A large data resource of genomic copy number variation across neurodevelopmental disorders.

Molecular medicine Neurodevelopmental disorders Pathogenesis

Journal

NPJ genomic medicine
ISSN: 2056-7944
Titre abrégé: NPJ Genom Med
Pays: England
ID NLM: 101685193

Informations de publication

Date de publication:
2019
Historique:
received: 06 05 2019
accepted: 05 09 2019
entrez: 12 10 2019
pubmed: 12 10 2019
medline: 12 10 2019
Statut: epublish

Résumé

Copy number variations (CNVs) are implicated across many neurodevelopmental disorders (NDDs) and contribute to their shared genetic etiology. Multiple studies have attempted to identify shared etiology among NDDs, but this is the first genome-wide CNV analysis across autism spectrum disorder (ASD), attention deficit hyperactivity disorder (ADHD), schizophrenia (SCZ), and obsessive-compulsive disorder (OCD) at once. Using microarray (Affymetrix CytoScan HD), we genotyped 2,691 subjects diagnosed with an NDD (204 SCZ, 1,838 ASD, 427 ADHD and 222 OCD) and 1,769 family members, mainly parents. We identified rare CNVs, defined as those found in <0.1% of 10,851 population control samples. We found clinically relevant CNVs (broadly defined) in 284 (10.5%) of total subjects, including 22 (10.8%) among subjects with SCZ, 209 (11.4%) with ASD, 40 (9.4%) with ADHD, and 13 (5.6%) with OCD. Among all NDD subjects, we identified 17 (0.63%) with aneuploidies and 115 (4.3%) with known genomic disorder variants. We searched further for genes impacted by different CNVs in multiple disorders. Examples of NDD-associated genes linked across more than one disorder (listed in order of occurrence frequency) are

Identifiants

pubmed: 31602316
doi: 10.1038/s41525-019-0098-3
pii: 98
pmc: PMC6779875
doi:

Types de publication

Journal Article

Langues

eng

Pagination

26

Subventions

Organisme : NHGRI NIH HHS
ID : U01 HG004438
Pays : United States
Organisme : NHGRI NIH HHS
ID : U01 HG004446
Pays : United States
Organisme : NIMH NIH HHS
ID : R01 MH101493
Pays : United States
Organisme : NCI NIH HHS
ID : P01 CA089392
Pays : United States
Organisme : NIDA NIH HHS
ID : P50 DA019706
Pays : United States
Organisme : NHGRI NIH HHS
ID : U01 HG004422
Pays : United States
Organisme : NIDA NIH HHS
ID : R01 DA013423
Pays : United States
Organisme : NIAAA NIH HHS
ID : U10 AA008401
Pays : United States
Organisme : NHGRI NIH HHS
ID : HHSN268200782096C
Pays : United States
Organisme : NIMH NIH HHS
ID : R01 MH085321
Pays : United States
Organisme : NCI NIH HHS
ID : P50 CA084724
Pays : United States

Informations de copyright

© The Author(s) 2019.

Déclaration de conflit d'intérêts

Competing interestsS.W.S. serves on the Scientific Advisory Committees of Population Bio and Deep Genomics; intellectual property originating from his research and held at the Hospital for Sick Children is licensed to Lineagen, and separately Athena Diagnostics. D.M. is a full-time employee of Deep Genomics and is entitled to a stock option. R.J.S., P.D.A., and J.C. consult for Highland Therapeutics. Intellectual property from ADHD research at the Hospital for Sick Children is licensed to Ehave and the National Research Council of Canada. Other authors declare no competing interests for the data and interpretation presented in this study. R.J.S., P.D.A., and J.C. consults for Highland Therapeutics. Intellectual property from their research at the Hospital for Sick Children is licensed to Ehave and the National Research Council. D.M. is a full-time employee of Deep Genomics and is entitled to stock options. S.W.S. is on the Scientific Advisory Committees of Population Bio and Deep Genomics; intellectual property from his research held at the Hospital for Sick Children is licensed to Athena Diagnostics, and separately to Lineagen. These relationships did not influence data interpretation or presentation during this study, but are disclosed for potential future consideration.

