Brain Plasticity in Charcot-Marie-Tooth Type 1A Patients? A Combined Structural and Diffusion MRI Study.

Charcot-Marie-Tooth disease cerebellum diffusion magnetic resonance imaging electrophysiology peripheral nervous system diseases structural magnetic resonance imaging

Journal

Frontiers in neurology
ISSN: 1664-2295
Titre abrégé: Front Neurol
Pays: Switzerland
ID NLM: 101546899

Informations de publication

Date de publication:
2020
Historique:
received: 09 04 2020
accepted: 25 06 2020
entrez: 5 10 2020
pubmed: 6 10 2020
medline: 6 10 2020
Statut: epublish

Résumé

Central nervous system involvement has been described in peripheral neuropathies, including different forms of Charcot-Marie-Tooth (CMT) disease. The aim of our study was to systematically investigate possible brain structural modifications in CMT1A patients, using volumetric MRI, and diffusion tensor imaging (DTI). In this prospective cross-sectional study, from May 2017 to May 2019, we acquired 3T MRI brain scans of genetically confirmed CMT1A patients and age- and sex-comparable healthy controls. Patients also underwent clinical and electrophysiological examinations assessing motor and sensory domains. Voxel-based morphometry (VBM) and tract-based spatial statistics (TBSS) analyses were performed using a non-parametric approach based on permutations, including age and sex (and total intracranial volume for VBM) as nuisance covariates. When between-group differences emerged at VBM or TBSS analyses, the first eigenvariate was extracted from the cluster and its age- and sex-adjusted standardized residuals tested for correlation with clinical and electrophysiological variables. Twenty CMT1A patients (34.5 ± 11.1 years; M/F:11/9) were enrolled, along with 20 healthy controls (30.1 ± 10.2 years; M/F:11/9). The VBM analysis revealed clusters of significantly increased GM volume in CMT1A patients compared to healthy controls, encompassing the bilateral cerebellar lobules III-VI and the left hippocampus (all

Identifiants

pubmed: 33013613
doi: 10.3389/fneur.2020.00795
pmc: PMC7506188
doi:

Types de publication

Journal Article

Langues

eng

Pagination

795

Informations de copyright

Copyright © 2020 Pontillo, Dubbioso, Cocozza, Tozza, Severi, Iodice, Tedeschi, Elefante, Brunetti, Manganelli and Quarantelli.

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Auteurs

Giuseppe Pontillo (G)

Department of Advanced Biomedical Sciences, University Federico II, Naples, Italy.

Raffaele Dubbioso (R)

Department of Neurosciences, Reproductive and Odontostomatological Sciences, University Federico II, Naples, Italy.

Sirio Cocozza (S)

Department of Advanced Biomedical Sciences, University Federico II, Naples, Italy.

Stefano Tozza (S)

Department of Neurosciences, Reproductive and Odontostomatological Sciences, University Federico II, Naples, Italy.

Daniele Severi (D)

Department of Neurosciences, Reproductive and Odontostomatological Sciences, University Federico II, Naples, Italy.

Rosa Iodice (R)

Department of Neurosciences, Reproductive and Odontostomatological Sciences, University Federico II, Naples, Italy.

Enrico Tedeschi (E)

Department of Advanced Biomedical Sciences, University Federico II, Naples, Italy.

Andrea Elefante (A)

Department of Advanced Biomedical Sciences, University Federico II, Naples, Italy.

Arturo Brunetti (A)

Department of Advanced Biomedical Sciences, University Federico II, Naples, Italy.

Fiore Manganelli (F)

Department of Neurosciences, Reproductive and Odontostomatological Sciences, University Federico II, Naples, Italy.

Mario Quarantelli (M)

Institute of Biostructure and Bioimaging, National Research Council, Naples, Italy.

Classifications MeSH