Zinsser-Engman-Cole Syndrome Presenting as Partial Limbal Stem Cell Deficiency.

dyskeratosis congenita limbal stem cell deficiency telomere

Journal

Cureus
ISSN: 2168-8184
Titre abrégé: Cureus
Pays: United States
ID NLM: 101596737

Informations de publication

Date de publication:
13 Oct 2020
Historique:
entrez: 16 11 2020
pubmed: 17 11 2020
medline: 17 11 2020
Statut: epublish

Résumé

To report a case of partial limbal stem cell deficiency and characteristic mucocutaneous triad in an 11-year-old boy. Systemic features along with ocular features are described in this case report. Ophthalmic evaluation showed bilateral partial limbal stem cell deficiency (LSCD) and systemic examination revealed characteristic mucocutaneous triad of oral leukoplakia, skin hypopigmentation, and nail dystrophy suggestive of the Zinsser-Engman-Cole syndrome or dyskeratosis congenita. Thorough ocular and systemic evaluation can help in clinching the diagnosis of this rare condition. Timely referral to a dermatologist and hemato-oncologist would help in the management of life-threatening complications like malignancy or progressive bone marrow failure.

Identifiants

pubmed: 33194499
doi: 10.7759/cureus.10933
pmc: PMC7660125
doi:

Types de publication

Case Reports

Langues

eng

Pagination

e10933

Informations de copyright

Copyright © 2020, Srirampur et al.

Déclaration de conflit d'intérêts

The authors have declared that no competing interests exist.

Références

Int Ophthalmol. 2012 Dec;32(6):615-22
pubmed: 22814958
Ophthalmology. 1998 Jul;105(7):1286-91
pubmed: 9663235
Ophthalmology. 2017 Aug;124(8):1246
pubmed: 28734336
Curr Mol Med. 2005 Mar;5(2):159-70
pubmed: 15974869
Pediatr Blood Cancer. 2009 Jul;53(1):95-7
pubmed: 19199342
Clin Genet. 2008 Feb;73(2):103-12
pubmed: 18005359

Auteurs

Arjun Srirampur (A)

Department of Cornea, Anand Eye Institute, Hyderabad, IND.

Tarannum Mansoori (T)

Department of Glaucoma, Anand Eye Institute, Hyderabad, IND.

Pravalika Rebbala (P)

Department of Cornea, Anand Eye Institute, Hyderabad, IND.

Classifications MeSH