The sociability spectrum: evidence from reciprocal genetic copy number variations.
7dupASD
7q11.23
Autism spectrum disorders
Hypersociability
Sociability
William-Beuren syndrome
iPSCs
Journal
Molecular autism
ISSN: 2040-2392
Titre abrégé: Mol Autism
Pays: England
ID NLM: 101534222
Informations de publication
Date de publication:
16 06 2020
16 06 2020
Historique:
received:
07
02
2020
accepted:
11
05
2020
entrez:
18
6
2020
pubmed:
18
6
2020
medline:
4
8
2021
Statut:
epublish
Résumé
Sociability entails some of the most complex behaviors processed by the central nervous system. It includes the detection, integration, and interpretation of social cues and elaboration of context-specific responses that are quintessentially species-specific. There is an ever-growing accumulation of molecular associations to autism spectrum disorders (ASD), from causative genes to endophenotypes across multiple functional layers; these however, have rarely been put in context with the opposite manifestation featured in hypersociability syndromes. Genetic copy number variations (CNVs) allow to investigate the relationships between gene dosage and its corresponding phenotypes. In particular, CNVs of the 7q11.23 locus, which manifest diametrically opposite social behaviors, offer a privileged window to look into the molecular substrates underlying the developmental trajectories of the social brain. As by definition sociability is studied in humans postnatally, the developmental fluctuations causing social impairments have thus far remained a black box. Here, we review key evidence of molecular players involved at both ends of the sociability spectrum, focusing on genetic and functional associations of neuroendocrine regulators and synaptic transmission pathways. We then proceed to propose the existence of a molecular axis centered around the paradigmatic dosage imbalances at the 7q11.23 locus, regulating networks responsible for the development of social behavior in humans and highlight the key role that neurodevelopmental models from reprogrammed pluripotent cells will play for its understanding.
Identifiants
pubmed: 32546261
doi: 10.1186/s13229-020-00347-0
pii: 10.1186/s13229-020-00347-0
pmc: PMC7298749
doi:
Types de publication
Journal Article
Research Support, Non-U.S. Gov't
Review
Langues
eng
Sous-ensembles de citation
IM
Pagination
50Références
Neuron. 2014 Jul 2;83(1):27-49
pubmed: 24991953
Am J Med Genet A. 2017 May;173(5):1243-1250
pubmed: 28371242
Curr Opin Psychiatry. 2018 Mar;31(2):123-127
pubmed: 29206687
J Neurochem. 2011 Oct;119(2):324-31
pubmed: 21848811
Lancet Psychiatry. 2018 Apr;5(4):370-378
pubmed: 29352661
Am J Med Genet A. 2017 Jul;173(7):1782-1791
pubmed: 28475290
Nat Neurosci. 2013 Apr;16(4):456-63
pubmed: 23502535
Prog Neurobiol. 2008 Jan;84(1):1-24
pubmed: 18053631
Neuron. 2016 Jun 15;90(6):1312-1324
pubmed: 27238866
