A homozygous truncating variant in GDF9 in siblings with primary ovarian insufficiency.


Journal

Journal of assisted reproduction and genetics
ISSN: 1573-7330
Titre abrégé: J Assist Reprod Genet
Pays: Netherlands
ID NLM: 9206495

Informations de publication

Date de publication:
Jun 2021
Historique:
received: 03 01 2021
accepted: 03 03 2021
pubmed: 3 4 2021
medline: 15 12 2021
entrez: 2 4 2021
Statut: ppublish

Résumé

Premature or primary ovarian insufficiency (POI) affects approximately 1% of women and can be due to a variety of causes. Genetic causes include syndromic and non-syndromic POI. There are several promising candidate genes for whom a clear Mendelian association with non-syndromic POI has not yet been conclusively established, including GDF9. GDF9 is an oocyte-secreted factor and is part of the TGF-beta superfamily of morphogens. It has an important role in follicular development and granulosa cell maturation. We report the case of two siblings with primary ovarian insufficiency (POI) and a homozygous truncating variant in GDF9 (c.604C>T; p.(Gln202*). This report helps establish a clear gene-disease association between GDF9 and POI and argues for routine evaluation for GDF9 variants in patients undergoing genomic investigation for POI.

Identifiants

pubmed: 33797006
doi: 10.1007/s10815-021-02144-x
pii: 10.1007/s10815-021-02144-x
pmc: PMC8266936
doi:

Substances chimiques

GDF9 protein, human 0
Growth Differentiation Factor 9 0
Transforming Growth Factor beta 0

Types de publication

Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

1539-1543

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Auteurs

Kunal P Verma (KP)

Department of Genomic Medicine and Familial Cancer Centre, Royal Melbourne Hospital, Parkville, VIC, 3050, Australia. kunal.verma@mh.org.au.

Bryony Thompson (B)

Department of Molecular Pathology, Royal Melbourne Hospital, Parkville, VIC, 3050, Australia.

James Wolfe (J)

Department of Genomic Medicine and Familial Cancer Centre, Royal Melbourne Hospital, Parkville, VIC, 3050, Australia.

Sarah Price (S)

Department of Endocrinology, Royal Melbourne Hospital, Parkville, VIC, 3050, Australia.

Frida Djukiadmodjo (F)

Department of Genomic Medicine and Familial Cancer Centre, Royal Melbourne Hospital, Parkville, VIC, 3050, Australia.

Alison Trainer (A)

Department of Genomic Medicine and Familial Cancer Centre, Royal Melbourne Hospital, Parkville, VIC, 3050, Australia.

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Classifications MeSH