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Auteurs

Mehdi Zarrei (M)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.

Christie L Burton (CL)

3Neurosciences and Mental Health Program, The Hospital for Sick Children, Toronto, ON Canada.

Worrawat Engchuan (W)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.

Edwin J Young (EJ)

4Genome Diagnostics, Department of Paediatric Laboratory Medicine, The Hospital for Sick Children, Toronto, ON Canada.

Edward J Higginbotham (EJ)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.
5Department of Molecular Genetics, University of Toronto, Toronto, ON Canada.

Jeffrey R MacDonald (JR)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Brett Trost (B)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.

Ada J S Chan (AJS)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.
5Department of Molecular Genetics, University of Toronto, Toronto, ON Canada.

Susan Walker (S)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Sylvia Lamoureux (S)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Tracy Heung (T)

6Clinical Genetics Research Program, Centre for Addiction and Mental Health, Toronto, ON Canada.

Bahareh A Mojarad (BA)

2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.

Barbara Kellam (B)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Tara Paton (T)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Muhammad Faheem (M)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.

Karin Miron (K)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.

Chao Lu (C)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Ting Wang (T)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Kozue Samler (K)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Xiaolin Wang (X)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Gregory Costain (G)

7Division of Clinical and Metabolic Genetics, The Hospital for Sick Children, Toronto, ON Canada.
8Medical Genetics Residency Training Program, University of Toronto, Toronto, ON Canada.

Ny Hoang (N)

2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.
5Department of Molecular Genetics, University of Toronto, Toronto, ON Canada.
9Department of Genetic Counselling, The Hospital for Sick Children, Toronto, ON Canada.

Giovanna Pellecchia (G)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

John Wei (J)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Rohan V Patel (RV)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Bhooma Thiruvahindrapuram (B)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Maian Roifman (M)

7Division of Clinical and Metabolic Genetics, The Hospital for Sick Children, Toronto, ON Canada.
10The Prenatal Diagnosis and Medical Genetics Program, Department of Obstetrics and Gynecology, Mount Sinai Hospital, Toronto, ON Canada.
11Department of Paediatrics, University of Toronto, Toronto, ON Canada.

Daniele Merico (D)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
Deep Genomics Inc., Toronto, ON Canada.

Tara Goodale (T)

3Neurosciences and Mental Health Program, The Hospital for Sick Children, Toronto, ON Canada.

Irene Drmic (I)

Hamilton Health Sciences, Ron Joyce Children's Health Centre, Hamilton, On Canada.

Marsha Speevak (M)

14Trillium Health Partners Credit Valley Site, Mississauga, Ontario Canada.

Jennifer L Howe (JL)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Ryan K C Yuen (RKC)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.

Janet A Buchanan (JA)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

Jacob A S Vorstman (JAS)

15Department of Psychiatry, University of Toronto, Toronto, ON Canada.
16Autism Research Unit, The Hospital for Sick Children, Toronto, ON Canada.

Christian R Marshall (CR)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
4Genome Diagnostics, Department of Paediatric Laboratory Medicine, The Hospital for Sick Children, Toronto, ON Canada.
17Laboratory Medicine and Pathobiology, University of Toronto, Toronto, ON Canada.

Richard F Wintle (RF)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.

David R Rosenberg (DR)

18Department of Psychiatry and Behavioral Neurosciences, Wayne State University, Detroit, MI USA.
19The Children's Hospital of Michigan, Detroit, MI United States.

Gregory L Hanna (GL)

20Department of Psychiatry, University of Michigan, Ann Arbor, MI USA.

Marc Woodbury-Smith (M)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
21Institute of Neuroscience, Newcastle University, Newcastle upon Tyne, UK.

