Paediatric multisystem inflammatory syndrome temporally associated with SARS-CoV-2 mimicking Kawasaki disease (Kawa-COVID-19): a multicentre cohort.


Journal

Annals of the rheumatic diseases
ISSN: 1468-2060
Titre abrégé: Ann Rheum Dis
Pays: England
ID NLM: 0372355

Informations de publication

Date de publication:
08 2020
Historique:
received: 12 05 2020
revised: 27 05 2020
accepted: 02 06 2020
pubmed: 13 6 2020
medline: 23 7 2020
entrez: 13 6 2020
Statut: ppublish

Résumé

Current data suggest that COVID-19 is less frequent in children, with a milder course. However, over the past weeks, an increase in the number of children presenting to hospitals in the greater Paris region with a phenotype resembling Kawasaki disease (KD) has led to an alert by the French national health authorities. Multicentre compilation of patients with KD in Paris region since April 2020, associated with the detection of severe acute respiratory syndrome coronavirus 2 (SARS-CoV-2) ('Kawa-COVID-19'). A historical cohort of 'classical' KD served as a comparator. Sixteen patients were included (sex ratio=1, median age 10 years IQR (4·7 to 12.5)). SARS-CoV-2 was detected in 12 cases (69%), while a further three cases had documented recent contact with a quantitative PCR-positive individual (19%). Cardiac involvement included myocarditis in 44% (n=7). Factors prognostic for the development of severe disease (ie, requiring intensive care, n=7) were age over 5 years and ferritinaemia >1400 µg/L. Only five patients (31%) were successfully treated with a single intravenous immunoglobulin (IVIg) infusion, while 10 patients (62%) required a second line of treatment. The Kawa-COVID-19 cohort differed from a comparator group of 'classical' KD by older age at onset 10 vs 2 years (p<0.0001), lower platelet count (188 vs 383 G/L (p<0.0001)), a higher rate of myocarditis 7/16 vs 3/220 (p=0.0001) and resistance to first IVIg treatment 10/16 vs 45/220 (p=0.004). Kawa-COVID-19 likely represents a new systemic inflammatory syndrome temporally associated with SARS-CoV-2 infection in children. Further prospective international studies are necessary to confirm these findings and better understand the pathophysiology of Kawa-COVID-19.

Sections du résumé

BACKGROUND
Current data suggest that COVID-19 is less frequent in children, with a milder course. However, over the past weeks, an increase in the number of children presenting to hospitals in the greater Paris region with a phenotype resembling Kawasaki disease (KD) has led to an alert by the French national health authorities.
METHODS
Multicentre compilation of patients with KD in Paris region since April 2020, associated with the detection of severe acute respiratory syndrome coronavirus 2 (SARS-CoV-2) ('Kawa-COVID-19'). A historical cohort of 'classical' KD served as a comparator.
RESULTS
Sixteen patients were included (sex ratio=1, median age 10 years IQR (4·7 to 12.5)). SARS-CoV-2 was detected in 12 cases (69%), while a further three cases had documented recent contact with a quantitative PCR-positive individual (19%). Cardiac involvement included myocarditis in 44% (n=7). Factors prognostic for the development of severe disease (ie, requiring intensive care, n=7) were age over 5 years and ferritinaemia >1400 µg/L. Only five patients (31%) were successfully treated with a single intravenous immunoglobulin (IVIg) infusion, while 10 patients (62%) required a second line of treatment. The Kawa-COVID-19 cohort differed from a comparator group of 'classical' KD by older age at onset 10 vs 2 years (p<0.0001), lower platelet count (188 vs 383 G/L (p<0.0001)), a higher rate of myocarditis 7/16 vs 3/220 (p=0.0001) and resistance to first IVIg treatment 10/16 vs 45/220 (p=0.004).
CONCLUSION
Kawa-COVID-19 likely represents a new systemic inflammatory syndrome temporally associated with SARS-CoV-2 infection in children. Further prospective international studies are necessary to confirm these findings and better understand the pathophysiology of Kawa-COVID-19.