J Med Genet. 2003 Feb;40(2):87-95
pubmed: 12566516
Cogn Affect Behav Neurosci. 2017 Oct;17(5):1002-1017
pubmed: 28685402
Mol Psychiatry. 2008 Oct;13(10):980-8
pubmed: 17893705
Am J Med Genet C Semin Med Genet. 2010 May 15;154C(2):209-19
pubmed: 20425782
PLoS Genet. 2017 Jul 13;13(7):e1006886
pubmed: 28704368
PLoS One. 2018 Oct 26;13(10):e0206114
pubmed: 30365517
Neuron. 2012 Feb 9;73(3):553-66
pubmed: 22325206
Genet Med. 2013 Apr;15(4):282-9
pubmed: 23018752
J Hum Genet. 2009 Apr;54(4):193-8
pubmed: 19282872
Proc Natl Acad Sci U S A. 2015 Nov 10;112(45):14084-9
pubmed: 26504214
Neuroscience. 2016 May 3;321:24-41
pubmed: 26577932
BMC Med Genet. 2010 Apr 19;11:61
pubmed: 20403157
Prog Brain Res. 1983;60:101-14
pubmed: 6198686
Proc Natl Acad Sci U S A. 2005 Nov 1;102(44):16096-101
pubmed: 16249339
N Engl J Med. 2010 Jan 21;362(3):239-52
pubmed: 20089974
Neurosci Lett. 2007 Apr 24;417(1):6-9
pubmed: 17383819
Mol Psychiatry. 2019 Sep;24(9):1248-1257
pubmed: 31089192
Trends Cogn Sci. 2012 Apr;16(4):231-9
pubmed: 22425667
Nat Ecol Evol. 2018 Jun;2(6):956-961
pubmed: 29632349
Mol Psychiatry. 2006 May;11(5):488-94
pubmed: 16520824
Adv Exp Med Biol. 2012;739:187-205
pubmed: 22399403
J Hum Genet. 2004;49(8):440-444
pubmed: 15258833
Transl Psychiatry. 2016 Sep 27;6(9):e905
pubmed: 27676446
Int J Biomed Sci. 2008 Sep;4(3):161-70
pubmed: 23675084
Philos Trans R Soc Lond B Biol Sci. 2006 Dec 29;361(1476):2187-98
pubmed: 17118932
J Mol Evol. 2013 Feb;76(1-2):28-47
pubmed: 23229069
Physiol Rev. 2001 Apr;81(2):629-83
pubmed: 11274341
Mol Psychiatry. 2004 Oct;9(10):968-72
pubmed: 15098001
Res Dev Disabil. 2011 Jan-Feb;32(1):11-24
pubmed: 21036013
Front Psychiatry. 2013 Feb 25;4:4
pubmed: 23444313
J Neurosci. 2007 Apr 4;27(14):3663-76
pubmed: 17409230
Neurosci Biobehav Rev. 1995 Summer;19(2):303-14
pubmed: 7630584
Science. 2018 Nov 16;362(6416):
pubmed: 30309905
Psychoneuroendocrinology. 2017 Jun;80:131-136
pubmed: 28343138
Proc Biol Sci. 2008 Dec 22;275(1653):2851-8
pubmed: 18755678
N Engl J Med. 2008 Oct 16;359(16):1685-99
pubmed: 18784092
Clin Endocrinol (Oxf). 2016 Dec;85(6):979-987
pubmed: 27486141
Gene. 2013 Sep 25;527(2):529-36
pubmed: 23831514
Autism Res. 2017 Jan;10(1):25-41
pubmed: 27651096
Eur J Med Genet. 2009 Mar-Jun;52(2-3):108-15
pubmed: 19328872
J Med Genet. 2007 Feb;44(2):136-43
pubmed: 16971481
Neurosci Res. 2012 Aug;73(4):333-6
pubmed: 22698779
Mol Psychiatry. 2013 Jun;18(6):666-73
pubmed: 22688187
Comp Biochem Physiol C Comp Pharmacol Toxicol. 1988;91(1):251-7
pubmed: 2905227
Am J Med Genet A. 2013 Apr;161A(4):717-31
pubmed: 23495017
Prog Neuropsychopharmacol Biol Psychiatry. 2013 Aug 1;45:131-43
pubmed: 23628433
Am J Psychiatry. 2010 Dec;167(12):1508-17
pubmed: 20952458
Physiol Rev. 2009 Jan;89(1):309-80
pubmed: 19126760
Genes Brain Behav. 2019 Jan;18(1):e12525
pubmed: 30311398
Am J Hum Genet. 2003 Oct;73(4):886-97
