A Novel

Crohn’s disease Smad7 inflammatory bowel disease single nucleotide polymorphisms ulcerative colitis

Journal

Biomedicines
ISSN: 2227-9059
Titre abrégé: Biomedicines
Pays: Switzerland
ID NLM: 101691304

Informations de publication

Date de publication:
22 Jul 2020
Historique:
received: 18 06 2020
revised: 16 07 2020
accepted: 20 07 2020
entrez: 26 7 2020
pubmed: 28 7 2020
medline: 28 7 2020
Statut: epublish

Résumé

Down-regulation of Smad7 with a specific Smad7 antisense (AS) oligonucleotide-containing oral drug (Mongersen) was effective in pre-clinical studies and initial clinical trials in Crohn's disease (CD) patients. A recent phase 3 trial was discontinued due to an apparent inefficacy of the drug, but factors contributing to the failure of this study remain unknown. Here, we analysed the frequency in CD of rs144204026 C/T single nucleotide polymorphism (SNP), which maps on the corresponding region targeted by the Smad7 AS contained in the Mongersen formulation and examined whether such a variant allele affects the ability of Smad7 AS to knockdown Smad7. rs144204026 SNP frequency was evaluated in two independent Italian cohorts of Crohn's disease patients and normal controls. Genotyping was performed by allelic discrimination assay. No TT genotype was seen in CD patients and controls. Heterozygous genotype was more frequent in CD patients of both cohort 1 (11/235, 4.68%) and cohort 2 (8/122, 6.56%) as compared to controls (6/363, 1.65%; This is the first study to show an association between

Sections du résumé

BACKGROUND BACKGROUND
Down-regulation of Smad7 with a specific Smad7 antisense (AS) oligonucleotide-containing oral drug (Mongersen) was effective in pre-clinical studies and initial clinical trials in Crohn's disease (CD) patients. A recent phase 3 trial was discontinued due to an apparent inefficacy of the drug, but factors contributing to the failure of this study remain unknown. Here, we analysed the frequency in CD of rs144204026 C/T single nucleotide polymorphism (SNP), which maps on the corresponding region targeted by the Smad7 AS contained in the Mongersen formulation and examined whether such a variant allele affects the ability of Smad7 AS to knockdown Smad7.
METHODS METHODS
rs144204026 SNP frequency was evaluated in two independent Italian cohorts of Crohn's disease patients and normal controls. Genotyping was performed by allelic discrimination assay.
RESULTS RESULTS
No TT genotype was seen in CD patients and controls. Heterozygous genotype was more frequent in CD patients of both cohort 1 (11/235, 4.68%) and cohort 2 (8/122, 6.56%) as compared to controls (6/363, 1.65%;
CONCLUSIONS CONCLUSIONS
This is the first study to show an association between

Identifiants

pubmed: 32707955
pii: biomedicines8080234
doi: 10.3390/biomedicines8080234
pmc: PMC7460430
pii:
doi:

Types de publication

Journal Article

Langues

eng

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Auteurs

Davide Di Fusco (D)

Department of Systems Medicine, University of Rome "Tor Vergata", 00133 Rome, Italy.

Irene Marafini (I)

Department of Systems Medicine, University of Rome "Tor Vergata", 00133 Rome, Italy.

Carmine Stolfi (C)

Department of Systems Medicine, University of Rome "Tor Vergata", 00133 Rome, Italy.

Edoardo Troncone (E)

Department of Systems Medicine, University of Rome "Tor Vergata", 00133 Rome, Italy.

Sara Onali (S)

Department of Biomedicine and Prevention, University of Rome "Tor Vergata", 00133 Rome, Italy.

Elisabetta Lolli (E)

Department of Systems Medicine, University of Rome "Tor Vergata", 00133 Rome, Italy.

Flavio Caprioli (F)

Gastroenterology and Endoscopy Unit, Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, 20122 Milan, Italy.
Department of Pathophysiology and Transplantation, Università degli Studi di Milano, 20122 Milan, Italy.

Stefano Mazza (S)

Gastroenterology and Endoscopy Unit, Fondazione IRCCS Ca' Granda Ospedale Maggiore Policlinico, 20122 Milan, Italy.
Department of Pathophysiology and Transplantation, Università degli Studi di Milano, 20122 Milan, Italy.

Cascella Raffaella (C)

Department of Biomedicine and Prevention, University of Rome "Tor Vergata", 00133 Rome, Italy.
Molecular Genetics Laboratory UILDM, Santa Lucia Foundation, 00179 Rome, Italy.

Laura Manzo (L)

Department of Biomedicine and Prevention, University of Rome "Tor Vergata", 00133 Rome, Italy.

Paola Borgiani (P)

Department of Biomedicine and Prevention, University of Rome "Tor Vergata", 00133 Rome, Italy.

Paolo Giuffrida (P)

Department of Internal Medicine, San Matteo Hospital Foundation, University of Pavia, 27100 Pavia, Italy.

Antonio Di Sabatino (A)

Department of Internal Medicine, San Matteo Hospital Foundation, University of Pavia, 27100 Pavia, Italy.

Ivan Monteleone (I)

Department of Biomedicine and Prevention, University of Rome "Tor Vergata", 00133 Rome, Italy.

Giovanni Monteleone (G)

Department of Systems Medicine, University of Rome "Tor Vergata", 00133 Rome, Italy.

Classifications MeSH