Emergence and Transmission of Drug-/Multidrug-resistant Mycobacterium leprae in a Former Leprosy Colony in the Brazilian Amazon.


Journal

Clinical infectious diseases : an official publication of the Infectious Diseases Society of America
ISSN: 1537-6591
Titre abrégé: Clin Infect Dis
Pays: United States
ID NLM: 9203213

Informations de publication

Date de publication:
06 05 2020
Historique:
received: 02 04 2019
accepted: 28 06 2019
pubmed: 2 7 2019
medline: 7 1 2021
entrez: 2 7 2019
Statut: ppublish

Résumé

Leprosy has been treated with multidrug therapy, which has been distributed for free across the globe and regarded as highly efficient. However, the impossibility of growing Mycobacterium leprae in axenic media has historically impaired assessments of M. leprae resistance, a parameter only recently detectable through molecular methods. A systematic, population-based search for M. leprae resistance in suspected leprosy relapse cases and contacts was performed in Prata Village, an isolated, hyperendemic, former leprosy colony located in the Brazilian Amazon. Results led to an extended active search involving the entire Prata population. Confirmed leprosy cases were investigated for bacterial resistance using a combination of in vivo testing and direct sequencing of resistance genes folP1, rpoB, and gyrA. A molecular epidemiology analysis was performed using data from 17 variable number tandem repeats (VNTR). Mycobacterium leprae was obtained from biopsies of 37 leprosy cases (18 relapses and 19 new cases): 16 (43.24%) displayed drug-resistance variants. Multidrug resistance to rifampicin and dapsone was observed in 8 relapses and 4 new cases. Single resistance to rifampicin was detected in 1 new case. Resistance to dapsone was present in 2 relapses and 1 new case. Combined molecular resistance and VNTR data revealed evidence of intra-familial primary transmission of resistant M. leprae. A comprehensive, population-based systematic approach to investigate M. leprae resistance in a unique population revealed an alarming scenario of the emergence and transmission of resistant strains. These findings may be used for the development of new strategies for surveillance of drug resistance in other populations.

Sections du résumé

BACKGROUND
Leprosy has been treated with multidrug therapy, which has been distributed for free across the globe and regarded as highly efficient. However, the impossibility of growing Mycobacterium leprae in axenic media has historically impaired assessments of M. leprae resistance, a parameter only recently detectable through molecular methods.
METHODS
A systematic, population-based search for M. leprae resistance in suspected leprosy relapse cases and contacts was performed in Prata Village, an isolated, hyperendemic, former leprosy colony located in the Brazilian Amazon. Results led to an extended active search involving the entire Prata population. Confirmed leprosy cases were investigated for bacterial resistance using a combination of in vivo testing and direct sequencing of resistance genes folP1, rpoB, and gyrA. A molecular epidemiology analysis was performed using data from 17 variable number tandem repeats (VNTR).
RESULTS
Mycobacterium leprae was obtained from biopsies of 37 leprosy cases (18 relapses and 19 new cases): 16 (43.24%) displayed drug-resistance variants. Multidrug resistance to rifampicin and dapsone was observed in 8 relapses and 4 new cases. Single resistance to rifampicin was detected in 1 new case. Resistance to dapsone was present in 2 relapses and 1 new case. Combined molecular resistance and VNTR data revealed evidence of intra-familial primary transmission of resistant M. leprae.
CONCLUSIONS
A comprehensive, population-based systematic approach to investigate M. leprae resistance in a unique population revealed an alarming scenario of the emergence and transmission of resistant strains. These findings may be used for the development of new strategies for surveillance of drug resistance in other populations.

Identifiants

pubmed: 31260522
pii: 5526733
doi: 10.1093/cid/ciz570
pmc: PMC7201420
doi:

Substances chimiques

Leprostatic Agents 0
Pharmaceutical Preparations 0

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

2054-2061

Informations de copyright

© The Author(s) 2019. Published by Oxford University Press for the Infectious Diseases Society of America.

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Auteurs

Patrícia S Rosa (PS)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Helena R S D'Espindula (HRS)

Graduate Program in Health Sciences, School of Medicine, Pontifícia Universidade Católica do Paraná, Curitiba, Brazil.

Ana C L Melo (ACL)

Centro de Referência Nacional em Dermatologia Sanitária Dona Libânia, Fortaleza, Ceará, Brazil.

Amanda N B Fontes (ANB)

Laboratory of Molecular Biology Applied in Mycobacteria, Fundação Oswaldo Cruz, Rio de Janeiro, Brazil.

Amanda J Finardi (AJ)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Andréa F F Belone (AFF)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Beatriz G C Sartori (BGC)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Carla A A Pires (CAA)

Core of Tropical Diseases, Universidade Federal do Pará, Belém, Brazil.

Cleverson T Soares (CT)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Flávio B Marques (FB)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Francisco J D Branco (FJD)

Centro de Referência Nacional em Dermatologia Sanitária Dona Libânia, Fortaleza, Ceará, Brazil.

Ida M F D Baptista (IMFD)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Lázara M Trino (LM)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Luciana R V Fachin (LRV)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Marília B Xavier (MB)

Core of Tropical Diseases, Universidade Federal do Pará, Belém, Brazil.
Center for Biological and Health Sciences, Universidade do Estado do Pará, Belém, Brazil.

Marcos C Floriano (MC)

Department of Dermatology, Universidade Federal de São Paulo, Brazil.

Somei Ura (S)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Suzana M Diório (SM)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Wladimir F B Delanina (WFB)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Milton O Moraes (MO)

Laboratory of Molecular Biology Applied in Mycobacteria, Fundação Oswaldo Cruz, Rio de Janeiro, Brazil.

Marcos C L Virmond (MCL)

Division of Research and Education, Instituto Lauro de Souza Lima, Bauru, São Paulo, Brazil.

Philip N Suffys (PN)

Laboratory of Molecular Biology Applied in Mycobacteria, Fundação Oswaldo Cruz, Rio de Janeiro, Brazil.

Marcelo T Mira (MT)

Graduate Program in Health Sciences, School of Medicine, Pontifícia Universidade Católica do Paraná, Curitiba, Brazil.

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Classifications MeSH