pubmed: 13680528
Behav Brain Sci. 2008 Jun;31(3):241-61; discussion 261-320
pubmed: 18578904
Genet Couns. 2002;13(4):385-96
pubmed: 12558108
Autism Res. 2010 Apr;3(2):53-67
pubmed: 20437601
Proc Natl Acad Sci U S A. 2009 Apr 7;106(14):5743-8
pubmed: 19307592
Eur J Hum Genet. 2010 Jan;18(1):33-8
pubmed: 19568270
Hum Genet. 2011 Oct;130(4):517-28
pubmed: 21359847
Biol Psychiatry. 2018 Aug 15;84(4):304-315
pubmed: 29458998
Nat Genet. 2015 Feb;47(2):132-41
pubmed: 25501393
Neuropsychopharmacology. 2016 Aug;41(9):2215-23
pubmed: 26860202
Nat Commun. 2019 Oct 30;10(1):4928
pubmed: 31666522
Am J Hum Genet. 2008 Feb;82(2):477-88
pubmed: 18252227
Nat Genet. 2008 Mar;40(3):322-8
pubmed: 18278044
Science. 2019 Dec 20;366(6472):1486-1492
pubmed: 31857479
Biol Psychiatry. 2005 Jul 1;58(1):74-7
pubmed: 15992526
Front Hum Neurosci. 2014 Oct 08;8:789
pubmed: 25339888
Nature. 2011 Aug 31;478(7367):97-102
pubmed: 21881559
Front Pediatr. 2018 Jun 05;6:163
pubmed: 29922639
Mol Cell Probes. 2000 Jun;14(3):191-4
pubmed: 10860717
Biol Psychiatry. 2017 Feb 1;81(3):e19-e21
pubmed: 28024707
Annu Rev Psychol. 2017 Jan 3;68:155-186
pubmed: 27732802
J Autism Dev Disord. 2012 Jul;42(7):1459-69
pubmed: 22048961
Exp Neurol. 2017 Jul;293:137-143
pubmed: 28411125
Adv Anat Embryol Cell Biol. 2007;190:1-65
pubmed: 17432114
Am J Med Genet A. 2014 Sep;164A(9):2232-9
pubmed: 24980612
Front Mol Neurosci. 2019 Jan 04;11:476
pubmed: 30686997
Biol Psychiatry. 2020 Jan 15;87(2):139-149
pubmed: 31540669
Am J Med Genet A. 2015 Dec;167A(12):2936-44
pubmed: 26331980
Am J Med Genet A. 2004 Aug 1;128A(4):340-51
pubmed: 15264279
Front Neuroendocrinol. 1995 Jul;16(3):237-89
pubmed: 7556852
Curr Psychiatry Rep. 2000 Apr;2(2):170-5
pubmed: 11122951
Clin Pediatr (Phila). 1975 Oct;14(10):902-8
pubmed: 1175328
Genes Brain Behav. 2016 Jan;15(1):7-26
pubmed: 26403076
Nat Genet. 2012 Apr 29;44(6):639-41
pubmed: 22544363
Eur J Neurosci. 2011 May;33(9):1611-21
pubmed: 21410795
Science. 2003 Jan 3;299(5603):76
pubmed: 12511643
EMBO Mol Med. 2009 Apr;1(1):50-65
pubmed: 20049703
Downs Syndr Res Pract. 2002 Sep;8(2):43-52
pubmed: 12407968
J Med Genet. 2011 Nov;48(11):776-8
pubmed: 21969336
Dev Neurosci. 2017;39(5):355-360
pubmed: 28750400
J Neurochem. 2015 Aug;134(3):578-89
pubmed: 25913238
Mol Neuropsychiatry. 2015 Jul;1(2):116-123
pubmed: 26528485
Psychoneuroendocrinology. 2014 Jan;39:257-268
pubmed: 24209975
Mol Psychiatry. 2002;7(9):975-84
pubmed: 12399951
Hum Mol Genet. 2006 Oct 15;15 Spec No 2:R138-50
pubmed: 16987877
Curr Opin Genet Dev. 2013 Jun;23(3):240-8
pubmed: 23747035
Prog Neuropsychopharmacol Biol Psychiatry. 2018 Mar 2;82:187-194
pubmed: 29169997
Int J Lang Commun Disord. 2004 Jan-Mar;39(1):45-64
pubmed: 14660186
Neuropeptides. 2018 Dec;72:1-11
pubmed: 30287150
J Hum Genet. 2010 Mar;55(3):137-41
pubmed: 20094064
Br J Cancer. 2011 Apr 12;104(8):1349-55
pubmed: 21407215
