Macular corneal dystrophy with isolated peripheral Descemet membrane deposits.

Corneal dystrophy Corneal endothelial disease Macular corneal dystrophy

Journal

American journal of ophthalmology case reports
ISSN: 2451-9936
Titre abrégé: Am J Ophthalmol Case Rep
Pays: United States
ID NLM: 101679941

Informations de publication

Date de publication:
Dec 2019
Historique:
received: 28 01 2019
revised: 02 09 2019
accepted: 05 11 2019
entrez: 5 12 2019
pubmed: 5 12 2019
medline: 5 12 2019
Statut: epublish

Résumé

Macular Corneal Dystrophy (MCD, MIM #217800) is a category 1 corneal stromal dystrophy as per the current IC3D classification. While characterized by macular stromal deposits, we report a case of MCD type II with isolated bilateral peripheral Decemet membrane opacities, describing the clinical features and results of screening the A 68-year-old man with an unremarkable past medical and family history presented with bilateral progressive decrease in vision. Ocular exam revealed bilateral clear corneas with the exception of peripheral, round, gray-white discrete deposits at the level of Descemet membrane and decreased central corneal thickness in both eyes. The morphology of the corneal deposits, decreased corneal thickness and the absence of a family history were consistent with MCD, prompting screening of the Although macular corneal dystrophy is classified as a corneal stromal dystrophy with endothelial involvement, we report a case of MCD with dystrophic deposits confined to the peripheral Descemet membrane, indicating that MCD may be associated with isolated endothelial involvement.

Identifiants

pubmed: 31799478
doi: 10.1016/j.ajoc.2019.100571
pii: S2451-9936(19)30013-1
pii: 100571
pmc: PMC6881691
doi:

Types de publication

Case Reports

Langues

eng

Pagination

100571

Subventions

Organisme : NEI NIH HHS
ID : P30 EY000331
Pays : United States

Informations de copyright

© 2019 Published by Elsevier Inc.

Déclaration de conflit d'intérêts

All authors have no conflicts of interest to report.

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Auteurs

Wenlin Zhang (W)

Stein Eye Institute, UCLA, Los Angeles, CA, 90095, USA.

Austin Connor Kassels (AC)

Stein Eye Institute, UCLA, Los Angeles, CA, 90095, USA.

Alice Barrington (A)

Stein Eye Institute, UCLA, Los Angeles, CA, 90095, USA.

Shaukat Khan (S)

Nemours/Alfred I duPont Hospital for Children, Wilmington, DE, 19803, USA.

Shunji Tomatsu (S)

Nemours/Alfred I duPont Hospital for Children, Wilmington, DE, 19803, USA.

Turad Alkadi (T)

Al Imam Mohammad Ibn Saud Islamic University, Riyadh, Saudi Arabia.

Anthony Aldave (A)

Stein Eye Institute, UCLA, Los Angeles, CA, 90095, USA.

Classifications MeSH