Six Exonic Variants in the

SLC5A2 gene exon skipping exonic variant minigene analysis missense variant pre-mRNA splicing

Journal

Frontiers in genetics
ISSN: 1664-8021
Titre abrégé: Front Genet
Pays: Switzerland
ID NLM: 101560621

Informations de publication

Date de publication:
2020
Historique:
received: 19 07 2020
accepted: 20 10 2020
entrez: 30 11 2020
pubmed: 1 12 2020
medline: 1 12 2020
Statut: epublish

Résumé

Familial renal glucosuria is a rare renal tubular disorder caused by We used bioinformatics programs to analyze 77 previously described presumed Our study indicated six of 7 candidate variants induced splicing alterations. Variants c.216C > A, c.294C > A, c.886G > C, c.932A > G and c.962A > G may disrupt splicing enhancer motifs and generate splicing silencer sequences resulting in the skipping of exon 3. Variants c.305C > T and c.1129G > A probably disturb splice sites leading to exon skipping. To our knowledge, we report, for the first time,

Sections du résumé

BACKGROUND BACKGROUND
Familial renal glucosuria is a rare renal tubular disorder caused by
METHODS METHODS
We used bioinformatics programs to analyze 77 previously described presumed
RESULTS RESULTS
Our study indicated six of 7 candidate variants induced splicing alterations. Variants c.216C > A, c.294C > A, c.886G > C, c.932A > G and c.962A > G may disrupt splicing enhancer motifs and generate splicing silencer sequences resulting in the skipping of exon 3. Variants c.305C > T and c.1129G > A probably disturb splice sites leading to exon skipping.
CONCLUSION CONCLUSIONS
To our knowledge, we report, for the first time,

Identifiants

pubmed: 33250922
doi: 10.3389/fgene.2020.585064
pmc: PMC7674938
doi:

Types de publication

Journal Article

Langues

eng

Pagination

585064

Informations de copyright

Copyright © 2020 Wang, Wang, Wang, Liu, Zhang, Shi, Han, Guo, Bottillo and Shao.

Références

Kidney Int. 2006 Mar;69(5):852-5
pubmed: 16518345
Front Genet. 2020 Feb 21;11:81
pubmed: 32153641
Gene. 2014 Aug 10;546(2):243-9
pubmed: 24907393
BMC Nephrol. 2020 Feb 28;21(1):69
pubmed: 32111189
Biomed Res Int. 2018 Oct 10;2018:8727941
pubmed: 30406144
Genomics. 1993 Sep;17(3):787-9
pubmed: 8244402
J Bras Nefrol. 2012 Jul-Sep;34(3):291-2
pubmed: 23099837
Hum Mutat. 2010 Jan;31(1):E1110-25
pubmed: 19953646
Nat Rev Genet. 2002 Apr;3(4):285-98
pubmed: 11967553
Mol Genet Genomic Med. 2015 Jul;3(4):327-45
pubmed: 26247049
BMC Med Genet. 2019 Jan 8;20(1):6
pubmed: 30621608
Eur J Hum Genet. 2014 Dec;22(12):1362-8
pubmed: 24667779
Clin Chim Acta. 2019 Mar;490:102-106
pubmed: 30593819
J Med Genet. 2010 Jun;47(6):398-403
pubmed: 20522429
Biosystems. 2018 Feb;164:39-48
pubmed: 29122587
Eur J Med Genet. 2017 Dec;60(12):631-634
pubmed: 28803024
J Diabetes Investig. 2020 May;11(3):573-577
pubmed: 31584752
Nephrol Dial Transplant. 2008 Dec;23(12):3874-9
pubmed: 18622023
Sci Rep. 2016 Sep 26;6:33920
pubmed: 27666404
PLoS Genet. 2016 Jan 13;12(1):e1005756
pubmed: 26761715
J Am Soc Nephrol. 2003 Nov;14(11):2873-82
pubmed: 14569097
J Am Soc Nephrol. 2016 May;27(5):1426-36
pubmed: 26376857
J Am Soc Nephrol. 2015 Feb;26(2):271-9
pubmed: 25060058
Curr Hematol Malig Rep. 2016 Dec;11(6):408-415
pubmed: 27492253
Clin Chim Acta. 2017 Jun;469:105-110
pubmed: 28365451
BMC Nephrol. 2016 Mar 21;17:31
pubmed: 27000029
Mol Genet Metab. 2004 May;82(1):56-8
pubmed: 15110322
J Clin Endocrinol Metab. 2017 May 1;102(5):1548-1556
pubmed: 28324025
Hum Genet. 2011 Mar;129(3):335-44
pubmed: 21165652
Nephron. 2015;129(4):300-4
pubmed: 25896487
Kidney Int. 2005 Jan;67(1):34-41
pubmed: 15610225
FEBS Lett. 2005 Mar 28;579(9):1900-3
pubmed: 15792793
Gene. 2016 Mar 1;578(1):117-23
pubmed: 26692149
Endocrine. 2019 Jun;64(3):708-718
pubmed: 30790175
FEBS Open Bio. 2018 Feb 10;8(3):461-469
pubmed: 29511623
Hum Genet. 2002 Dec;111(6):544-7
pubmed: 12436245
Exp Ther Med. 2016 Aug;12(2):649-652
pubmed: 27446256

Auteurs

Sai Wang (S)

Department of Nephrology, The Affiliated Qingdao Municipal Hospital of Qingdao University, Qingdao, China.
Department of Dermatology, Peking University First Hospital, Beijing, China.

Yixiu Wang (Y)

Department of Hepatic Surgery, Shanghai Cancer Center, Shanghai Medical College, Fudan University, Shanghai, China.

Jinchao Wang (J)

Yantai Branch of Wenden Osteopathic Hospital, Yantai, China.

Zhiying Liu (Z)

Department of Nephrology, The Affiliated Qingdao Municipal Hospital of Qingdao University, Qingdao, China.

Ruixiao Zhang (R)

Department of Nephrology, The Affiliated Qingdao Municipal Hospital of Qingdao University, Qingdao, China.

Xiaomeng Shi (X)

Department of Nephrology, The Affiliated Qingdao Municipal Hospital of Qingdao University, Qingdao, China.

Yue Han (Y)

Department of Nephrology, The Affiliated Qingdao Municipal Hospital of Qingdao University, Qingdao, China.

Wencong Guo (W)

Department of Nephrology, The Affiliated Qingdao Municipal Hospital of Qingdao University, Qingdao, China.

Irene Bottillo (I)

Division of Medical Genetics, Department of Molecular Medicine, Sapienza University, San Camillo-Forlanini Hospital, Italy.

Leping Shao (L)

Department of Nephrology, The Affiliated Qingdao Municipal Hospital of Qingdao University, Qingdao, China.

Classifications MeSH