Adrenal Corticomedullary Mixed Tumor Associated With the

FGFR4-G388R variant adrenal gland corticomedullary mixed tumor

Journal

Journal of the Endocrine Society
ISSN: 2472-1972
Titre abrégé: J Endocr Soc
Pays: United States
ID NLM: 101697997

Informations de publication

Date de publication:
01 Sep 2020
Historique:
received: 28 04 2020
accepted: 16 07 2020
entrez: 18 8 2020
pubmed: 18 8 2020
medline: 18 8 2020
Statut: epublish

Résumé

Adrenal corticomedullary mixed tumors (CMMTs) are extremely rare; with only 20 cases being reported to date, the pathogenesis has remained elusive. A 31-year-old woman developed gestational hypertension with psychiatric disturbances persistent to postpartum and was diagnosed with pheochromocytoma, for which adrenalectomy was performed. Histological findings showed mixed adrenocortical adenoma and pheochromocytoma. Double immunostaining of inhibin and INSM1 (insulinoma-associated protein 1) showed that the 2 tumor components had distinct functional properties. Exome analysis of peripheral leukocytes and tumor (singular, as anatomically it is only 1 mass) revealed a homozygous germline

Identifiants

pubmed: 32803097
doi: 10.1210/jendso/bvaa101
pii: bvaa101
pmc: PMC7417000
doi:

Types de publication

Case Reports

Langues

eng

Pagination

bvaa101

Informations de copyright

© Endocrine Society 2020.

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Auteurs

Maki Kanzawa (M)

Department of Diagnostic Pathology, Kobe University Hospital, Kobe, Japan.

Hidenori Fukuoka (H)

Division of Diabetes and Endocrinology, Kobe University Hospital, Kobe, Japan.

Akane Yamamoto (A)

Division of Diabetes and Endocrinology, Kobe University Hospital, Kobe, Japan.

Kentaro Suda (K)

Division of Diabetes and Endocrinology, Kobe University Hospital, Kobe, Japan.

Katsumi Shigemura (K)

Division of Diabetes and Endocrinology, Kobe University Graduate School of Medicine, Kobe, Japan.

Shigeo Hara (S)

Division of Urology, Department of Surgery Related, Kobe University Graduate School of Medicine, Kobe, Japan.

Naoko Imagawa (N)

Department of Diagnostic Pathology, Kobe University Hospital, Kobe, Japan.

Ryuko Tsukamoto (R)

Department of Diagnostic Pathology, Kobe University Hospital, Kobe, Japan.

Yayoi Aoyama (Y)

Department of Diagnostic Pathology, Kobe City Medical Center General Hospital, Kobe, Japan.

Yasuhiro Nakamura (Y)

Department of Pathology, Tohoku University Hospital, Sendai, Japan.

Masato Fujisawa (M)

Division of Diabetes and Endocrinology, Kobe University Graduate School of Medicine, Kobe, Japan.

Wataru Ogawa (W)

Division of Pathology, Faculty of Medicine, Tohoku Medical and Pharmaceutical University, Sendai, Japan.

Yutaka Takahashi (Y)

Division of Pathology, Faculty of Medicine, Tohoku Medical and Pharmaceutical University, Sendai, Japan.

Tomoo Itoh (T)

Department of Diagnostic Pathology, Kobe University Hospital, Kobe, Japan.

Classifications MeSH