Monoclonal Gammopathy of Renal Significance: Clinical and Histological Efficacy of a Bortezomib-Based Regimen.

C3 glomerulonephritis (C3GN) Immunotactoid glomerulonephritis bortezomib glomerulonephritis monoclonal gammopathy of renal significance (MGRS)

Journal

Frontiers in medicine
ISSN: 2296-858X
Titre abrégé: Front Med (Lausanne)
Pays: Switzerland
ID NLM: 101648047

Informations de publication

Date de publication:
2020
Historique:
received: 25 07 2020
accepted: 23 11 2020
entrez: 4 1 2021
pubmed: 5 1 2021
medline: 5 1 2021
Statut: epublish

Résumé

Monoclonal Gammopathy of Renal Significance (MGRS) is a group of heterogeneous disorders characterized by renal dysfunction secondary to the production of a monoclonal immunoglobulin by a nonmalignant B cell or plasma cell clone. We report the clinical and histological outcomes of two patients with biopsy-proven MGRS: one patient showed membranoproliferative glomerulonephritis with monoclonal k-light chain and C3 deposits, the second patient showed immunotactoid glomerulopathy. Both patients were treated with a 9-month chemotherapy protocol including bortezomib, cyclophosphamide, and dexamethasone. Renal biospy was repeated after 1 year. The estimated glomerular filtration rate (eGFR) increased from 22.5 (baseline) to 40 ml/min per 1.73 m2 after 12 months, then to 51.5 ml/min per 1.73 m2 after 24 months; proteinuria decreased from 4.85 (baseline) to 0.17 g/day after 12 months, then to 0.14 g/day after 24 months. Repeat renal biopsies showed a dramatic improvement of the glomerular proliferative lesions and near complete disappearance of the immune deposits. A bortezomib-based treatment proved very effective and was well-tolerated in the two patients presenting with clinically and histologically aggressive MGRS.

Identifiants

pubmed: 33392216
doi: 10.3389/fmed.2020.587345
pmc: PMC7772466
doi:

Types de publication

Case Reports

Langues

eng

Pagination

587345

Informations de copyright

Copyright © 2020 Quattrocchio, Barreca, Vaccarino, Del Vecchio, De Simone, Fenoglio, Ferro, Pagliaro, Pini, Manes and Roccatello.

Déclaration de conflit d'intérêts

The authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.

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Auteurs

Giacomo Quattrocchio (G)

Nephrology and Dialysis Unit, San Giovanni Bosco Hospital, Turin, Italy.

Antonella Barreca (A)

Division of Pathology, Città della Salute e della Scienza Hospital, Turin, Italy.

Antonella Vaccarino (A)

Hematology and Thrombotic Diseases, San Giovanni Bosco Hospital, Turin, Italy.

Giulio Del Vecchio (G)

Nephrology and Dialysis Unit, San Giovanni Bosco Hospital, Turin, Italy.

Emanuele De Simone (E)

Nephrology and Dialysis Unit, San Giovanni Bosco Hospital, Turin, Italy.

Roberta Fenoglio (R)

Nephrology and Dialysis Unit, San Giovanni Bosco Hospital, Turin, Italy.

Michela Ferro (M)

Nephrology and Dialysis Unit, San Giovanni Bosco Hospital, Turin, Italy.

Maria Pagliaro (M)

Hematology and Thrombotic Diseases, San Giovanni Bosco Hospital, Turin, Italy.

Massimo Pini (M)

Hematology and Thrombotic Diseases, San Giovanni Bosco Hospital, Turin, Italy.

Massimo Manes (M)

Nephrology and Dialysis Unit, Umberto Parini Hospital, Aosta, Italy.

Dario Roccatello (D)

Nephrology and Dialysis Unit, San Giovanni Bosco Hospital, Turin, Italy.
Center of Research of Immunopathology and Rare Diseases (CMID), Department of Rare, Immunologic, Hematologic and Immunohematologic Diseases, San Giovanni Bosco Hospital, University of Turin, Turin, Italy.

Classifications MeSH