Calculating the net clinical benefit in neuro-oncology clinical trials using two methods: quality-adjusted survival effect sizes and joint modeling.

glioma joint model net clinical benefit quality of life survival

Journal

Neuro-oncology advances
ISSN: 2632-2498
Titre abrégé: Neurooncol Adv
Pays: England
ID NLM: 101755003

Informations de publication

Date de publication:
Historique:
entrez: 7 1 2021
pubmed: 8 1 2021
medline: 8 1 2021
Statut: epublish

Résumé

Two methods combining survival and health-related quality of life (HRQoL) data in glioma trials to calculate the "net clinical benefit" were evaluated: Quality-adjusted effect sizes (QASES) and joint modeling (JM). The net clinical benefit in two trials was calculated as proof of concept for other trials. With the QASES method, effect sizes for differences in progression-free survival (PFS) or overall survival (OS) and HRQoL between the experimental arm and standard treatment arm were calculated, while the relative emphasis placed on survival/HRQoL varied. JM allows simultaneous modeling of HRQoL and OS/PFS. In the EORTC 26951 trial, combined radiochemotherapy significantly prolonged OS (difference 11.7 months), but also resulted in more patients experiencing clinically relevant worsening (≥10 points) in appetite loss and nausea/vomiting shortly after treatment. Using QASES, the survival benefit of additional procarbazine, lomustine, and vincristine (PCV) decreased from 42.3 months to 29.5 and 28.2 months when accounting for appetite loss and nausea/vomiting, respectively. JM analyses resulted in a loss of the beneficial effect of additional PCV between 13% and 24% when adjusting for different HRQoL parameters. The EORTC 22033 trial showed no significant PFS difference between radiotherapy or temozolomide alone (46 vs 39 months), nor clinically relevant differences in HRQoL. JM analyses also showed no significant association between PFS and HRQoL scales/items, whereas QASES showed that temozolomide alone was more favorable when considering symptom burden (47-49 instead of 39 months). Both methods resulted in different outcomes, but adjusting for the impact of treatment on HRQoL resulted in theoretically reduced survival benefits.

Sections du résumé

BACKGROUND BACKGROUND
Two methods combining survival and health-related quality of life (HRQoL) data in glioma trials to calculate the "net clinical benefit" were evaluated: Quality-adjusted effect sizes (QASES) and joint modeling (JM).
METHODS METHODS
The net clinical benefit in two trials was calculated as proof of concept for other trials. With the QASES method, effect sizes for differences in progression-free survival (PFS) or overall survival (OS) and HRQoL between the experimental arm and standard treatment arm were calculated, while the relative emphasis placed on survival/HRQoL varied. JM allows simultaneous modeling of HRQoL and OS/PFS.
RESULTS RESULTS
In the EORTC 26951 trial, combined radiochemotherapy significantly prolonged OS (difference 11.7 months), but also resulted in more patients experiencing clinically relevant worsening (≥10 points) in appetite loss and nausea/vomiting shortly after treatment. Using QASES, the survival benefit of additional procarbazine, lomustine, and vincristine (PCV) decreased from 42.3 months to 29.5 and 28.2 months when accounting for appetite loss and nausea/vomiting, respectively. JM analyses resulted in a loss of the beneficial effect of additional PCV between 13% and 24% when adjusting for different HRQoL parameters. The EORTC 22033 trial showed no significant PFS difference between radiotherapy or temozolomide alone (46 vs 39 months), nor clinically relevant differences in HRQoL. JM analyses also showed no significant association between PFS and HRQoL scales/items, whereas QASES showed that temozolomide alone was more favorable when considering symptom burden (47-49 instead of 39 months).
CONCLUSIONS CONCLUSIONS
Both methods resulted in different outcomes, but adjusting for the impact of treatment on HRQoL resulted in theoretically reduced survival benefits.

Identifiants

pubmed: 33409496
doi: 10.1093/noajnl/vdaa147
pii: vdaa147
pmc: PMC7772555
doi:

Types de publication

Journal Article

Langues

eng

Pagination

vdaa147

Informations de copyright

© The Author(s) 2020. Published by Oxford University Press, the Society for Neuro-Oncology and the European Association of Neuro-Oncology.

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Auteurs

Marijke B Coomans (MB)

Department of Neurology, Leiden University Medical Center, Leiden, the Netherlands.

Linda Dirven (L)

Department of Neurology, Leiden University Medical Center, Leiden, the Netherlands.
Department of Neurology, Haaglanden Medical Center, Den Haag, the Netherlands.

Neil K Aaronson (NK)

Division of Psychosocial Research and Epidemiology, The Netherlands Cancer Institute, Amsterdam, the Netherlands.

Brigitta G Baumert (BG)

Institute of Radiation-Oncology, Kantonsspital Graubünden, Chur, Switzerland.
Department of Radiation Oncology (MAASTRO clinic), and GROW (School for Oncology and Developmental Biology), Maastricht University Medical Center, Maastricht, the Netherlands.

Martin van den Bent (M)

The Brain Tumor Center, Erasmus MC Cancer Institute, Rotterdam, the Netherlands.

Andrew Bottomley (A)

Quality of Life Department, European Organisation for Research and Treatment of Cancer, Brussels, Belgium.

Alba A Brandes (AA)

Department of Medical Oncology, Azienda USL-IRCCS Institute of Neurological Sciences, Bologna, Italy.

Olivier Chinot (O)

Aix-Marseille Univ, APHM, CNRS, INP, Inst Neurophysiopathol, CHU Timone, Service de Neuro-Oncologie, Marseille, France.

Corneel Coens (C)

Quality of Life Department, European Organisation for Research and Treatment of Cancer, Brussels, Belgium.

Thierry Gorlia (T)

European Organization for Research and Treatment of Cancer Headquarters, Brussels, Belgium.

Ulrich Herrlinger (U)

Division of Clinical Neurooncology, Department of Neurology, University of Bonn Medical Center, Bonn, Germany.

Florence Keime-Guibert (F)

Groupe Hôpital Pitié-Salpetrière, Paris, France.

Annika Malmström (A)

Division of Cell biology and Department of Biomedicine and Clinical Sciences, Linköping University, Linköping, Sweden.

Francesca Martinelli (F)

Quality of Life Department, European Organisation for Research and Treatment of Cancer, Brussels, Belgium.

Jeff A Sloan (JA)

Department of Health Sciences Research, Mayo Clinic, Rochester, Minnesota, USA.

Roger Stupp (R)

Northwestern University, Feinberg School of Medicine, Chicago, Illinois, USA.

Andrea Talacchi (A)

Department of Neurosciences, Azienda Ospedaliera San Giovanni Addolorata, Roma, Italia.

Michael Weller (M)

Department of Neurology, University Hospital and University of Zurich, Zurich, Switzerland.

Wolfgang Wick (W)

Neurology Clinic and National Centre for Tumour Diseases, University Hospital Heidelberg, Heidelberg, Germany; German Consortium of Translational Cancer Research (DKTK), Clinical Cooperation Unit Neurooncology, German Cancer Research Center, Heidelberg, Germany.

Jaap C Reijneveld (JC)

Department of Neurology and Brain Tumour Center Amsterdam, Amsterdam University Medical Center, Amsterdam, the Netherlands.
Stichting Epilepsie Instellingen Nederland (SEIN), Heemstede, the Netherlands.

Martin J B Taphoorn (MJB)

Department of Neurology, Leiden University Medical Center, Leiden, the Netherlands.
Department of Neurology, Haaglanden Medical Center, Den Haag, the Netherlands.

Classifications MeSH