Quantification of Plasma and Urine Thymidine and 2'-Deoxyuridine by LC-MS/MS for the Pharmacodynamic Evaluation of Erythrocyte Encapsulated Thymidine Phosphorylase in Patients with Mitochondrial Neurogastrointestinal Encephalomyopathy.

2’-deoxyuridine EE-TP LC–MS/MS erythrocyte encapsulated thymidine phosphorylase method validation mitochondrial neurogastrointestinal encephalomyopathy thymidine

Journal

Journal of clinical medicine
ISSN: 2077-0383
Titre abrégé: J Clin Med
Pays: Switzerland
ID NLM: 101606588

Informations de publication

Date de publication:
13 Mar 2020
Historique:
received: 12 02 2020
revised: 05 03 2020
accepted: 11 03 2020
entrez: 19 3 2020
pubmed: 19 3 2020
medline: 19 3 2020
Statut: epublish

Résumé

Mitochondrial neurogastrointestinal encephalomyopathy (MNGIE) is an ultra-rare disorder caused by mutations in

Identifiants

pubmed: 32183169
pii: jcm9030788
doi: 10.3390/jcm9030788
pmc: PMC7141342
pii:
doi:

Types de publication

Journal Article

Langues

eng

Subventions

Organisme : Medical Research Council
ID : MR/K025406/1
Pays : United Kingdom
Organisme : Orphan Technologies
ID : MR/K025406/1

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Auteurs

Karin Kipper (K)

Analytical Services International Ltd., St George's University of London, Cranmer Terrace, London SW17 0RE, UK.
University of Tartu, Institute of Chemistry, 14a Ravila Street, 50411 Tartu, Estonia.

Max Hecht (M)

Analytical Services International Ltd., St George's University of London, Cranmer Terrace, London SW17 0RE, UK.
University of Tartu, Institute of Chemistry, 14a Ravila Street, 50411 Tartu, Estonia.

Natalicia J Antunes (NJ)

Analytical Services International Ltd., St George's University of London, Cranmer Terrace, London SW17 0RE, UK.
Department of Pharmacology, Faculty of Medical Sciences, State University of Campinas (UNICAMP), Campinas, SP 13083-881, Brazil.
Clinical Pharmacology, William Harvey Research Institute, Barts and The London School of Medicine and Dentistry, Queen Mary University of London, London EC1M 6BQ, UK.

Lynette D Fairbanks (LD)

The Purine Research Laboratory, St Thomas' Hospital, London SE1 7EH, UK.

Michelle Levene (M)

Molecular and Clinical Sciences, St George's University of London, London SW17 0RE, UK.

Sema Kalkan Uçar (S)

Division of Inborn Error of Metabolism, Ege University Medical Faculty, 35100 Izmir, Turkey.

Andrew Schaefer (A)

The NHS Highly Specialised Service for Rare Mitochondrial Disorders, Newcastle upon Tyne NE2 4HH, UK.

Emma L Blakely (EL)

The NHS Highly Specialised Service for Rare Mitochondrial Disorders, Newcastle upon Tyne NE2 4HH, UK.

Bridget E Bax (BE)

Molecular and Clinical Sciences, St George's University of London, London SW17 0RE, UK.

Classifications MeSH