Late-onset argininosuccinic aciduria associated with hyperammonemia triggered by influenza infection in an adolescent: A case report.

ASA, argininosuccinic aciduria ASL, argininosuccinate lyase Adolescence Argininosuccinic acid lyase deficiency Argininosuccinic aciduria Hyperammonemia Influenza A Late-onset

Journal

Molecular genetics and metabolism reports
ISSN: 2214-4269
Titre abrégé: Mol Genet Metab Rep
Pays: United States
ID NLM: 101624422

Informations de publication

Date de publication:
Sep 2020
Historique:
received: 14 03 2020
revised: 05 05 2020
entrez: 22 5 2020
pubmed: 22 5 2020
medline: 22 5 2020
Statut: epublish

Résumé

Hyperammonemia is a typical symptom of urea cycle disorders. While early-onset argininosuccinic aciduria (ASA) can often be detected by hyperammonemia, patients with late-onset ASA predominantly present with psychomotor retardation and mental disorders. However, in late-onset ASA that develops during early childhood, hyperammonemia can sometimes be caused by acute infections, stress, and reduced dietary intake. Here, we report the case of a 14-year-old boy with late-onset ASA associated with hyperammonemia that was triggered by an influenza A infection. Due to the infection, he presented with a fever and was unable to eat food or take oral medication. He then experienced restlessness, a disturbance in his level of consciousness, and seizures. Hyperammonemia (3286 μg/dL, reference value ≤100 μg/dL) was detected. He was biochemically diagnosed with ASA based on increased serum and urinary argininosuccinic acid levels. Additionally, genetic testing revealed compound heterozygous mutations in the

Identifiants

pubmed: 32435591
doi: 10.1016/j.ymgmr.2020.100605
pii: S2214-4269(20)30051-3
pii: 100605
pmc: PMC7232106
doi:

Types de publication

Case Reports

Langues

eng

Pagination

100605

Informations de copyright

© 2020 The Authors.

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Auteurs

Yoshimitsu Osawa (Y)

Department of Pediatrics, Gunma University Graduate School of Medicine, Japan.
Department of Pediatrics, Shimane University Faculty of Medicine, Japan.

Aya Wada (A)

Department of Pediatrics, Gunma University Graduate School of Medicine, Japan.

Yoshiaki Ohtsu (Y)

Department of Pediatrics, Gunma University Graduate School of Medicine, Japan.

Kenji Yamada (K)

Department of Pediatrics, Shimane University Faculty of Medicine, Japan.

Takumi Takizawa (T)

Department of Pediatrics, Gunma University Graduate School of Medicine, Japan.

Classifications MeSH