Bcor deficiency perturbs erythro-megakaryopoiesis and cooperates with Dnmt3a loss in acute erythroid leukemia onset in mice.


Journal

Leukemia
ISSN: 1476-5551
Titre abrégé: Leukemia
Pays: England
ID NLM: 8704895

Informations de publication

Date de publication:
07 2021
Historique:
received: 16 06 2020
accepted: 20 10 2020
revised: 19 08 2020
pubmed: 8 11 2020
medline: 17 8 2021
entrez: 7 11 2020
Statut: ppublish

Résumé

Recurrent loss-of-function mutations of BCL6 co-repressor (BCOR) gene are found in about 4% of AML patients with normal karyotype and are associated with DNMT3a mutations and poor prognosis. Therefore, new anti-leukemia treatments and mouse models are needed for this combinatorial AML genotype. For this purpose, we first generated a Bcor

Identifiants

pubmed: 33159179
doi: 10.1038/s41375-020-01075-3
pii: 10.1038/s41375-020-01075-3
pmc: PMC8257496
doi:

Substances chimiques

Bcor protein, mouse 0
Dnmt3a protein, mouse 0
Repressor Proteins 0
DNA (Cytosine-5-)-Methyltransferases EC 2.1.1.37
DNA Methyltransferase 3A EC 2.1.1.37

Types de publication

Journal Article Research Support, N.I.H., Extramural Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Pagination

1949-1963

Subventions

Organisme : NIDDK NIH HHS
ID : R56 DK092883
Pays : United States
Organisme : NIA NIH HHS
ID : P01 AG036695
Pays : United States
Organisme : NCI NIH HHS
ID : P30 CA125123
Pays : United States
Organisme : NCI NIH HHS
ID : R01 CA183252
Pays : United States
Organisme : NIDDK NIH HHS
ID : R01 DK092883
Pays : United States
Organisme : Howard Hughes Medical Institute
Pays : United States

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Auteurs

Paolo Sportoletti (P)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy. paolo.sportoletti@unipg.it.

Daniele Sorcini (D)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Anna G Guzman (AG)

Stem Cell and Regenerative Medicine, Baylor College of Medicine, Houston, TX, 77030, USA.
Center for Cell and Gene Therapy, Texas Children's Hospital and Houston Methodist Hospital, Baylor College of Medicine, Houston, TX, 77030, USA.

Jaime M Reyes (JM)

Stem Cell and Regenerative Medicine, Baylor College of Medicine, Houston, TX, 77030, USA.
Center for Cell and Gene Therapy, Texas Children's Hospital and Houston Methodist Hospital, Baylor College of Medicine, Houston, TX, 77030, USA.

Arianna Stella (A)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Andrea Marra (A)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Sara Sartori (S)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Lorenzo Brunetti (L)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Roberta Rossi (R)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Beatrice Del Papa (BD)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Francesco Maria Adamo (FM)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Giulia Pianigiani (G)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Camilla Betti (C)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Annarita Scialdone (A)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Valerio Guarente (V)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Giulio Spinozzi (G)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Valentina Tini (V)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Maria Paola Martelli (MP)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy.

Margaret A Goodell (MA)

Stem Cell and Regenerative Medicine, Baylor College of Medicine, Houston, TX, 77030, USA.
Center for Cell and Gene Therapy, Texas Children's Hospital and Houston Methodist Hospital, Baylor College of Medicine, Houston, TX, 77030, USA.

Brunangelo Falini (B)

Centro di Ricerca Emato-Oncologica (CREO), University of Perugia, Perugia, 06132, Italy. brunangelo.falini@unipg.it.

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