Peripersonal Visuospatial Abilities in Williams Syndrome Analyzed by a Table Radial Arm Maze Task.

children ecological behavioral task navigation abilities spatial exploration spatial memory

Journal

Frontiers in human neuroscience
ISSN: 1662-5161
Titre abrégé: Front Hum Neurosci
Pays: Switzerland
ID NLM: 101477954

Informations de publication

Date de publication:
2020
Historique:
received: 26 02 2020
accepted: 09 06 2020
entrez: 28 8 2020
pubmed: 28 8 2020
medline: 28 8 2020
Statut: epublish

Résumé

Williams syndrome (WS) is a genetic deletion syndrome characterized by severe visuospatial deficits affecting spatial exploration and navigation abilities in extra-personal space.To date, little is known about spatial elaboration and reaching abilities in the peripersonal space in individuals with WS. The present study is aimed at evaluating the visuospatial abilities in individuals with WS and comparing their performances with those of mental age-matched typically developing (TD) children by using a highly sensitive ecological version of the Radial Arm Maze (table RAM). We evaluated 15 individuals with WS and 15 TD children in two different table RAM paradigms: the free-choice paradigm, mainly to analyze the aspects linked to procedural and memory components, and the forced-choice paradigm, to disentangle the components linked to spatial working memory from the procedural ones.Data show that individuals with WS made significantly more working memory errors as compared with TD children, thus evidencing a marked deficit in resolving the task when the mnesic load increased. Our findings provide new insights on the cognitive profile of WS.

Identifiants

pubmed: 32848661
doi: 10.3389/fnhum.2020.00254
pmc: PMC7396499
doi:

Types de publication

Journal Article

Langues

eng

Pagination

254

Informations de copyright

Copyright © 2020 Foti, Sorrentino, Menghini, Montuori, Pesoli, Turriziani, Vicari, Petrosini and Mandolesi.

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Auteurs

Francesca Foti (F)

Department of Medical and Surgical Sciences, Magna Graecia University of Catanzaro, Catanzaro, Italy.

Pierpaolo Sorrentino (P)

Department of Engineering, Parthenope University of Naples, Naples, Italy.

Deny Menghini (D)

Child Neuropsychiatry Unit, Neuroscience Department, "Children's Hospital Bambino Gesù", Rome, Italy.

Simone Montuori (S)

Department of Movement Sciences and Wellbeing, Parthenope University of Naples, Naples, Italy.

Matteo Pesoli (M)

Department of Movement Sciences and Wellbeing, Parthenope University of Naples, Naples, Italy.

Patrizia Turriziani (P)

Department of Psychology, Educational Sciences and Human Movement, University of Palermo, Palermo, Italy.

Stefano Vicari (S)

Child and Adolescent Neuropsychiatry Unit, Department of Neuroscience, Bambino Gesù Children's Hospital (IRCCS), Rome, Italy.
Department of Life Sciences and Public Health, Catholic University, Rome, Italy.

Laura Petrosini (L)

Laboratory of Experimental and Behavioural Neurophysiology, IRCCS Fondazione Santa Lucia, Rome, Italy.

Laura Mandolesi (L)

Department of Humanistic Studies, University of Naples Federico II, Naples, Italy.

Classifications MeSH