A Novel Frameshift Mutation Associated with Hurler's Syndrome: A Case Report.

alpha-l-iduronidase lysosomal storage disorder mucopolysaccharidosis type 1 mutation

Journal

Journal of pediatric genetics
ISSN: 2146-4596
Titre abrégé: J Pediatr Genet
Pays: Germany
ID NLM: 101589859

Informations de publication

Date de publication:
Dec 2019
Historique:
received: 04 12 2018
accepted: 02 03 2019
entrez: 6 11 2019
pubmed: 7 11 2019
medline: 7 11 2019
Statut: ppublish

Résumé

Mucopolysaccharidosis 1 (MPS1) is a rare inherited lysosomal storage disorder resulting from the absence or reduction of lysosomal alpha-l-iduronidase due to mutations in the

Identifiants

pubmed: 31687259
doi: 10.1055/s-0039-1685190
pii: 1800056
pmc: PMC6824898
doi:

Types de publication

Case Reports

Langues

eng

Pagination

212-217

Informations de copyright

© Thieme Medical Publishers.

Références

Genet Med. 2003 Jul-Aug;5(4):286-94
pubmed: 12865757
Am J Med Genet A. 2009 May;149A(5):965-74
pubmed: 19396826
J Inherit Metab Dis. 2013 Mar;36(2):179-87
pubmed: 22976768
Mutat Res Rev Mutat Res. 2014 Oct-Dec;762:52-64
pubmed: 25485595
J Inherit Metab Dis. 2010 Aug;33(4):421-7
pubmed: 20532982
Hum Mutat. 1995;6(4):288-302
pubmed: 8680403
Mol Genet Metab. 2013 Aug;109(4):377-81
pubmed: 23786846
Nat Chem Biol. 2013 Nov;9(11):739-45
pubmed: 24036510
Hum Mutat. 2011 Jun;32(6):E2189-210
pubmed: 21394825
Orphanet J Rare Dis. 2011 Aug 10;6:55
pubmed: 21831279
Genet Med. 2002 Nov-Dec;4(6):420-6
pubmed: 12509712
Clin Chim Acta. 2017 Nov;474:88-95
pubmed: 28844463
Cochrane Database Syst Rev. 2016 Apr 01;4:CD009354
pubmed: 27033167
Org Biomol Chem. 2016 Feb 7;14(5):1559-63
pubmed: 26740124
J Formos Med Assoc. 2002 Jun;101(6):425-8
pubmed: 12189649
Hum Mol Genet. 1993 Sep;2(9):1471-3
pubmed: 8242073
J Pediatr. 2017 Mar;182:363-370
pubmed: 27939258
Mol Genet Metab. 2014 Feb;111(2):63-72
pubmed: 24388732
Biochem J. 2010 Sep 15;430(3):365-77
pubmed: 20795950
Hum Mol Genet. 1994 Jun;3(6):861-6
pubmed: 7951228
Genomics. 1992 Aug;13(4):1311-3
pubmed: 1505961
Clin Genet. 2018 Jul;94(1):95-102
pubmed: 29393969
Proc Natl Acad Sci U S A. 1991 Nov 1;88(21):9695-9
pubmed: 1946389
Clin Chim Acta. 2014 Sep 25;436:112-20
pubmed: 24875751
Orphanet J Rare Dis. 2015 Sep 25;10:121
pubmed: 26407983

Auteurs

Mana Kamranjam (M)

Department of Medical Genetics, Special Medical Center, Tehran, Iran.

Seyedeh Maryam Hosseini (SM)

Department of Medical Genetics, Special Medical Center, Tehran, Iran.

Mohammadreza Alaei (M)

Department of Pediatric Endocrinology, Faculty of Medicine, Shahid Beheshti University of Medical Sciences, Tehran, Iran.

Classifications MeSH