Successful fenofibrate therapy for severe and persistent hypertriglyceridemia in a boy with cirrhosis and glycerol-3-phosphate dehydrogenase 1 deficiency.

GPD1 gene Glycerol‐3‐phosphate dehydrogenase 1 deficiency fenofibrate hepatic steatosis hepatomegaly

Journal

JIMD reports
ISSN: 2192-8304
Titre abrégé: JIMD Rep
Pays: United States
ID NLM: 101568557

Informations de publication

Date de publication:
Jul 2020
Historique:
received: 27 02 2020
revised: 03 04 2020
accepted: 11 04 2020
entrez: 21 7 2020
pubmed: 21 7 2020
medline: 21 7 2020
Statut: epublish

Résumé

Glycerol-3-phosphate dehydrogenase 1 deficiency is a rare autosomal recessive disorder caused by mutations in the

Identifiants

pubmed: 32685347
doi: 10.1002/jmd2.12125
pii: JMD212125
pmc: PMC7358666
doi:

Types de publication

Case Reports

Langues

eng

Pagination

25-31

Informations de copyright

© 2020 The Authors. Journal of Inherited Metabolic Disease published by John Wiley & Sons Ltd on behalf of SSIEM.

Déclaration de conflit d'intérêts

L. M., V. R., C. M., A. L., D. C., G. B. V., G. L., A. S., and G. M. declare that they have no conflict of interest.

Références

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Auteurs

Lorenza Matarazzo (L)

Department of Medicine, Surgery, and Health Sciences University of Trieste Trieste Italy.

Valentina Ragnoni (V)

Section of Pediatrics, Department of Medical Sciences University of Ferrara Ferrara Italy.

Cristina Malaventura (C)

Section of Pediatrics, Department of Medical Sciences University of Ferrara Ferrara Italy.

Alberta Leon (A)

Research & Innovation Srl (R&I Genetics) Padova Italy.

Davide Colavito (D)

Research & Innovation Srl (R&I Genetics) Padova Italy.

Giovanni Battista Vigna (GB)

Medical Department University of Ferrara Ferrara Italy.

Giovanni Lanza (G)

Department of Medical Sciences, Pathology Unit University of Ferrara Ferrara Italy.

Aurelio Sonzogni (A)

Department of Pathology ASST Papa Giovanni XXIII Bergamo Italy.

Giuseppe Maggiore (G)

Section of Pediatrics, Department of Medical Sciences University of Ferrara Ferrara Italy.
Gastrointestinal, Liver and Nutrition Unit IRCCS Ospedale Pediatrico Bambino Gesù Rome Italy.

Classifications MeSH