Update on the Swedish Newborn Screening for Congenital Adrenal Hyperplasia Due to 21-Hydroxylase Deficiency.

21-hydroxylase deficiency CAH CYP21A2 DBS PPV congenital adrenal hyperplasia dried blood spots neonatal screening positive predictive value

Journal

International journal of neonatal screening
ISSN: 2409-515X
Titre abrégé: Int J Neonatal Screen
Pays: Switzerland
ID NLM: 101665400

Informations de publication

Date de publication:
28 Aug 2020
Historique:
received: 11 08 2020
revised: 25 08 2020
accepted: 26 08 2020
entrez: 26 11 2020
pubmed: 27 11 2020
medline: 27 11 2020
Statut: epublish

Résumé

Congenital adrenal hyperplasia (CAH) was the fourth disorder added to the national Swedish neonatal screening program in 1986, and approximately 115,000 newborns are screened annually. Dried blood spot (DBS) screening with measurement of 17-hydroxyprogesterone (17OHP) is also offered to older children moving to Sweden from countries lacking a national DBS screening program. Here, we report an update on the CAH screening from January 2011 until December 2019.

Identifiants

pubmed: 33239597
pii: ijns6030071
doi: 10.3390/ijns6030071
pmc: PMC7570065
pii:
doi:

Types de publication

Journal Article

Langues

eng

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Auteurs

Rolf H Zetterström (RH)

Centre for Inherited Metabolic Diseases, Karolinska University Hospital, SE-171 76 Stockholm, Sweden.
Department of Molecular Medicine and Surgery, Karolinska Institutet, SE-171 76 Stockholm, Sweden.

Leif Karlsson (L)

Centre for Inherited Metabolic Diseases, Karolinska University Hospital, SE-171 76 Stockholm, Sweden.
Department of Women's and Children's Health, Karolinska Institutet, SE-171 76 Stockholm, Sweden.

Henrik Falhammar (H)

Department of Molecular Medicine and Surgery, Karolinska Institutet, SE-171 76 Stockholm, Sweden.
Department of Endocrinology, Metabolism and Diabetes, Karolinska University Hospital, SE-171 77 Stockholm, Sweden.

Svetlana Lajic (S)

Department of Women's and Children's Health, Karolinska Institutet, SE-171 76 Stockholm, Sweden.
Pediatric Endocrinology Unit, Astrid Lindgren´s Children's Hospital, Karolinska University Hospital, SE-171 76 Stockholm, Sweden.

Anna Nordenström (A)

Centre for Inherited Metabolic Diseases, Karolinska University Hospital, SE-171 76 Stockholm, Sweden.
Department of Women's and Children's Health, Karolinska Institutet, SE-171 76 Stockholm, Sweden.
Pediatric Endocrinology Unit, Astrid Lindgren´s Children's Hospital, Karolinska University Hospital, SE-171 76 Stockholm, Sweden.

Classifications MeSH