Cytomorphologic Spectrum of SMARCB1-Deficient Soft Tissue Neoplasms.


Journal

American journal of clinical pathology
ISSN: 1943-7722
Titre abrégé: Am J Clin Pathol
Pays: England
ID NLM: 0370470

Informations de publication

Date de publication:
06 07 2021
Historique:
pubmed: 21 2 2021
medline: 27 8 2021
entrez: 20 2 2021
Statut: ppublish

Résumé

The SWI/SNF complex core subunit SMARCB1 is inactivated in a variety of neoplasms that share characteristic "rhabdoid" cytomorphology. The aim of this study was to evaluate SMARCB1-deficient soft tissue neoplasms on cytology to identify diagnostic clues. Eleven SMARCB1-deficient tumors, including six epithelioid sarcomas, three malignant rhabdoid tumors, one epithelioid malignant peripheral nerve sheath tumor (MPNST), and one poorly differentiated chordoma with fine-needle aspiration (FNA), serous effusion, or touch prep (TP) from two institutions, were included. Targeted next-generation sequencing (NGS) was performed in two cases. Evaluation of FNA (n = 4), effusion (n = 4), and TP (n = 3) in nine adult and two pediatric patients demonstrated cellular samples (n = 11), epithelioid cells with rhabdoid morphology (n = 9), eccentrically located nuclei with prominent nucleoli (n = 7), and cytoplasmic bodies (n = 4); two patients were diagnosed on FNA with cell block. Immunohistochemistry (IHC) demonstrated SMARCB1 loss in all cases and keratin and/or EMA expression in all but the epithelioid MPNST; NGS identified SMARCB1 inactivation in both cases. SMARCB1-deficient soft tissue neoplasms comprise a variety of tumors with epithelioid morphology and frequent expression of keratin and/or EMA. Recognition of characteristic rhabdoid morphology on cytology can prompt IHC and/or NGS testing for SMARCB1 deficiency and help establish the diagnosis.

Identifiants

pubmed: 33608696
pii: 6145292
doi: 10.1093/ajcp/aqaa223
pmc: PMC8259500
doi:

Substances chimiques

SMARCB1 Protein 0
SMARCB1 protein, human 0

Types de publication

Journal Article Research Support, N.I.H., Extramural

Langues

eng

Sous-ensembles de citation

IM

Pagination

229-245

Subventions

Organisme : NCI NIH HHS
ID : K08 CA241085
Pays : United States

Informations de copyright

© American Society for Clinical Pathology, 2021. All rights reserved. For permissions, please e-mail: journals.permissions@oup.com.

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Auteurs

Inga-Marie Schaefer (IM)

Department of Pathology, Brigham and Women's Hospital.

Alyaa Al-Ibraheemi (A)

Department of Pathology, Boston Children's Hospital, Harvard Medical School, Boston, MA, USA.

Xiaohua Qian (X)

Department of Pathology, Brigham and Women's Hospital.

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