Mothers' perspectives on challenging behaviours in their children with fragile X syndrome.
Fragile X syndrome
autism spectrum disorders
problem behaviour
Journal
Journal of intellectual & developmental disability
ISSN: 1469-9532
Titre abrégé: J Intellect Dev Disabil
Pays: England
ID NLM: 9610837
Informations de publication
Date de publication:
2019
2019
Historique:
entrez:
4
1
2020
pubmed:
4
1
2020
medline:
19
2
2020
Statut:
ppublish
Résumé
Individuals with intellectual and developmental disabilities are more likely to engage in problem behaviours than peers with typical development. The purpose of this study was to provide descriptive and qualitative information about problem behaviours in children with fragile X syndrome (FXS) and how families respond to these behaviours. We examined interview responses from 53 mothers of 9-year-old children with FXS. Defiance, tantrums, inattention, stereotypy, and aggression were the most frequently reported problem behaviours of children with FXS. Stereotypy, physical aggression, self-injury, and elopement were reported more often by mothers of children with dual diagnoses of FXS and autism than by mothers of children with a single diagnosis of FXS. Results indicated that for many families, by 9 years of age, problem behaviours led to frustration and altered family activities.
Sections du résumé
BACKGROUND
BACKGROUND
Individuals with intellectual and developmental disabilities are more likely to engage in problem behaviours than peers with typical development. The purpose of this study was to provide descriptive and qualitative information about problem behaviours in children with fragile X syndrome (FXS) and how families respond to these behaviours.
METHOD
METHODS
We examined interview responses from 53 mothers of 9-year-old children with FXS.
RESULTS
RESULTS
Defiance, tantrums, inattention, stereotypy, and aggression were the most frequently reported problem behaviours of children with FXS. Stereotypy, physical aggression, self-injury, and elopement were reported more often by mothers of children with dual diagnoses of FXS and autism than by mothers of children with a single diagnosis of FXS.
CONCLUSIONS
CONCLUSIONS
Results indicated that for many families, by 9 years of age, problem behaviours led to frustration and altered family activities.
Identifiants
pubmed: 31896952
doi: 10.3109/13668250.2018.1496379
pmc: PMC6939860
mid: NIHMS1064229
doi:
Types de publication
Journal Article
Langues
eng
Sous-ensembles de citation
IM
Pagination
481-491Subventions
Organisme : NICHD NIH HHS
ID : R01 HD084563
Pays : United States
Organisme : NICHD NIH HHS
ID : U54 HD090216
Pays : United States
Déclaration de conflit d'intérêts
Disclosure statement No potential conflict of interest was reported by the authors.
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