetics, Institute of Genomics and Medical Genetics, Sir Ganga Ram Hospital, New Delhi, India.

Renu Saxena (R)

Department of Medical Genetics, Institute of Genomics and Medical Genetics, Sir Ganga Ram Hospital, New Delhi, India.

Ishwar C Verma (IC)

Department of Medical Genetics, Institute of Genomics and Medical Genetics, Sir Ganga Ram Hospital, New Delhi, India.

Classifications MeSH