Is There an Independent Role of TERT and NF1 in High Grade Gliomas?


Journal

Translational oncology
ISSN: 1936-5233
Titre abrégé: Transl Oncol
Pays: United States
ID NLM: 101472619

Informations de publication

Date de publication:
Feb 2020
Historique:
received: 10 07 2019
revised: 25 10 2019
accepted: 29 10 2019
pubmed: 1 1 2020
medline: 1 1 2020
entrez: 1 1 2020
Statut: ppublish

Résumé

High grade glioma molecular profiling is of particular interest in neurooncology. The role of telomerase reverse transcriptase (TERT) varies dependent upon other molecular parameters. We explored the role of TERT in 101 high-grade gliomas. A total of 101 patients (pts) with grade III-IV gliomas treated with standard of care and informative tumor genotypes were included in the present study. Of 55 genes targeted with the next-generation sequencing panel, mutations (muts) were found in 37; these were included in the analysis. TERT mut were tested with Sanger sequencing. MGMT promoter methylation status was determined by methylation specific PCR. 270 mut were detected in 92/101 tumors (91.1%). TERT was the most frequently mutated gene (74.3%). IDH1/2 mut were mutually exclusive with mut in the neurofibromin 1 (NF1) gene. Mutated TERT was associated with wild-type (wt) IDH1/2 (p = 0.025). The 12-month overall survival (OS) rate was 74.3% (median OS: 22 months). Pts with TERT and NF1 wt had a median OS of 40.8 months, while among pts with NF1 wt/TERT mutant, the median OS was 18.5 months. NF1 and TERT mut univariately conferred shorter OS (HR = 3.19; p = 0.004 and HR = 2.28; p = 0.002). Upon multivariate analysis, mutated TERT showed marginal unfavorable prognostic significance for OS (p = 0.049), while NF1 lost its unfavorable significance (p = 0.151). TERT is herein proven to confer poor prognosis in high grade gliomas, independent of IDH and MGMT. NF1 seems to also confer poor prognosis although our small numbers do not allow for firm conclusions.

Sections du résumé

BACKGROUND BACKGROUND
High grade glioma molecular profiling is of particular interest in neurooncology. The role of telomerase reverse transcriptase (TERT) varies dependent upon other molecular parameters. We explored the role of TERT in 101 high-grade gliomas.
METHODS METHODS
A total of 101 patients (pts) with grade III-IV gliomas treated with standard of care and informative tumor genotypes were included in the present study. Of 55 genes targeted with the next-generation sequencing panel, mutations (muts) were found in 37; these were included in the analysis. TERT mut were tested with Sanger sequencing. MGMT promoter methylation status was determined by methylation specific PCR.
RESULTS RESULTS
270 mut were detected in 92/101 tumors (91.1%). TERT was the most frequently mutated gene (74.3%). IDH1/2 mut were mutually exclusive with mut in the neurofibromin 1 (NF1) gene. Mutated TERT was associated with wild-type (wt) IDH1/2 (p = 0.025). The 12-month overall survival (OS) rate was 74.3% (median OS: 22 months). Pts with TERT and NF1 wt had a median OS of 40.8 months, while among pts with NF1 wt/TERT mutant, the median OS was 18.5 months. NF1 and TERT mut univariately conferred shorter OS (HR = 3.19; p = 0.004 and HR = 2.28; p = 0.002). Upon multivariate analysis, mutated TERT showed marginal unfavorable prognostic significance for OS (p = 0.049), while NF1 lost its unfavorable significance (p = 0.151).
CONCLUSIONS CONCLUSIONS
TERT is herein proven to confer poor prognosis in high grade gliomas, independent of IDH and MGMT. NF1 seems to also confer poor prognosis although our small numbers do not allow for firm conclusions.

Identifiants

pubmed: 31891871
pii: S1936-5233(19)30350-X
doi: 10.1016/j.tranon.2019.10.016
pmc: PMC6940679
pii:
doi:

Types de publication

Journal Article

Langues

eng

Pagination

346-354

Informations de copyright

Copyright © 2019 The Authors. Published by Elsevier Inc. All rights reserved.

