Autoimmune limbic encephalitis related to SARS-CoV-2 infection: Case-report and review of the literature.

Autoimmune limbic encephalitis COVID-19 Memory deficits Post-infectious encephalitis SARS-CoV-2 Seizures

Journal

Brain, behavior, & immunity - health
ISSN: 2666-3546
Titre abrégé: Brain Behav Immun Health
Pays: United States
ID NLM: 101759062

Informations de publication

Date de publication:
Mar 2021
Historique:
received: 30 12 2020
revised: 19 01 2021
accepted: 21 01 2021
entrez: 1 2 2021
pubmed: 2 2 2021
medline: 2 2 2021
Statut: ppublish

Résumé

SARS-CoV-2 infection is associated with a wide spectrum of neurological complications, including encephalitis. Most cases showed features consistent with a central nervous system (CNS) cytokine-mediated damage. However, few cases arguing for an autoimmune mechanism have been described, mainly as single reports or sparse in large case series involving other CNS manifestations. In this paper, we described a case of definite autoimmune limbic encephalitis (LE) COVID-19 related and reviewed the existing literature on other reported cases. Two weeks after the onset of COVID-19 infection, a 74-year-old woman presented with subacute confusion and focal motor seizures with impaired awareness, starting from left temporal region. Cerebrospinal fluid analysis revealed hyperproteinorrachia. Brain MRI showed bilateral T2/FLAIR hyperintensities in both hippocampi and total body PET/TC scan revealed hypermetabolism in basal ganglia bilaterally. A diagnosis of autoimmune LE was made. Thus, high dose corticosteroids and antiseizure medications were started, with a marked improvement of neurological conditions. We systematically reviewed the literature to identify all well-documented cases of definite autoimmune LE (according to Graus criteria) in patients with COVID-19 infection, identifying other five cases exhibiting a good response to immunomodulating therapy. A very limited number of autoimmune LE have been described until now. It is important to monitor neurological symptoms in COVID-19 patients and to consider the possibility of an autoimmune LE, in particular when altered mental status and seizures appear late in the disease course. This allows to promptly start the appropriate treatments and avoid unnecessary delays.

Sections du résumé

BACKGROUND BACKGROUND
SARS-CoV-2 infection is associated with a wide spectrum of neurological complications, including encephalitis. Most cases showed features consistent with a central nervous system (CNS) cytokine-mediated damage. However, few cases arguing for an autoimmune mechanism have been described, mainly as single reports or sparse in large case series involving other CNS manifestations. In this paper, we described a case of definite autoimmune limbic encephalitis (LE) COVID-19 related and reviewed the existing literature on other reported cases.
CASE REPORT METHODS
Two weeks after the onset of COVID-19 infection, a 74-year-old woman presented with subacute confusion and focal motor seizures with impaired awareness, starting from left temporal region. Cerebrospinal fluid analysis revealed hyperproteinorrachia. Brain MRI showed bilateral T2/FLAIR hyperintensities in both hippocampi and total body PET/TC scan revealed hypermetabolism in basal ganglia bilaterally. A diagnosis of autoimmune LE was made. Thus, high dose corticosteroids and antiseizure medications were started, with a marked improvement of neurological conditions.
LITERATURE REVIEW METHODS
We systematically reviewed the literature to identify all well-documented cases of definite autoimmune LE (according to Graus criteria) in patients with COVID-19 infection, identifying other five cases exhibiting a good response to immunomodulating therapy.
CONCLUSION CONCLUSIONS
A very limited number of autoimmune LE have been described until now. It is important to monitor neurological symptoms in COVID-19 patients and to consider the possibility of an autoimmune LE, in particular when altered mental status and seizures appear late in the disease course. This allows to promptly start the appropriate treatments and avoid unnecessary delays.

Identifiants

pubmed: 33521691
doi: 10.1016/j.bbih.2021.100210
pii: S2666-3546(21)00013-2
pmc: PMC7830195
doi:

Types de publication

Journal Article

Langues

eng

Pagination

100210

Informations de copyright

© 2021 Published by Elsevier Inc.

Déclaration de conflit d'intérêts

The Authors have no conflicts of interest to disclose.

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Auteurs

Chiara Pizzanelli (C)

Neurology Unit, Department of Clinical and Experimental Medicine, University of Pisa, Pisa, Italy.

Chiara Milano (C)

Neurology Unit, Department of Clinical and Experimental Medicine, University of Pisa, Pisa, Italy.

Silvia Canovetti (S)

Department of Translational Research and New Technologies in Medicine and Surgery, University of Pisa, Pisa, Italy.

Enrico Tagliaferri (E)

Infectious Diseases Unit, Nuovo Santa Chiara University Hospital, Azienda Ospedaliera Universitaria Pisana, Pisa, Italy.

Francesco Turco (F)

Neurology Unit, Department of Clinical and Experimental Medicine, University of Pisa, Pisa, Italy.

Stefano Verdenelli (S)

Infectious Diseases Unit, Nuovo Santa Chiara University Hospital, Azienda Ospedaliera Universitaria Pisana, Pisa, Italy.

Lorenzo Nesti (L)

Department of Clinical and Experimental Medicine, University of Pisa, Pisa, Italy.

Marta Franchi (M)

Department of Translational Research and New Technologies in Medicine and Surgery, University of Pisa, Pisa, Italy.
Radiology Unit, Azienda Ospedaliera Universitaria Città della Scienza e della Salute, University of Torino, Torino, Italy.

Enrica Bonanni (E)

Neurology Unit, Department of Clinical and Experimental Medicine, University of Pisa, Pisa, Italy.

Francesco Menichetti (F)

Infectious Diseases Unit, Nuovo Santa Chiara University Hospital, Azienda Ospedaliera Universitaria Pisana, Pisa, Italy.

Duccio Volterrani (D)

Nuclear Medicine Unit, University of Pisa, Pisa, Italy.

Mirco Cosottini (M)

Department of Translational Research and New Technologies in Medicine and Surgery, University of Pisa, Pisa, Italy.

Gabriele Siciliano (G)

Neurology Unit, Department of Clinical and Experimental Medicine, University of Pisa, Pisa, Italy.

Classifications MeSH