Identification of novel compound heterozygous mutations of the

DYNC2H1 compound heterozygous mutations short-rib thoracic dysplasia 3 with or without polydactyly

Journal

Intractable & rare diseases research
ISSN: 2186-3644
Titre abrégé: Intractable Rare Dis Res
Pays: Japan
ID NLM: 101586847

Informations de publication

Date de publication:
May 2020
Historique:
entrez: 5 6 2020
pubmed: 5 6 2020
medline: 5 6 2020
Statut: ppublish

Résumé

A prenatal sonograph revealed a 26-week-old fetus with short limbs and a narrow chest in a 23-year-old woman with a history of fetal skeletal dysplasia. A single nucleotide polymorphism-based chromosomal microarray (CMA) indicated a normal karyotype, and no chromosomal segments with abnormal copy numbers were noted in the fetus. Whole exome sequencing identified compound heterozygous mutations in the

Identifiants

pubmed: 32494556
doi: 10.5582/irdr.2020.01031
pmc: PMC7263985
doi:

Types de publication

Journal Article

Langues

eng

Pagination

95-98

Informations de copyright

2020, International Research and Cooperation Association for Bio & Socio - Sciences Advancement.

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Auteurs

Kaiyue Geng (K)

School of Medicine and Life Sciences, University of Jinan-Shandong Academy of Medical Sciences, Ji'nan, Shandong, China.
Key Laboratory for Rare Disease Research of Shandong Province, Key Laboratory for Biotech Drugs of the Ministry of Health, Shandong Medical Biotechnological Center, Shandong Academy of Medical Sciences, Ji'nan, Shandong, China.

Kai Mu (K)

Zibo Maternal and Child Health Hospital, Zibo, Shandong, China.

Yan Zhao (Y)

Key Laboratory for Rare Disease Research of Shandong Province, Key Laboratory for Biotech Drugs of the Ministry of Health, Shandong Medical Biotechnological Center, Shandong Academy of Medical Sciences, Ji'nan, Shandong, China.

Jing Luan (J)

Key Laboratory for Rare Disease Research of Shandong Province, Key Laboratory for Biotech Drugs of the Ministry of Health, Shandong Medical Biotechnological Center, Shandong Academy of Medical Sciences, Ji'nan, Shandong, China.

Yazhou Cui (Y)

Key Laboratory for Rare Disease Research of Shandong Province, Key Laboratory for Biotech Drugs of the Ministry of Health, Shandong Medical Biotechnological Center, Shandong Academy of Medical Sciences, Ji'nan, Shandong, China.

Jinxiang Han (J)

Key Laboratory for Rare Disease Research of Shandong Province, Key Laboratory for Biotech Drugs of the Ministry of Health, Shandong Medical Biotechnological Center, Shandong Academy of Medical Sciences, Ji'nan, Shandong, China.

Classifications MeSH