Multiple neoplasia in a patient with Gitelman syndrome harboring germline monoallelic

Cancer genetics Genetics research

Journal

NPJ genomic medicine
ISSN: 2056-7944
Titre abrégé: NPJ Genom Med
Pays: England
ID NLM: 101685193

Informations de publication

Date de publication:
2020
Historique:
received: 31 01 2020
accepted: 19 08 2020
entrez: 7 10 2020
pubmed: 8 10 2020
medline: 8 10 2020
Statut: epublish

Résumé

Gitelman syndrome is a rare, recessively inherited disease characterized by chronic hypokalemia and hypomagnesemia as a result of defective electrolyte co-transport at the level of the distal convoluted tubule of the kidney. Here, we present the first report of a patient with Gitelman syndrome who developed multiple neoplasia including colorectal polyposis, synchronous colorectal cancers, recurrent breast fibroadenomata and a desmoid tumor. Whole-exome sequencing confirmed germline compound heterozygous mutations of c.179C > T and c.1326C > G in

Identifiants

pubmed: 33024574
doi: 10.1038/s41525-020-00146-9
pii: 10.1038/s41525-020-00146-9
pmc: PMC7501863
doi:

Types de publication

Journal Article

Langues

eng

Pagination

39

Informations de copyright

© The Author(s) 2020.

Déclaration de conflit d'intérêts

Competing interestsThe authors declare no competing interests.

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Auteurs

Jason Yongsheng Chan (JY)

Division of Medical Oncology, National Cancer Centre Singapore, Singapore, Singapore.
SingHealth Duke-NUS Blood Cancer Centre, Singapore, Singapore.
Cancer Science Institute of Singapore, National University of Singapore, Singapore, Singapore.

Ming Ren Toh (MR)

Cancer Genetics Service, Division of Medical Oncology, National Cancer Centre Singapore, Singapore, Singapore.

Siao Ting Chong (ST)

Cancer Genetics Service, Division of Medical Oncology, National Cancer Centre Singapore, Singapore, Singapore.

Nur Diana Binte Ishak (NDB)

Cancer Genetics Service, Division of Medical Oncology, National Cancer Centre Singapore, Singapore, Singapore.

Arun Mouli Kolinjivadi (AM)

Lee Kong Chian School of Medicine, Nanyang Technological University, Singapore, Singapore.

Sock Hoai Chan (SH)

Cancer Genetics Service, Division of Medical Oncology, National Cancer Centre Singapore, Singapore, Singapore.

Elizabeth Lee (E)

Division of Medical Oncology, National Cancer Centre Singapore, Singapore, Singapore.

Arnoud Boot (A)

Centre for Computational Biology, Duke-NUS Medical School, Singapore, Singapore.
Programme in Cancer and Stem Cell Biology, Duke-NUS Medical School, Singapore, Singapore.

Li Shao-Tzu (L)

Cancer Genetics Service, Division of Medical Oncology, National Cancer Centre Singapore, Singapore, Singapore.

Min-Hoe Chew (MH)

Department of General Surgery, Sengkang Health, Singapore, Singapore.

Joanne Ngeow (J)

Cancer Genetics Service, Division of Medical Oncology, National Cancer Centre Singapore, Singapore, Singapore.
Lee Kong Chian School of Medicine, Nanyang Technological University, Singapore, Singapore.
NUS Graduate School for Integrative Sciences and Engineering, Singapore, Singapore.
Oncology Academic Clinical Program, Duke-NUS Medical School, Singapore, Singapore.
Institute of Molecular and Cellular Biology, ASTAR, Singapore, Singapore.

Classifications MeSH