Gamma Knife Radiosurgery for Short Unilateral Neuralgiform Headache Attacks with Conjunctival Injection and Tearing (SUNCT) Syndrome: Targeting the Trigeminal Nerve and the Sphenopalatine Ganglion. Case Report and Literature Review.

Gamma knife radiosurgery Short-lasting unilateral neuralgiform headache attacks with conjunctival injection and tearing Sphenopalatine ganglion Trigeminal nerve

Journal

World neurosurgery
ISSN: 1878-8769
Titre abrégé: World Neurosurg
Pays: United States
ID NLM: 101528275

Informations de publication

Date de publication:
Jan 2020
Historique:
received: 28 06 2019
revised: 02 10 2019
accepted: 03 10 2019
pubmed: 14 10 2019
medline: 28 1 2020
entrez: 14 10 2019
Statut: ppublish

Résumé

Short-lasting unilateral neuralgiform headache attacks with conjunctival injection and tearing (SUNCT) is a primary headache syndrome with an unclear pathogenesis, and only in very few cases, SUNCT is secondary to known lesions (secondary SUNCT). Several pharmacological as well as interventional and invasive treatments have been used to treat SUNT cases, with no definitive results. We describe a patient with idiopathic SUNCT syndrome, successfully treated with gamma knife radiosurgery and we report a review of the cases of the literature treated with radiosurgery. A 63-year-old woman complained of episodes of intense and regular paroxysmal facial pain in the territory of the maxillary branch of the trigeminal nerve accompanied by inflammation of conjunctiva and involuntary lacrimation from 2006. During the following years, she received several treatments: combination of drugs, acupuncture, and endonasal infiltration of the sphenopalatine ganglion. The frequency of the painful attacks increased progressively and it was impossible for her to have a normal active life. Combined gamma knife radiosurgery treatment, targeting the trigeminal nerve (80 Gy maximum dose) and the sphenopalatine ganglion (80 Gy maximum dose) was performed in April 2016 (visual analog score before treatment = 6). Pain gradually reduced in the following months, as well as frequency and severity of the attacks. No sensory deficit developed. The follow-up length of our patient is 37 months: she is nearly pain free (visual analog score = 2) and has resumed a normal life. Patients with idiopathic SUNCT have few therapeutic options. Our case demonstrates that gamma knife radiosurgery is a feasible and effective noninvasive option to treat patients with medically refractory idiopathic SUNCT.

Sections du résumé

BACKGROUND BACKGROUND
Short-lasting unilateral neuralgiform headache attacks with conjunctival injection and tearing (SUNCT) is a primary headache syndrome with an unclear pathogenesis, and only in very few cases, SUNCT is secondary to known lesions (secondary SUNCT). Several pharmacological as well as interventional and invasive treatments have been used to treat SUNT cases, with no definitive results. We describe a patient with idiopathic SUNCT syndrome, successfully treated with gamma knife radiosurgery and we report a review of the cases of the literature treated with radiosurgery.
CASE REPORT METHODS
A 63-year-old woman complained of episodes of intense and regular paroxysmal facial pain in the territory of the maxillary branch of the trigeminal nerve accompanied by inflammation of conjunctiva and involuntary lacrimation from 2006. During the following years, she received several treatments: combination of drugs, acupuncture, and endonasal infiltration of the sphenopalatine ganglion. The frequency of the painful attacks increased progressively and it was impossible for her to have a normal active life. Combined gamma knife radiosurgery treatment, targeting the trigeminal nerve (80 Gy maximum dose) and the sphenopalatine ganglion (80 Gy maximum dose) was performed in April 2016 (visual analog score before treatment = 6). Pain gradually reduced in the following months, as well as frequency and severity of the attacks. No sensory deficit developed. The follow-up length of our patient is 37 months: she is nearly pain free (visual analog score = 2) and has resumed a normal life.
CONCLUSIONS CONCLUSIONS
Patients with idiopathic SUNCT have few therapeutic options. Our case demonstrates that gamma knife radiosurgery is a feasible and effective noninvasive option to treat patients with medically refractory idiopathic SUNCT.

Identifiants

pubmed: 31606507
pii: S1878-8750(19)32631-2
doi: 10.1016/j.wneu.2019.10.016
pii:
doi:

Types de publication

Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

167-171

Informations de copyright

Copyright © 2019 Elsevier Inc. All rights reserved.

Auteurs

Ismail Zaed (I)

Neurosurgery, Humanitas Clinical and Research Center - IRCCS, Via Alessandro Manzoni, 56, 22089, Rozzano - Milano, Italy. Electronic address: ismailzaed1@gmail.com.

Luca Attuati (L)

Neurosurgery, Humanitas Clinical and Research Center - IRCCS, Via Alessandro Manzoni, 56, 22089, Rozzano - Milano, Italy.

Concezione Tommasino (C)

Department of Biomedical, Surgical and Odontoiatric Sciences, University of Milano, ASST Santi Paolo e Carlo University Hospital, Milano, Italy.

Enrico Massimo Arosio (EM)

Anesthesia, Humanitas Clinical and Research Center - IRCCS, Rozzano - Milano, Italy.

Pierina Navarria (P)

Radiation Oncology, Humanitas Clinical and Research Center - IRCCS, Rozzano - Milano, Italy.

Antonella Stravato (A)

Medical Physics, Humanitas Clinical and Research Center - IRCCS, Rozzano - Milano, Italy.

Giovanni Colombo (G)

Otorhinolaryngology Unit, Humanitas Clinical and Research Center-IRCCS, Rozzano - Milano, Italy.

Piero Picozzi (P)

Neurosurgery, Humanitas Clinical and Research Center - IRCCS, Via Alessandro Manzoni, 56, 22089, Rozzano - Milano, Italy.

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