Isolated sulfite oxidase deficiency: a founder mutation.


Journal

Cold Spring Harbor molecular case studies
ISSN: 2373-2873
Titre abrégé: Cold Spring Harb Mol Case Stud
Pays: United States
ID NLM: 101660017

Informations de publication

Date de publication:
12 2020
Historique:
received: 12 10 2020
accepted: 05 11 2020
entrez: 18 12 2020
pubmed: 19 12 2020
medline: 15 9 2021
Statut: epublish

Résumé

Isolated sulfite oxidase deficiency is a rare autosomal recessive inborn error of sulfur metabolism. Clinical features generally include devastating neurologic dysfunction, ectopia lentis, and increased urinary excretion of sulfite, thiosulfate, and

Identifiants

pubmed: 33335014
pii: mcs.a005900
doi: 10.1101/mcs.a005900
pmc: PMC7784486
pii:
doi:

Substances chimiques

Thiosulfates 0
Uric Acid 268B43MJ25
Sulfite Oxidase EC 1.8.3.1

Types de publication

Journal Article Research Support, N.I.H., Extramural

Langues

eng

Sous-ensembles de citation

IM

Informations de copyright

© 2020 Mhanni et al.; Published by Cold Spring Harbor Laboratory Press.

Références

Cell. 1997 Dec 26;91(7):973-83
pubmed: 9428520
J Clin Invest. 1976 Sep;58(3):551-6
pubmed: 956384

Auteurs

Aizeddin A Mhanni (AA)

Department of Pediatrics and Child Health, University of Manitoba, Winnipeg, Manitoba R3A 1S1, Canada.

Cheryl R Greenberg (CR)

Department of Pediatrics and Child Health, University of Manitoba, Winnipeg, Manitoba R3A 1S1, Canada.
Department of Biochemistry and Medical Genetics, University of Manitoba, Winnipeg, Manitoba R3A 1S1, Canada.

Elizabeth L Spriggs (EL)

Department of Pediatrics and Child Health, University of Manitoba, Winnipeg, Manitoba R3A 1S1, Canada.
Department of Biochemistry and Medical Genetics, University of Manitoba, Winnipeg, Manitoba R3A 1S1, Canada.

Ronald Agatep (R)

Department of Biochemistry and Medical Genetics, University of Manitoba, Winnipeg, Manitoba R3A 1S1, Canada.

Reena Ray Sisk (RR)

Saskatoon Health Authority, Saskatoon S7K 0M7, Canada.

Chitra Prasad (C)

London Health Sciences Centre, Western University, London, Ontario N6A 5A5, Canada.

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Classifications MeSH