Management of Ewing Sarcoma Family of Tumors: A Short Description of a Rare Primitive Uterine pPNET and Literature Review.

Ewing Sarcoma PNET genetics pPNET

Journal

OncoTargets and therapy
ISSN: 1178-6930
Titre abrégé: Onco Targets Ther
Pays: New Zealand
ID NLM: 101514322

Informations de publication

Date de publication:
2020
Historique:
received: 23 04 2019
accepted: 12 12 2019
entrez: 29 2 2020
pubmed: 29 2 2020
medline: 29 2 2020
Statut: epublish

Résumé

To describe the outcome of a patient with a rare primitive uterine pPNET and to perform a review of the available data in literature, leading the clinicians to better face this rare disease. We have rescued data regarding the multidisciplinary treatment of pPNET from the PUBMED database, highlighting also issues regarding the pathogenesis and the genetic landscape of the ESFTs (Ewing Sarcoma Family of Tumors). Ewing sarcoma and primitive neuroectodermal tumors (PNETs) are small round cell tumors presenting with different degrees of neuroectodermal differentiation. PNETs are further divided into central PNET and peripheral PNET (pPNET). Since pPNETs share the same genetic background of Ewing Sarcomas, they are considered to belong to the Ewing Sarcoma Family of Tumors (ESFTs). Multimodality treatment currently represents the best choice to offer to the affected patients. Although pPNETs are generally diagnosed in children and young adults, an elderly woman aged 85 years came to our attention after a diagnosis of uterine pPNET. Her medical history is presented here, along with a literature review of the subject, highlighting the main biological, pathological and clinical features, with a hypothesis about the possible future therapeutic approaches for these rare malignancies.

Identifiants

pubmed: 32110037
doi: 10.2147/OTT.S213233
pii: 213233
pmc: PMC7034293
doi:

Types de publication

Case Reports

Langues

eng

Pagination

1179-1184

Informations de copyright

© 2020 Pisconti et al.

Déclaration de conflit d'intérêts

All authors declared no conflicts of interest in this work.

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Auteurs

Salvatore Pisconti (S)

Medical Oncology Unit, POC, SS Annunziata, Taranto, Italy.

Giuseppina Della Vittoria Scarpati (G)

Medical Oncology Unit, Pollena Trocchia Hospital, ASL NA3sud, Naples, Italy.

Carlo Buonerba (C)

Department of Clinical Medicine and Surgery, University Federico II of Naples, Naples, Italy.

Simona Messinese (S)

Medical Oncology Unit, POC, SS Annunziata, Taranto, Italy.

Roberta Carella (R)

Medical Oncology Unit, POC, SS Annunziata, Taranto, Italy.

Massimiliano Di Marzo (M)

Department of Abdominal Surgery, National Tumor Institute of Naples IRCCS G. Pascale, Naples, Italy.

Giuseppe Di Lorenzo (G)

Department of Clinical Medicine and Surgery, University Federico II of Naples, Naples, Italy.

Grazia Lazzari (G)

Department of Radiation Oncology, POC, SS Annunziata, Taranto, Italy.

Francesco Perri (F)

Head and Neck Medical Oncology Unit, National Tumor Institute of Naples IRCCS G. Pascale, Naples, Italy.

Raffaele Solla (R)

Department of Radiation Oncology, University of Naples Federico II, Naples, Italy.
Italian National Research Council, Institute of Biostructure & Bioimaging, Naples, Italy.

Classifications MeSH