Science. 1967 Jan 13;155(3759):217-9
pubmed: 6015530
J Med Genet. 2010 Mar;47(3):195-203
pubmed: 19755429
Nat Rev Genet. 2019 Jan;20(1):51-63
pubmed: 30390048
Nature. 2014 Nov 13;515(7526):216-21
pubmed: 25363768
Arch Dis Child. 1967 Jun;42(223):298-302
pubmed: 6025370
JCI Insight. 2018 Jun 21;3(12):
pubmed: 29925684
J Neurosci. 2011 Jun 29;31(26):9563-73
pubmed: 21715621
Elife. 2019 Feb 12;8:
pubmed: 30747104
Nat Rev Neurol. 2016 Oct;12(10):584-93
pubmed: 27615419
Nature. 2017 Mar 23;543(7646):507-512
pubmed: 28297715
Am J Med Genet A. 2005 Feb 1;132A(4):425-30
pubmed: 15633179
Am J Med Genet A. 2009 Mar;149A(3):302-14
pubmed: 19205026
Horm Behav. 2004 Dec;46(5):638-45
pubmed: 15555506
J Neurodev Disord. 2011 Sep;3(3):225-37
pubmed: 21858456
J Biol Chem. 2008 Jul 4;283(27):18841-51
pubmed: 18463095
Cleft Palate Craniofac J. 2011 Jan;48(1):109-16
pubmed: 20500075
Sci Adv. 2019 Dec 04;5(12):eaaw7908
pubmed: 31840056
Am J Ment Retard. 2006 Nov;111(6):442-6
pubmed: 17029501
Adv Exp Med Biol. 1995;395:615-27
pubmed: 8714026
Sci Am. 1993 Jun;268(6):100-6
pubmed: 8516669
Genes Brain Behav. 2019 Jan;18(1):e12512
pubmed: 30101538
Am J Med Genet A. 2008 Aug 15;146A(16):2041-52
pubmed: 18627066
Psychiatry Clin Neurosci. 2013 Sep;67(6):457-8
pubmed: 23992289
Am J Hum Genet. 2004 Dec;75(6):1117-23
pubmed: 15467983
J Med Genet. 1998 Nov;35(11):939-42
pubmed: 9832042
Nat Genet. 2007 Jan;39(1):25-7
pubmed: 17173049
Am J Med Genet B Neuropsychiatr Genet. 2005 May 5;135B(1):42-6
pubmed: 15768392
Int J Mol Sci. 2019 Mar 01;20(5):
pubmed: 30832249
Am J Hum Genet. 2003 Jul;73(1):131-51
pubmed: 12796854
Mol Brain. 2009 Jun 18;2:19
pubmed: 19538708
Genet Med. 2010 Oct;12(10):641-7
pubmed: 20808231
Mol Psychiatry. 2007 Apr;12(4):376-84
pubmed: 17179998
Nature. 2012 Apr 04;485(7397):237-41
pubmed: 22495306
Cleft Palate Craniofac J. 2013 May;50(3):347-50
pubmed: 23145914
Dialogues Clin Neurosci. 2013 Jun;15(2):135-46
pubmed: 24174888
Am J Hum Genet. 2005 Aug;77(2):265-79
pubmed: 15995945
Br J Psychiatry. 1998 Jan;172:85-9
pubmed: 9534839
Orphanet J Rare Dis. 2011 Jun 24;6:47
pubmed: 21702900
Proc Natl Acad Sci U S A. 2010 Aug 3;107(31):13936-41
pubmed: 20647384
PLoS One. 2012;7(7):e38786
pubmed: 22848344
Mol Psychiatry. 2002;7(5):503-7
pubmed: 12082568
Psychopharmacology (Berl). 2014 Mar;231(6):1079-88
pubmed: 23839283
Prog Neurobiol. 2009 Jun;88(2):127-51
pubmed: 19482229
Eur J Hum Genet. 2015 Jun;23(6):753-60
pubmed: 25138099
Mol Neurobiol. 2018 Jul;55(7):5658-5671
pubmed: 29027111
Behav Brain Res. 2018 Oct 15;352:35-45
pubmed: 28189758
Nat Genet. 2012 Apr 29;44(6):636-8
pubmed: 22544367
J Med Genet. 2010 May;47(5):312-20
pubmed: 19897463
J Clin Invest. 2000 Feb;105(4):413-8
pubmed: 10683369
Am J Ment Retard. 2002 May;107(3):194-200
pubmed: 11966332
Sci Adv. 2017 Jul 19;3(7):e1700398
pubmed: 28776031
Clin Genet. 2000 Feb;57(2):103-9
pubmed: 10735630