Management of primary hyperparathyroidism in pregnancy: a case series.

2019 Abdominal discomfort Bone CT scan Calcium (serum) Calcium to creatinine clearance ratio Diarrhoea Diet Fatigue Female Fluid repletion Gestational diabetes mellitus Headache Histopathology Hypercalcaemia Hyperparathyroidism (primary) MEN1 May Molecular genetic analysis Nausea Novel diagnostic procedure PTH Parathyroid adenoma Parathyroid hyperplasia Parathyroidectomy Phosphate (serum) Polydipsia Polyuria Pregnant adult SPECT scan Sestamibi scan Ultrasound scan United Kingdom Vitamin D Vomiting White

Journal

Endocrinology, diabetes & metabolism case reports
ISSN: 2052-0573
Titre abrégé: Endocrinol Diabetes Metab Case Rep
Pays: England
ID NLM: 101618943

Informations de publication

Date de publication:
16 May 2019
Historique:
received: 12 04 2019
accepted: 26 04 2019
entrez: 17 5 2019
pubmed: 17 5 2019
medline: 17 5 2019
Statut: aheadofprint

Résumé

Primary hyperparathyroidism (PHPT) is characterised by the overproduction of parathyroid hormone (PTH) due to parathyroid hyperplasia, adenoma or carcinoma and results in hypercalcaemia and a raised or inappropriately normal PTH. Symptoms of hypercalcaemia occur in 20% of patients and include fatigue, nausea, constipation, depression, renal impairment and cardiac arrythmias. In the most severe cases, uraemia, coma or cardiac arrest can result. Primary hyperparathyroidism in pregnancy is rare, with a reported incidence of 1%. Maternal and fetal/neonatal complications are estimated to occur in 67 and 80% of untreated cases respectively. Maternal complications include nephrolithiasis, pancreatitis, hyperemesis gravidarum, pre-eclampsia and hypercalcemic crises. Fetal complications include intrauterine growth restriction; preterm delivery and a three to five-fold increased risk of miscarriage. There is a direct relationship between the degree of severity of hypercalcaemia and miscarriage risk, with miscarriage being more common in those patients with a serum calcium greater than 2.85 mmol/L. Neonatal complications include hypocalcemia. Herein, we present a case series of three women who were diagnosed with primary hyperparathyroidism in pregnancy. Case 1 was diagnosed with multiple endocrine neoplasia type 1 (MEN1) in pregnancy and required a bilateral neck exploration and subtotal parathyroidectomy in the second trimester of her pregnancy due to symptomatic severe hypercalcaemia. Both case 2 and case 3 were diagnosed with primary hyperparathyroidism due to a parathyroid adenoma and required a unilateral parathyroidectomy in the second trimester. This case series highlights the work-up and the tailored management approach to patients with primary hyperparathyroidism in pregnancy. Learning points: Primary hyperparathyroidism in pregnancy is associated with a high incidence of associated maternal fetal and neonatal complications directly proportionate to degree of maternal serum calcium levels. Parathyroidectomy is the definitive treatment for primary hyperparathyroidism in pregnancy and was used in the management of all three cases in this series. It is recommended when serum calcium is persistently greater than 2.75 mmol/L and or for the management of maternal or fetal complications of hypercalcaemia. Surgical management, when necessary is ideally performed in the second trimester. Primary hyperparathyroidism is genetically determined in ~10% of cases, where the likelihood is increased in those under 40 years, where there is relevant family history and those with other related endocrinopathies. Genetic testing is a useful diagnostic adjunct and can guide treatment and management options for patients diagnosed with primary hyperparathyroidism in pregnancy, as described in case 1 in this series, who was diagnosed with MEN1 syndrome. Women of reproductive age with primary hyperparathyroidism need to be informed of the risks and complications associated with primary hyperparathyroidism in pregnancy and pregnancy should be deferred and or avoided until curative surgery has been performed and calcium levels have normalised.

Identifiants

pubmed: 31096181
doi: 10.1530/EDM-19-0039
pii: EDM190039
pmc: PMC6528402
doi:
pii:

Types de publication

Journal Article

Langues

eng

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Auteurs

Aisling McCarthy (A)

University Hospital Galway, Galway, Ireland.

Sophie Howarth (S)

Department of Diabetes and Endocrinology, Cambridge University NHS Foundation Trust, Cambridge, UK.

Serena Khoo (S)

Department of Diabetes and Endocrinology, Cambridge University NHS Foundation Trust, Cambridge, UK.

Julia Hale (J)

Department of Diabetes and Endocrinology, Cambridge University NHS Foundation Trust, Cambridge, UK.

Sue Oddy (S)

Department of Clinical Biochemistry, Cambridge University NHS Foundation Trust, Cambridge, UK.

David Halsall (D)

Department of Clinical Biochemistry, Cambridge University NHS Foundation Trust, Cambridge, UK.

Brian Fish (B)

Department of Head and Neck Surgery, Cambridge University NHS Foundation Trust, Cambridge, UK.

Sashi Mariathasan (S)

Department of Diabetes and Endocrinology, Cambridge University NHS Foundation Trust, Cambridge, UK.

Katrina Andrews (K)

East Anglian Medical Genetics Service, Cambridge University Hospitals NHS Foundation Trust, Cambridge Biomedical Campus, Cambridge, UK.

Samson O Oyibo (SO)

Department of Diabetes and Endocrinology, Peterborough City Hospital, North West Anglia NHS Foundation Trust, Peterborough, UK.

Manjula Samyraju (M)

Department of Obstetrics and Gynecology, Peterborough City Hospital, North West Anglia NHS Foundation Trust, Peterborough, UK.

Katarzyna Gajewska-Knapik (K)

Department of Obstetrics and Gynecology, Cambridge University NHS Foundation Trust, Cambridge, UK.

Soo-Mi Park (SM)

East Anglian Medical Genetics Service, Cambridge University Hospitals NHS Foundation Trust, Cambridge Biomedical Campus, Cambridge, UK.

Diana Wood (D)

Department of Diabetes and Endocrinology, Cambridge University NHS Foundation Trust, Cambridge, UK.

Carla Moran (C)

Department of Diabetes and Endocrinology, Cambridge University NHS Foundation Trust, Cambridge, UK.

Ruth T Casey (RT)

Department of Diabetes and Endocrinology, Cambridge University NHS Foundation Trust, Cambridge, UK.
Department of Medical Genetics, Cambridge University, Cambridge, UK.

Classifications MeSH