Unilateral Submandibular Gland Aplasia with Ipsilateral Sublingual Ranula - A Case Report.
Nonsyndromic unilateral aplasia
salivary gland aplasia
submandibular gland
Journal
Annals of maxillofacial surgery
ISSN: 2231-0746
Titre abrégé: Ann Maxillofac Surg
Pays: India
ID NLM: 101598423
Informations de publication
Date de publication:
Historique:
received:
04
03
2020
revised:
01
04
2020
accepted:
17
04
2020
entrez:
12
3
2021
pubmed:
13
3
2021
medline:
13
3
2021
Statut:
ppublish
Résumé
Congenital aplasia of major salivary glands is a very rare entity, especially if it concerns an ipsilateral aplasia in a nonsyndromic patient. The aim of this report is to present a case of an aplasia of the left submandibular gland, which was incidentally diagnosed during presurgical imaging for an ipsilateral sublingual ranula. Histopathological evidence of the lack of sublingual gland tissue in the excised specimen of the ranula is discussed. Unilateral submandibular aplasia has unknown etiology. Clinicians should be aware of this condition mainly to be able to differentially diagnose a hypertrophy/dysplasia of the contralateral or other major salivary glands, or when xerostomia is the main patient's symptom.
Sections du résumé
BACKGROUND
BACKGROUND
Congenital aplasia of major salivary glands is a very rare entity, especially if it concerns an ipsilateral aplasia in a nonsyndromic patient.
KEY POINTS FROM THE CASE
UNASSIGNED
The aim of this report is to present a case of an aplasia of the left submandibular gland, which was incidentally diagnosed during presurgical imaging for an ipsilateral sublingual ranula. Histopathological evidence of the lack of sublingual gland tissue in the excised specimen of the ranula is discussed.
MAIN LESSONS TO BE LEARNED FROM THIS CASE REPORT
UNASSIGNED
Unilateral submandibular aplasia has unknown etiology. Clinicians should be aware of this condition mainly to be able to differentially diagnose a hypertrophy/dysplasia of the contralateral or other major salivary glands, or when xerostomia is the main patient's symptom.
Identifiants
pubmed: 33708614
doi: 10.4103/ams.ams_63_20
pii: AMS-10-543
pmc: PMC7944001
doi:
Types de publication
Case Reports
Langues
eng
Pagination
543-546Informations de copyright
Copyright: © 2020 Annals of Maxillofacial Surgery.
Déclaration de conflit d'intérêts
There are no conflicts of interest.
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