Identifiants

pubmed: 32527868
pii: annrheumdis-2020-217960
doi: 10.1136/annrheumdis-2020-217960
pmc: PMC7299653
doi:

Banques de données

ClinicalTrials.gov
['NCT02377245']

Types de publication

Journal Article Multicenter Study

Langues

eng

Sous-ensembles de citation

IM

Pagination

999-1006

Commentaires et corrections

Type : CommentIn
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Informations de copyright

© Author(s) (or their employer(s)) 2020. No commercial re-use. See rights and permissions. Published by BMJ.

Déclaration de conflit d'intérêts

Competing interests: None declared.

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Auteurs

Marie Pouletty (M)

General Paediatrics, Department of Infectious Disease and Internal Medicine, Reference centre for Rheumatic, AutoImmune and Systemic diseases in children (RAISE), Paris, France, Robert Debré University Hospital, AP-HP, Paris, France.
Université de Paris, UFR de Médecine Paris Nord, 75010 Paris, France.

Charlotte Borocco (C)

Department of Pediatric Rheumatology Reference centre for Autoinflammatory diseases and amyloidosis (CEREMAIA), Hôpital Bicêtre, AP-HP, Le Kremlin-Bicêtre, France.
Université Paris Sud-Saclay, UVSQ, 94276 Le Kremlin-Bicêtre, France.

Naim Ouldali (N)

General Paediatrics, Department of Infectious Disease and Internal Medicine, Reference centre for Rheumatic, AutoImmune and Systemic diseases in children (RAISE), Paris, France, Robert Debré University Hospital, AP-HP, Paris, France.
INSERM UMR 1123, ECEVE, Paris, France.

Marion Caseris (M)

General Paediatrics, Department of Infectious Disease and Internal Medicine, Reference centre for Rheumatic, AutoImmune and Systemic diseases in children (RAISE), Paris, France, Robert Debré University Hospital, AP-HP, Paris, France.
Department of Microbiology, Robert Debré University Hospital,AP-HP, Paris, France.

Romain Basmaci (R)

Departments of General Paediatrics and Paediatric Emergency, Louis-Mourier Hospital, AP-HP, Colombes, France.
Infection-Antimicrobials-Modelling-Evolution IAME, INSERM, UMR-1137, Université de Paris, 75018, Paris, France.

Noémie Lachaume (N)

Departments of General Paediatrics and Paediatric Emergency, Louis-Mourier Hospital, AP-HP, Colombes, France.
Infection-Antimicrobials-Modelling-Evolution IAME, INSERM, UMR-1137, Université de Paris, 75018, Paris, France.

Philippe Bensaid (P)

Department of General Paediatrics, Victor Dupouy Hospital, Argenteuil, France.

Samia Pichard (S)

Department of General Paediatrics, Victor Dupouy Hospital, Argenteuil, France.

Hanane Kouider (H)

Department of General Paediatrics, René Dubos, Pontoise Hospital, Pontoise, France.

Guillaume Morelle (G)

Department of General Paediatrics, Hôpital Bicêtre, AP-HP, Le Kremlin-Bicêtre, France.

Irina Craiu (I)

Paediatric emergency Department, Hôpital Bicêtre, AP-HP, Le Kremlin-Bicêtre, France.

Corinne Pondarre (C)

Sickle cell disease referal center, INSERM U955, Centre hospitalier Intercommunal de Créteil, Paris XII University, Créteil, France.

Anna Deho (A)

Paediatric Intensive Care Unit, Robert Debré University Hospital, AP-HP, Paris, France.

Arielle Maroni (A)

Paediatric Intensive Care Unit, Robert Debré University Hospital, AP-HP, Paris, France.

Mehdi Oualha (M)

Paediatric Intensive Care Unit, Necker-Enfants-Malades University Hospital, AP-HP, Paris, France.

