Cutaneous Adnexal Carcinoma with Apocrine Differentiation: A Challenging Diagnosis and Personalized Treatment with mTOR Inhibitor in a Very Rare Disease.

Cutaneous adnexal carcinoma Everolimus Next-generation sequencing test PI3KCA mutation

Journal

Case reports in oncology
ISSN: 1662-6575
Titre abrégé: Case Rep Oncol
Pays: Switzerland
ID NLM: 101517601

Informations de publication

Date de publication:
Historique:
received: 12 07 2020
accepted: 13 07 2020
entrez: 21 10 2020
pubmed: 22 10 2020
medline: 22 10 2020
Statut: epublish

Résumé

Cutaneous adnexal carcinoma with apocrine differentiation is a rare neoplasm arising from cutaneous adnexa, especially of the head and neck and trunk region. Because of its rarity, the diagnosis is challenging and often impossible to distinguish from metastatic cutaneous adenocarcinoma of the breast. The standard of care remains surgery for resectable disease. To date, univocal guidelines for metastatic disease are lacking, particularly regarding systemic therapy. We report a clinical case of a patient diagnosed with cutaneous adnexal adenocarcinoma with apocrine differentiation of the left axilla with lymph node and bone metastasis. We started with carboplatin and paclitaxel chemotherapy regimen, with good response. After progression, we performed a next-generation sequencing analysis (by the Foundation One CDx test) to identify genomic alteration in cancer-related genes. We found PIK3CA and KRAS mutations. Due to this result, the patient started a second-line treatment with a personalized therapy including an mTOR inhibitor, everolimus, and, to date, he is still under treatment. To our knowledge, this is the first case of a patient responding both to chemotherapy and to a personalized treatment with an mTOR inhibitor. It is important to support the value of genomic screening in this rare neoplasm.

Identifiants

pubmed: 33082753
doi: 10.1159/000510097
pii: cro-0013-1091
pmc: PMC7548910
doi:

Types de publication

Case Reports

Langues

eng

Pagination

1091-1096

Informations de copyright

Copyright © 2020 by S. Karger AG, Basel.

Déclaration de conflit d'intérêts

The authors declare no conflicts of interest.

Références

Nat Rev Cancer. 2003 Jan;3(1):11-22
pubmed: 12509763
J Dermatol. 2019 Jun;46(6):507-514
pubmed: 31038235
Acta Dermatovenerol Alp Pannonica Adriat. 2009 Sep;18(3):141-2
pubmed: 19784530
J Surg Oncol. 2012 Mar 15;105(4):415-9
pubmed: 21913192
Cancer. 1987 Jul 15;60(2):170-2
pubmed: 3594354
J Clin Oncol. 2010 Aug 20;28(24):e412-4
pubmed: 20406935
Head Neck. 2017 May;39(5):E69-E71
pubmed: 28225558
Am J Clin Oncol. 1999 Apr;22(2):131-5
pubmed: 10199445
JAMA Dermatol. 2016 Jan;152(1):111-3
pubmed: 26375389
J Immunother Cancer. 2018 Jun 19;6(1):58
pubmed: 29914578
Cancer. 2010 Sep 15;116(18):4256-65
pubmed: 20549832
Nature. 2016 Jun 30;534(7609):647-51
pubmed: 27338794
N Engl J Med. 2012 Feb 9;366(6):520-9
pubmed: 22149876
Curr Opin Cell Biol. 2010 Apr;22(2):169-76
pubmed: 19945836
J Clin Pathol. 2015 Dec;68(12):992-1002
pubmed: 26602416
Acta Derm Venereol. 2012 Nov;92(6):654-5
pubmed: 22504780
J Eur Acad Dermatol Venereol. 2010 Feb;24(2):199-203
pubmed: 19522717
Am J Clin Pathol. 2002 Dec;118 Suppl:S33-49
pubmed: 14569812

Auteurs

Michela Libertini (M)

Clinical Oncology Department, Fondazione Poliambulanza, Brescia, Italy.

Ester Oneda (E)

Clinical Oncology Department, Fondazione Poliambulanza, Brescia, Italy.

Brunella Di Biasi (B)

Clinical Oncology Department, Fondazione Poliambulanza, Brescia, Italy.

Giordano Savelli (G)

Nuclear Medicine Department, Fondazione Poliambulanza, Brescia, Italy.

Alberto Zaniboni (A)

Clinical Oncology Department, Fondazione Poliambulanza, Brescia, Italy.

Classifications MeSH