The Multiple Sclerosis Functional Composite and Symbol Digit Modalities Test as outcome measures in pediatric multiple sclerosis.

MSFC Multiple sclerosis SDMT outcome measure pediatric

Journal

Multiple sclerosis journal - experimental, translational and clinical
ISSN: 2055-2173
Titre abrégé: Mult Scler J Exp Transl Clin
Pays: United States
ID NLM: 101668877

Informations de publication

Date de publication:
Historique:
received: 08 02 2019
accepted: 03 04 2019
entrez: 9 5 2019
pubmed: 9 5 2019
medline: 9 5 2019
Statut: epublish

Résumé

There is an increasing number of pediatric multiple sclerosis (MS) clinical trials occurring; however, data validating outcome metrics that accurately capture functional disability within pediatric cohorts are limited. The aim of this study was to investigate the ability of the MS Functional Composite (MSFC) and Symbol Digit Modalities Test (SDMT) to distinguish functional disability in pediatric MS patients. A total of 20 pediatric MS patients and 40 age and sex-matched controls completed the SDMT and MSFC components: a timed 25-foot walk (T25FW); 9-hole peg test (9HPT); and paced auditory serial addition test (PASAT). Pediatric MS patients exhibited low levels of disability on EDSS, median [range]: 1.5 [1.0-3.0]. Compared with controls, MS patients performed significantly lower on SDMT ( Despite low levels of neurologic disability as measured by EDSS, pediatric patients with MS exhibit impaired performance in leg function, upper limb fine motor function, and auditory/visuospatial processing speeds, supporting the value of the MSFC and SDMT in this population. Longitudinal studies are needed to further validate their utility.

Sections du résumé

BACKGROUND BACKGROUND
There is an increasing number of pediatric multiple sclerosis (MS) clinical trials occurring; however, data validating outcome metrics that accurately capture functional disability within pediatric cohorts are limited.
OBJECTIVE OBJECTIVE
The aim of this study was to investigate the ability of the MS Functional Composite (MSFC) and Symbol Digit Modalities Test (SDMT) to distinguish functional disability in pediatric MS patients.
METHODS METHODS
A total of 20 pediatric MS patients and 40 age and sex-matched controls completed the SDMT and MSFC components: a timed 25-foot walk (T25FW); 9-hole peg test (9HPT); and paced auditory serial addition test (PASAT).
RESULTS RESULTS
Pediatric MS patients exhibited low levels of disability on EDSS, median [range]: 1.5 [1.0-3.0]. Compared with controls, MS patients performed significantly lower on SDMT (
CONCLUSIONS CONCLUSIONS
Despite low levels of neurologic disability as measured by EDSS, pediatric patients with MS exhibit impaired performance in leg function, upper limb fine motor function, and auditory/visuospatial processing speeds, supporting the value of the MSFC and SDMT in this population. Longitudinal studies are needed to further validate their utility.

Identifiants

pubmed: 31065380
doi: 10.1177/2055217319846141
pii: 10.1177_2055217319846141
pmc: PMC6488791
doi:

Types de publication

Journal Article

Langues

eng

Pagination

2055217319846141

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Auteurs

J Nicholas Brenton (JN)

Department of Neurology, Division of Pediatric Neurology, University of Virginia, Charlottesville, VA USA.

Hitoshi Koshiya (H)

School of Medicine, University of Virginia, Charlottesville, VA USA.

Emma Woolbright (E)

College of Arts and Sciences, University of Virginia, Charlottesville, VA USA.

Myla D Goldman (MD)

Department of Neurology, University of Virginia, Charlottesville, VA USA.

Classifications MeSH