Zahir Amoura (Z)

Inserm UMR-S 1135, Sorbonne Université, Paris, France.
Department of Immunology and Infectious disease (CIMI-Paris), Pitié-Salpêtrière Hospital, AP-HP, Paris, France.

Julien Haroche (J)

Inserm UMR-S 1135, Sorbonne Université, Paris, France.
Department of Immunology and Infectious disease (CIMI-Paris), Pitié-Salpêtrière Hospital, AP-HP, Paris, France.

Juliette Chommeloux (J)

Medical Intensive Care Unit, Institut de Cardiologie, AP-HP, Sorbonne University, Pitié-Salpêtrière Hospital, Paris, France.

Fanny Bajolle (F)

Cardiopaediatric Unit, M3-C, Necker-Enfants-Malades University Hospital, AP-HP, Paris, France.

Constance Beyler (C)

Cardiopaediatric Unit, Robert Debré University Hospital, AP-HP, Paris, France.

Stéphane Bonacorsi (S)

Department of Microbiology, Robert Debré University Hospital,AP-HP, Paris, France.
Infection-Antimicrobials-Modelling-Evolution IAME, INSERM, UMR-1137, Université de Paris, 75018, Paris, France.

Guislaine Carcelain (G)

Department of Immunology, Robert Debré University Hospital, AP-HP, Paris, France.

Isabelle Koné-Paut (I)

Department of Pediatric Rheumatology Reference centre for Autoinflammatory diseases and amyloidosis (CEREMAIA), Hôpital Bicêtre, AP-HP, Le Kremlin-Bicêtre, France.
Université Paris Sud-Saclay, UVSQ, 94276 Le Kremlin-Bicêtre, France.

Brigitte Bader-Meunier (B)

Paediatric Hematology-Immunology and Rheumatology Department, Reference centre for Rheumatic, AutoImmune and Systemic diseases in children (RAISE), Paris, France, Necker-Enfants-Malades University Hospital, AP-HP, Paris, France.
Laboratory of Immunogenetics of paediatric autoimmune diseases, INSERM UMR 1163, Paris, France.

Albert Faye (A)

General Paediatrics, Department of Infectious Disease and Internal Medicine, Reference centre for Rheumatic, AutoImmune and Systemic diseases in children (RAISE), Paris, France, Robert Debré University Hospital, AP-HP, Paris, France.
Université de Paris, UFR de Médecine Paris Nord, 75010 Paris, France.
INSERM UMR 1123, ECEVE, Paris, France.

Ulrich Meinzer (U)

General Paediatrics, Department of Infectious Disease and Internal Medicine, Reference centre for Rheumatic, AutoImmune and Systemic diseases in children (RAISE), Paris, France, Robert Debré University Hospital, AP-HP, Paris, France.
Université de Paris, UFR de Médecine Paris Nord, 75010 Paris, France.
Center for Research on Inflammation, INSERM, UMR1149, Paris, France.
Biology and Genetics of Bacterial Cell Wall Unit, Pasteur Institute, Paris, France.

Caroline Galeotti (C)

Department of Pediatric Rheumatology Reference centre for Autoinflammatory diseases and amyloidosis (CEREMAIA), Hôpital Bicêtre, AP-HP, Le Kremlin-Bicêtre, France.

Isabelle Melki (I)

General Paediatrics, Department of Infectious Disease and Internal Medicine, Reference centre for Rheumatic, AutoImmune and Systemic diseases in children (RAISE), Paris, France, Robert Debré University Hospital, AP-HP, Paris, France isabelle.melki@aphp.fr.
Paediatric Hematology-Immunology and Rheumatology Department, Reference centre for Rheumatic, AutoImmune and Systemic diseases in children (RAISE), Paris, France, Necker-Enfants-Malades University Hospital, AP-HP, Paris, France.
Laboratory of Neurogenetics and Neuroinflammation, Imagine Institute, Paris, France.

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