CDK6 is an essential direct target of NUP98 fusion proteins in acute myeloid leukemia.


Journal

Blood
ISSN: 1528-0020
Titre abrégé: Blood
Pays: United States
ID NLM: 7603509

Informations de publication

Date de publication:
23 07 2020
Historique:
received: 10 09 2019
accepted: 08 04 2020
pubmed: 29 4 2020
medline: 26 2 2021
entrez: 29 4 2020
Statut: ppublish

Résumé

Fusion proteins involving Nucleoporin 98 (NUP98) are recurrently found in acute myeloid leukemia (AML) and are associated with poor prognosis. Lack of mechanistic insight into NUP98-fusion-dependent oncogenic transformation has so far precluded the development of rational targeted therapies. We reasoned that different NUP98-fusion proteins deregulate a common set of transcriptional targets that might be exploitable for therapy. To decipher transcriptional programs controlled by diverse NUP98-fusion proteins, we developed mouse models for regulatable expression of NUP98/NSD1, NUP98/JARID1A, and NUP98/DDX10. By integrating chromatin occupancy profiles of NUP98-fusion proteins with transcriptome profiling upon acute fusion protein inactivation in vivo, we defined the core set of direct transcriptional targets of NUP98-fusion proteins. Among those, CDK6 was highly expressed in murine and human AML samples. Loss of CDK6 severely attenuated NUP98-fusion-driven leukemogenesis, and NUP98-fusion AML was sensitive to pharmacologic CDK6 inhibition in vitro and in vivo. These findings identify CDK6 as a conserved, critical direct target of NUP98-fusion proteins, proposing CDK4/CDK6 inhibitors as a new rational treatment option for AML patients with NUP98-fusions.

Identifiants

pubmed: 32344427
pii: S0006-4971(20)61858-4
doi: 10.1182/blood.2019003267
pmc: PMC7115844
mid: EMS86766
doi:

Substances chimiques

Nuclear Pore Complex Proteins 0
Nup98 protein, human 0
Oncogene Proteins, Fusion 0
CDK6 protein, human EC 2.7.11.22
Cdk6 protein, mouse EC 2.7.11.22
Cyclin-Dependent Kinase 6 EC 2.7.11.22

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

387-400

Subventions

Organisme : European Research Council
ID : 636855
Pays : International

Commentaires et corrections

Type : CommentIn

Informations de copyright

© 2020 by The American Society of Hematology.

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Auteurs

Johannes Schmoellerl (J)

Institute for Medical Biochemistry, University of Veterinary Medicine Vienna, Vienna, Austria.

Inês Amorim Monteiro Barbosa (IAM)

Research Institute of Molecular Pathology, Vienna BioCenter, Vienna, Austria.

Thomas Eder (T)

Institute for Medical Biochemistry, University of Veterinary Medicine Vienna, Vienna, Austria.

Tania Brandstoetter (T)

Institute of Pharmacology and Toxicology, University of Veterinary Medicine Vienna, Vienna, Austria.

Luisa Schmidt (L)

Institute for Medical Biochemistry, University of Veterinary Medicine Vienna, Vienna, Austria.

Barbara Maurer (B)

Institute of Pharmacology and Toxicology, University of Veterinary Medicine Vienna, Vienna, Austria.

Selina Troester (S)

Institute for Medical Biochemistry, University of Veterinary Medicine Vienna, Vienna, Austria.

Ha Thi Thanh Pham (HTT)

Institute for Animal Breeding and Genetics, University of Veterinary Medicine Vienna, Vienna, Austria.

Mohanty Sagarajit (M)

Department of Hematology, Hemostasis, Oncology and Stem Cell Transplantation, Hannover Medical School, Hannover, Germany.

Jessica Ebner (J)

Institute for Medical Biochemistry, University of Veterinary Medicine Vienna, Vienna, Austria.
Ludwig Boltzmann Institute for Cancer Research, Vienna, Austria.

Gabriele Manhart (G)

Institute for Medical Biochemistry, University of Veterinary Medicine Vienna, Vienna, Austria.

Ezgi Aslan (E)

Team of Project Machine, Medical Faculty, Istanbul Medeniyet University, Istanbul, Turkey.

Stefan Terlecki-Zaniewicz (S)

Institute for Medical Biochemistry, University of Veterinary Medicine Vienna, Vienna, Austria.

Christa Van der Veen (C)

Ludwig Boltzmann Institute for Cancer Research, Vienna, Austria.

Gregor Hoermann (G)

Department of Laboratory Medicine, Medical University of Vienna, Vienna, Austria.
Central Institute for Medical and Chemical Laboratory Diagnosis, University Hospital Innsbruck, Innsbruck, Austria.

Nicolas Duployez (N)

Laboratory of Hematology, INSERM Unité Mixte de Recherche en Santé (UMR-S) 1172, Lille University Hospital, Lille, France.

Arnaud Petit (A)

Hopital Trousseau, Assistance Publique-Hopitaux de Paris, Paris, France.

Helene Lapillonne (H)

Hopital Trousseau, Assistance Publique-Hopitaux de Paris, Paris, France.

Alexandre Puissant (A)

INSERM U944, Saint-Louis Research Institute, University of Paris, Paris, France.

Raphael Itzykson (R)

INSERM U944, Saint-Louis Research Institute, University of Paris, Paris, France.

Richard Moriggl (R)

Institute for Animal Breeding and Genetics, University of Veterinary Medicine Vienna, Vienna, Austria.
Medical University of Vienna, Vienna, Austria.

Michael Heuser (M)

Department of Hematology, Hemostasis, Oncology and Stem Cell Transplantation, Hannover Medical School, Hannover, Germany.

Roland Meisel (R)

Division of Pediatric Stem Cell Therapy, Clinic for Pediatric Oncology, Hematology and Clinical Immunology, Medical Faculty, Heinrich Heine University, Düsseldorf, Germany.

Peter Valent (P)

Division of Hematology and Hemostaseology, Department of Internal Medicine I, and.
Ludwig Boltzmann Institute for Hematology and Oncology, Medical University of Vienna, Vienna, Austria.

Veronika Sexl (V)

Institute of Pharmacology and Toxicology, University of Veterinary Medicine Vienna, Vienna, Austria.

Johannes Zuber (J)

Research Institute of Molecular Pathology, Vienna BioCenter, Vienna, Austria.
Medical University of Vienna, Vienna, Austria.

Florian Grebien (F)

Institute for Medical Biochemistry, University of Veterinary Medicine Vienna, Vienna, Austria.

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Classifications MeSH