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Auteurs

Evangelia Razis (E)

Third Department of Medical Oncology, Hygeia Hospital, 4 Erithrou Stavrou St, Marousi, 15123 Athens, Greece. Electronic address: e.razis@hygeia.gr.

Vassiliki Kotoula (V)

Department of Pathology, Aristotle University of Thessaloniki, School of Health Sciences, Faculty of Medicine, University Campus, Building 17B, 54006 Thessaloniki, Greece; Laboratory of Molecular Oncology, Hellenic Foundation for Cancer Research/Aristotle University of Thessaloniki, University Campus, Building 17B, 54006 Thessaloniki, Greece.

Georgia-Angeliki Koliou (GA)

Section of Biostatistics, Hellenic Cooperative Oncology Group, Athens, Greece.

Kyriaki Papadopoulou (K)

Laboratory of Molecular Oncology, Hellenic Foundation for Cancer Research/Aristotle University of Thessaloniki, University Campus, Building 17B, 54006 Thessaloniki, Greece.

Eleni Vrettou (E)

Department of Pathology, Aristotle University of Thessaloniki, School of Health Sciences, Faculty of Medicine, University Campus, Building 17B, 54006 Thessaloniki, Greece.

Eleni Giannoulatou (E)

Victor Chang Cardiac Research Institute, Lowy Packer Building, 405 Liverpool Street, Darlinghurst, NSW 2010, Australia; The University of New South Wales, Kensington, Sydney, NSW 2052, Australia.

Ioannis Tikas (I)

Laboratory of Molecular Oncology, Hellenic Foundation for Cancer Research/Aristotle University of Thessaloniki, University Campus, Building 17B, 54006 Thessaloniki, Greece.

Stefanos V Labropoulos (SV)

Third Department of Medical Oncology, Hygeia Hospital, 4 Erithrou Stavrou St, Marousi, 15123 Athens, Greece.

Georgios Rigakos (G)

Third Department of Medical Oncology, Hygeia Hospital, 4 Erithrou Stavrou St, Marousi, 15123 Athens, Greece.

Styliani Papaemmanoyil (S)

Department of Pathology, General Hospital G. Papanikolaou, Leof. Papanikolaou, Pilea Chortiatis, 57010 Thessaloniki, Greece.

Ourania Romanidou (O)

Department of Medical Oncology, Papageorgiou Hospital, Aristotle University of Thessaloniki, School of Health Sciences, Faculty of Medicine, Periferiaki Odos, Nea Efkarpia, 56403 Thessaloniki, Greece.

Eugenia Bourkoula (E)

GeneKor Medical SA, Leof. Spaton 52, Gerakas, 153 44 Athens, Greece.

Panagiotis Nomikos (P)

Department of Neurosurgery and Gamma Knife Radiosurgery, Hygeia Hospital, 4 Erithrou Stavrou St, Marousi, 15123 Athens, Greece.

Georgios Iliadis (G)

Radiotherapy Department, Interbalkan European Medical Center, Asklipiou 10, Pilea Chortiatis 555 35, Thessaloniki, Greece.

George Nasioulas (G)

GeneKor Medical SA, Leof. Spaton 52, Gerakas, 153 44 Athens, Greece.

Panagiotis Selviaridis (P)

First Department of Neurosurgery, AHEPA University General Hospital, Aristotle University of Thessaloniki, School of Health Sciences, Faculty of Medicine, Kiriakidi 1, 546 21 Thessaloniki, Greece.

Konstantinos Polyzoidis (K)

First Department of Neurosurgery, AHEPA University General Hospital, Aristotle University of Thessaloniki, School of Health Sciences, Faculty of Medicine, Kiriakidi 1, 546 21 Thessaloniki, Greece.

George Fountzilas (G)

Laboratory of Molecular Oncology, Hellenic Foundation for Cancer Research/Aristotle University of Thessaloniki, University Campus, Building 17B, 54006 Thessaloniki, Greece; Aristotle University of Thessaloniki, 54124 Thessaloniki, Greece; German Oncology Center, Avenue Nikis 1, 4108 Agios Athanasios, Limassol, Cyprus.

Classifications MeSH