Acute Myocarditis-Like Episode in a Curly-Haired Young Boy-Red Flags for Familial Arrhythmogenic Cardiomyopathy.

arrhythmogenic cardiomyopathy cardiocutaneous syndrome cardiovascular magnetic resonance desmoplakin myocarditis sudden cardiac death

Journal

Diagnostics (Basel, Switzerland)
ISSN: 2075-4418
Titre abrégé: Diagnostics (Basel)
Pays: Switzerland
ID NLM: 101658402

Informations de publication

Date de publication:
31 Aug 2020
Historique:
received: 30 07 2020
revised: 26 08 2020
accepted: 26 08 2020
entrez: 4 9 2020
pubmed: 4 9 2020
medline: 4 9 2020
Statut: epublish

Résumé

The present case report describes a mother and son with arrhythmogenic cardiomyopathy (ACM) with early and greater left ventricle (LV) involvement. The presence of curly hair in both, together with the resuscitated sudden cardiac death of the mother, allowed timely genetic testing, which found a pathogenic nonsense mutation of the desmoplakin gene. While asymptomatic from an arrhythmic point of view, the son's evolution was characterized by a well-documented exercise-induced myocarditis-like stage.

Identifiants

pubmed: 32878047
pii: diagnostics10090651
doi: 10.3390/diagnostics10090651
pmc: PMC7555819
pii:
doi:

Types de publication

Case Reports

Langues

eng

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Auteurs

Alina Elena Pătru (AE)

Expert Center for Genetic Cardiovascular Diseases, Emergency Institute for Cardiovascular Diseases, Sos. Fundeni nr. 258, 022328 Bucharest, Romania.

Sebastian Onciul (S)

Department 4-Cardiothoracic Pathology, University of Medicine and Pharmacy Carol Davila, Eroii Sanitari Bvd. 8, 050474 Bucharest, Romania.
Department of Cardiology, Emergency Clinical Hospital Floreasca, Calea Floreasca nr 8, 014461 Bucharest, Romania.
Emerald Medical Center, Nicolae G. Caramfil, no 75, 077190 Bucharest, Romania.

Adrian Sturzu (A)

Expert Center for Genetic Cardiovascular Diseases, Emergency Institute for Cardiovascular Diseases, Sos. Fundeni nr. 258, 022328 Bucharest, Romania.
Department 4-Cardiothoracic Pathology, University of Medicine and Pharmacy Carol Davila, Eroii Sanitari Bvd. 8, 050474 Bucharest, Romania.

Eliza Cinteză (E)

Department 4-Cardiothoracic Pathology, University of Medicine and Pharmacy Carol Davila, Eroii Sanitari Bvd. 8, 050474 Bucharest, Romania.
Department of Pediatric Cardiology, Emergency Clinical Children's Hospital "Marie S. Curie", Bd. Constantin Brâncoveanu 20, 077120 Bucharest, Romania.

Eleonora Gima (E)

Department of Cardiology, University County Clinical Hospital, Bd. Tomis 145, 900591 Constanta, Romania.

Bogdan A Popescu (BA)

Expert Center for Genetic Cardiovascular Diseases, Emergency Institute for Cardiovascular Diseases, Sos. Fundeni nr. 258, 022328 Bucharest, Romania.
Department 4-Cardiothoracic Pathology, University of Medicine and Pharmacy Carol Davila, Eroii Sanitari Bvd. 8, 050474 Bucharest, Romania.

Philippe Chevalier (P)

Department of Rhythmology, Hospices Civils de Lyon, Louis Pradel Cardiovascular Hospital, 26 Avenue du Doyen Jean Lépine, 69500 Lyon, France.
Lyon Reference Center for Inherited Arrhythmias, Louis Pradel Cardiovascular Hospital, Université de Lyon, 28 avenue Doyen Lépine, 69500 Lyon, France.

Ruxandra Jurcuț (R)

Expert Center for Genetic Cardiovascular Diseases, Emergency Institute for Cardiovascular Diseases, Sos. Fundeni nr. 258, 022328 Bucharest, Romania.
Department 4-Cardiothoracic Pathology, University of Medicine and Pharmacy Carol Davila, Eroii Sanitari Bvd. 8, 050474 Bucharest, Romania.

Classifications MeSH