Malignant transformation of phosphaturic mesenchymal tumor: a case report and literature review.

FGF23 malignant phosphaturic mesenchymal tumor-mixed connective tissue variant (PMT-MCT) tumor-induced osteomalacia

Journal

Clinical pediatric endocrinology : case reports and clinical investigations : official journal of the Japanese Society for Pediatric Endocrinology
ISSN: 0918-5739
Titre abrégé: Clin Pediatr Endocrinol
Pays: Japan
ID NLM: 9433330

Informations de publication

Date de publication:
2020
Historique:
received: 14 10 2019
accepted: 26 12 2019
entrez: 22 4 2020
pubmed: 22 4 2020
medline: 22 4 2020
Statut: ppublish

Résumé

Phosphaturic mesenchymal tumor, mixed connective tissue variant (PMT-MCT) causes tumor-induced osteomalacia (TIO). Most cases follow a benign clinical course, with rare occurrences of malignant transformation. We report a case of malignant PMT-MCT and review previous malignant cases to identify predictive factors for transformation. A 13-yr-old female, who presented with hypophosphatemic rickets, elevated serum intact fibroblast growth factor 23 (FGF23) levels, and a nodule in the back, received a diagnosis of TIO because of the benign PMT histopathology. After resection of the primary tumor, regular imaging analyses did not indicate any relapse. At 17 years of age, a tumor developed in the left leg and increased in size. The resected tumor showed a histopathology of pleomorphic sarcoma positive for the

Identifiants

pubmed: 32313375
doi: 10.1297/cpe.29.69
pii: 2019-0026
pmc: PMC7160461
doi:

Types de publication

Case Reports

Langues

eng

Pagination

69-75

Informations de copyright

2020©The Japanese Society for Pediatric Endocrinology.

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Auteurs

Noriko Oyama (N)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Kanako Kojima-Ishii (K)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Naoko Toda (N)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Terumichi Matsuo (T)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.
Department of Pediatrics, National Hospital Organization Kyushu Medical Center, Fukuoka, Japan.

Vlad Tocan (V)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Kazuhiro Ohkubo (K)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Utako Oba (U)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Yuhki Koga (Y)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Nokitaka Setsu (N)

Department of Orthopedics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Yuichi Yamada (Y)

Department of Anatomic Pathology, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Kenichi Kohashi (K)

Department of Anatomic Pathology, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Yasuharu Nakashima (Y)

Department of Orthopedics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Yoshinao Oda (Y)

Department of Anatomic Pathology, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Kenji Ihara (K)

Department of Pediatrics, Oita University Faculty of Medicine, Yufu, Japan.

Shouichi Ohga (S)

Department of Pediatrics, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Classifications MeSH