Reliability of the Charcot-Marie-Tooth functional outcome measure.


Journal

Journal of the peripheral nervous system : JPNS
ISSN: 1529-8027
Titre abrégé: J Peripher Nerv Syst
Pays: United States
ID NLM: 9704532

Informations de publication

Date de publication:
09 2020
Historique:
received: 30 06 2020
revised: 31 07 2020
accepted: 03 08 2020
pubmed: 28 8 2020
medline: 28 9 2021
entrez: 27 8 2020
Statut: ppublish

Résumé

The CMT-FOM is a 13-item clinical outcome assessment (COA) that measures physical ability in adults with Charcot-Marie-Tooth disease (CMT). Test-retest reliability, internal consistency and convergent validity have been established for the CMT-FOM. This current study sought to establish inter-rater reliability. Following an in-person training of six international clinical evaluators we recruited 10 participants with genetically diagnosed CMT1A, (aged 18-74 years, 6 female). Participants were evaluated using the CMT-FOM over 2 days. Participants were given at least a 3 hour rest between evaluations, and were assessed twice each day. Following the provision of training by master trainers, all 13 items of the CMT-FOM exhibited excellent inter-rater reliability for raw scores (ICC

Identifiants

pubmed: 32844461
doi: 10.1111/jns.12406
pmc: PMC7520097
mid: NIHMS1630654
doi:

Types de publication

Journal Article Multicenter Study Research Support, N.I.H., Extramural

Langues

eng

Sous-ensembles de citation

IM

Pagination

288-291

Subventions

Organisme : NINDS NIH HHS
ID : U01 NS109403
Pays : United States
Organisme : NINDS NIH HHS
ID : U54 NS065712
Pays : United States

Informations de copyright

© 2020 Peripheral Nerve Society.

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Auteurs

Paula Bray (P)

University of Sydney, School of Health Sciences & The Children's Hospital at Westmead, Sydney, Australia.

Kayla M D Cornett (KMD)

University of Sydney, School of Health Sciences & The Children's Hospital at Westmead, Sydney, Australia.

Timothy Estilow (T)

Department of Occupational Therapy, The Children's Hospital of Philadelphia, Philadelphia, Pennsylvania, USA.
Department of Neurology, Hospital of the University of Pennsylvania, Philadelphia, Pennsylvania, USA.

Davide Pareyson (D)

Fondazione IRCCS, Istituto Neurologico Carlo Besta, Milan, Italy.

Riccardo Zuccarino (R)

Department of Neurology, University of Iowa, Carver College of Medicine, Iowa City, Iowa, USA.
Neuromuscular Omnicentre (NEMO)-Fondazione Serena Onlus, Genoa, Italy.

Mariola Skorupinska (M)

MRC Centre for Neuromuscular Diseases, UCL Queen Square Institute of Neurology, London, UK.

Menelaos Pipis (M)

MRC Centre for Neuromuscular Diseases, UCL Queen Square Institute of Neurology, London, UK.

Janet E Sowden (JE)

Department of Neurology, University of Rochester, Rochester, New York, USA.

Steven Scherer (S)

Department of Neurology, Hospital of the University of Pennsylvania, Philadelphia, Pennsylvania, USA.

Mary M Reilly (MM)

MRC Centre for Neuromuscular Diseases, UCL Queen Square Institute of Neurology, London, UK.

Michael E Shy (ME)

Department of Neurology, University of Iowa, Carver College of Medicine, Iowa City, Iowa, USA.

David N Herrmann (DN)

Department of Neurology, University of Rochester, Rochester, New York, USA.

Joshua Burns (J)

University of Sydney, School of Health Sciences & The Children's Hospital at Westmead, Sydney, Australia.

Katy J Eichinger (KJ)

Department of Neurology, University of Rochester, Rochester, New York, USA.

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Classifications MeSH