Cheryl Cytrynbaum (C)

2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.
5Department of Molecular Genetics, University of Toronto, Toronto, ON Canada.
7Division of Clinical and Metabolic Genetics, The Hospital for Sick Children, Toronto, ON Canada.
22Dalla Lana School of Public Health and the Department of Family and Community Medicine, University of Toronto, Toronto, ON Canada.

Lonnie Zwaigenbaum (L)

23Department of Pediatrics, University of Alberta, Edmonton, AB Canada.

Mayada Elsabbagh (M)

24Montreal Neurological Institute, McGill University, Montreal, QC Canada.

Janine Flanagan (J)

11Department of Paediatrics, University of Toronto, Toronto, ON Canada.

Bridget A Fernandez (BA)

25Discipline of Genetics, Faculty of Medicine, Memorial University of Newfoundland, St. John's, NL Canada.

Melissa T Carter (MT)

26Regional Genetics Program, The Children's Hospital of Eastern Ontario, Ottawa, ON Canada.

Peter Szatmari (P)

15Department of Psychiatry, University of Toronto, Toronto, ON Canada.
27Centre for Addiction and Mental Health, Toronto, ON Canada.
28Department of Psychiatry, The Hospital for Sick Children, Toronto, ON Canada.

Wendy Roberts (W)

16Autism Research Unit, The Hospital for Sick Children, Toronto, ON Canada.

Jason Lerch (J)

29Mouse Imaging Centre, Hospital for Sick Children, Toronto, ON Canada.
30Department of Medical Biophysics, The University of Toronto, Toronto, ON Canada.

Xudong Liu (X)

31Department of Psychiatry, Queen's University, Kinston, ON Canada.

Rob Nicolson (R)

32Children's Health Research Institute, London, ON Canada.
33Western University, London, ON Canada.

Stelios Georgiades (S)

34Department of Psychiatry and Behavioural Neurosciences, McMaster University, Hamilton, ON Canada.

Rosanna Weksberg (R)

2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.
7Division of Clinical and Metabolic Genetics, The Hospital for Sick Children, Toronto, ON Canada.
5Department of Molecular Genetics, University of Toronto, Toronto, ON Canada.

Paul D Arnold (PD)

2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.
35Mathison Centre for Mental Health Research and Education, University of Calgary, Calgary, AB Canada.
36Departments of Psychiatry and Medical Genetics, Cumming School of Medicine, University of Calgary, Calgary, AB Canada.

Anne S Bassett (AS)

6Clinical Genetics Research Program, Centre for Addiction and Mental Health, Toronto, ON Canada.
15Department of Psychiatry, University of Toronto, Toronto, ON Canada.
37The Dalglish Family 22q Clinic, Toronto General Hospital, Toronto, ON Canada.

Jennifer Crosbie (J)

3Neurosciences and Mental Health Program, The Hospital for Sick Children, Toronto, ON Canada.
15Department of Psychiatry, University of Toronto, Toronto, ON Canada.

Russell Schachar (R)

3Neurosciences and Mental Health Program, The Hospital for Sick Children, Toronto, ON Canada.
15Department of Psychiatry, University of Toronto, Toronto, ON Canada.
38Institute of Medical Science, University of Toronto, Toronto, ON Canada.

Dimitri J Stavropoulos (DJ)

4Genome Diagnostics, Department of Paediatric Laboratory Medicine, The Hospital for Sick Children, Toronto, ON Canada.

Evdokia Anagnostou (E)

39Holland Bloorview Kids Rehabilitation Hospital, University of Toronto, Toronto, ON Canada.

Stephen W Scherer (SW)

1The Centre for Applied Genomics, The Hospital for Sick Children, Toronto, ON Canada.
2Program in Genetics and Genome Biology, The Hospital for Sick Children, Toronto, ON Canada.
5Department of Molecular Genetics, University of Toronto, Toronto, ON Canada.
40Department of Molecular Genetics and McLaughlin Centre, University of Toronto, Toronto, ON Canada.

Classifications MeSH