Integrated multiomics analysis of hepatoblastoma unravels its heterogeneity and provides novel druggable targets.

Cancer genomics Liver cancer Next-generation sequencing Paediatric cancer

Journal

NPJ precision oncology
ISSN: 2397-768X
Titre abrégé: NPJ Precis Oncol
Pays: England
ID NLM: 101708166

Informations de publication

Date de publication:
2020
Historique:
received: 06 01 2020
accepted: 01 06 2020
entrez: 14 7 2020
pubmed: 14 7 2020
medline: 14 7 2020
Statut: epublish

Résumé

Although hepatoblastoma is the most common pediatric liver cancer, its genetic heterogeneity and therapeutic targets are not well elucidated. Therefore, we conducted a multiomics analysis, including mutatome, DNA methylome, and transcriptome analyses, of 59 hepatoblastoma samples. Based on DNA methylation patterns, hepatoblastoma was classified into three clusters exhibiting remarkable correlation with clinical, histological, and genetic features. Cluster F was largely composed of cases with fetal histology and good outcomes, whereas clusters E1 and E2 corresponded primarily to embryonal/combined histology and poor outcomes. E1 and E2, albeit distinguishable by different patient age distributions, were genetically characterized by hypermethylation of the HNF4A/CEBPA-binding regions, fetal liver-like expression patterns, upregulation of the cell cycle pathway, and overexpression of

Identifiants

pubmed: 32656360
doi: 10.1038/s41698-020-0125-y
pii: 125
pmc: PMC7341754
doi:

Types de publication

Journal Article

Langues

eng

Pagination

20

Informations de copyright

© The Author(s) 2020.

Déclaration de conflit d'intérêts

Competing interestsThe authors declare no competing interests.

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Auteurs

Masahiro Sekiguchi (M)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Masafumi Seki (M)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Tomoko Kawai (T)

Department of Maternal-Fetal Biology, National Research Institute for Child Health and Development, Tokyo, Japan.

Kenichi Yoshida (K)

Department of Pathology and Tumor Biology, Graduate School of Medicine, Kyoto University, Kyoto, Japan.

Misa Yoshida (M)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Tomoya Isobe (T)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Noriko Hoshino (N)

Department of Pediatric Surgery, The University of Tokyo Hospital, Tokyo, Japan.

Ryota Shirai (R)

Children's Cancer Center, National Center for Child Health and Development, Tokyo, Japan.

Mio Tanaka (M)

Department of Pathology, Kanagawa Children's Medical Center, Kanagawa, Japan.

Ryota Souzaki (R)

Department of Pediatric Surgery, Faculty of Medical Sciences, Kyushu University, Fukuoka, Japan.

Kentaro Watanabe (K)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Yuki Arakawa (Y)

Department of Hematology/Oncology, Saitama Children's Medical Center, Saitama, Japan.

Yasuhito Nannya (Y)

Department of Pathology and Tumor Biology, Graduate School of Medicine, Kyoto University, Kyoto, Japan.

Hiromichi Suzuki (H)

Department of Pathology and Tumor Biology, Graduate School of Medicine, Kyoto University, Kyoto, Japan.

Yoichi Fujii (Y)

Department of Urology, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Keisuke Kataoka (K)

Division of Molecular Oncology, National Cancer Center Research Institute, Tokyo, Japan.

Yuichi Shiraishi (Y)

Center for Cancer Genomics and Advanced Therapeutics, National Cancer Center Research Institute, Tokyo, Japan.

Kenichi Chiba (K)

Center for Cancer Genomics and Advanced Therapeutics, National Cancer Center Research Institute, Tokyo, Japan.

Hiroko Tanaka (H)

Laboratory of DNA Information Analysis, Human Genome Center, The Institute of Medical Science, The University of Tokyo, Tokyo, Japan.

Teppei Shimamura (T)

Department of Systems Biology, Graduate School of Medicine, Nagoya University, Nagoya, Japan.

Yusuke Sato (Y)

Department of Urology, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Aiko Sato-Otsubo (A)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Shunsuke Kimura (S)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.
Department of Pediatrics, Graduate School of Biomedical Sciences, Hiroshima University, Hiroshima, Japan.

Yasuo Kubota (Y)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Mitsuteru Hiwatari (M)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Katsuyoshi Koh (K)

Department of Hematology/Oncology, Saitama Children's Medical Center, Saitama, Japan.

Yasuhide Hayashi (Y)

Jobu University, Gunma, Japan.

Yutaka Kanamori (Y)

Division of Surgery, Department of Surgical Specialties, National Center for Child Health and Development, Tokyo, Japan.

Mureo Kasahara (M)

Transplantation Center, National Center for Child Health and Development, Tokyo, Japan.

Kenichi Kohashi (K)

Department of Anatomic Pathology, Graduate School of Medical Sciences, Kyushu University, Fukuoka, Japan.

Motohiro Kato (M)

Children's Cancer Center, National Center for Child Health and Development, Tokyo, Japan.

Takako Yoshioka (T)

Department of Pathology, National Center for Child Health and Development, Tokyo, Japan.

Kimikazu Matsumoto (K)

Children's Cancer Center, National Center for Child Health and Development, Tokyo, Japan.

Akira Oka (A)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.

Tomoaki Taguchi (T)

Department of Pediatric Surgery, Faculty of Medical Sciences, Kyushu University, Fukuoka, Japan.

Masashi Sanada (M)

Department of Advanced Diagnosis, Clinical Research Center, Nagoya Medical Center, Nagoya, Japan.

Yukichi Tanaka (Y)

Department of Pathology, Kanagawa Children's Medical Center, Kanagawa, Japan.

Satoru Miyano (S)

Center for Cancer Genomics and Advanced Therapeutics, National Cancer Center Research Institute, Tokyo, Japan.

Kenichiro Hata (K)

Department of Maternal-Fetal Biology, National Research Institute for Child Health and Development, Tokyo, Japan.

Seishi Ogawa (S)

Department of Pathology and Tumor Biology, Graduate School of Medicine, Kyoto University, Kyoto, Japan.
Institute for the Advanced Study of Human Biology (WPI-ASHBi), Kyoto, Japan.
Department of Medicine, Center for Hematology and Regenerative Medicine, Karolinska Institute, Stockholm, Sweden.

Junko Takita (J)

Department of Pediatrics, Graduate School of Medicine, The University of Tokyo, Tokyo, Japan.
Department of Pediatrics, Graduate School of Medicine, Kyoto University, Kyoto, Japan.

Classifications MeSH