Eye Tumors in Childhood as First Sign of Tumor Predisposition Syndromes: Insights from an Observational Study Conducted in Germany and Austria.

DICER1 syndrome cancer predisposition syndrome ciliary body medulloepithelioma genetic counseling nevus Ota retinal astrocytoma retinoblastoma uveal melanoma

Journal

Cancers
ISSN: 2072-6694
Titre abrégé: Cancers (Basel)
Pays: Switzerland
ID NLM: 101526829

Informations de publication

Date de publication:
14 Apr 2021
Historique:
received: 03 02 2021
revised: 05 04 2021
accepted: 09 04 2021
entrez: 30 4 2021
pubmed: 1 5 2021
medline: 1 5 2021
Statut: epublish

Résumé

Retinoblastoma and other eye tumors in childhood are rare diseases. Many eye tumors are the first signs of a genetic tumor predisposition syndrome and the affected children carry a higher risk of developing other cancers later in life. Clinical and genetic data of all children with eye tumors diagnosed between 2013-2018 in Germany and Austria were collected in a multicenter prospective observational study. In five years, 300 children were recruited into the study: 287 with retinoblastoma, 7 uveal melanoma, 3 ciliary body medulloepithelioma, 2 retinal astrocytoma, 1 meningioma of the optic nerve extending into the eye. Heritable retinoblastoma was diagnosed in 44% of children with retinoblastoma. One child with meningioma of the optic nerve extending into the eye was diagnosed with neurofibromatosis 2. No pathogenic constitutional variant in

Identifiants

pubmed: 33919815
pii: cancers13081876
doi: 10.3390/cancers13081876
pmc: PMC8070790
pii:
doi:

Types de publication

Journal Article

Langues

eng

Subventions

Organisme : Deutsche Kinderkrebsstiftung
ID : 2013.11
Organisme : Deutsche Kinderkrebsstiftung
ID : 2016.09
Organisme : Deutsche Kinderkrebsstiftung
ID : 2018.12

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Auteurs

Madlen Reschke (M)

Department of Pediatric Hematology and Oncology, Charité-Universitätsmedizin, 13353 Berlin, Germany.

Eva Biewald (E)

Department of Ophthalmology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Leo Bronstein (L)

Institute of Biostatistics and Clinical Research, University of Muenster, 48149 Münster, Germany.

Ines B Brecht (IB)

Department of Pediatric Hematology and Oncology, Children's University Hospital Tübingen, 72076 Tübingen, Germany.

Sabine Dittner-Moormann (S)

Department of Pediatric Hematology and Oncology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Frank Driever (F)

Institute of Pathology, University Hospital Essen, University Duisburg-Essen, 45122 Essen, Germany.

Martin Ebinger (M)

Department of Pediatric Hematology and Oncology, Children's University Hospital Tübingen, 72076 Tübingen, Germany.

Gudrun Fleischhack (G)

Department of Pediatric Hematology and Oncology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Desiree Grabow (D)

Division of Childhood Cancer Epidemiology, German Childhood Cancer Registry at Institute of Medical Biostatistics, Epidemiology and Informatics (IMBEI), University Medical Center of the Johannes Gutenberg University Mainz, 55131 Mainz, Germany.

Dirk Geismar (D)

Clinic for Particle Therapy, West German Proton Therapy Centre Essen (WPE), University Hospital Essen, 45122 Essen, Germany.

Sophia Göricke (S)

Department of Diagnostic and Interventional Radiology and Neuroradiology, University Hospital Essen, 45122 Essen, Germany.

Maja Guberina (M)

Department for Radiotherapy, University Hospital Essen, 45122 Essen, Germany.

Claudia H D Le Guin (CHD)

Department of Ophthalmology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Tobias Kiefer (T)

Department of Ophthalmology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Christian P Kratz (CP)

Department of Pediatric Hematology and Oncology, Hannover Medical School, 30625 Hannover, Germany.

Klaus Metz (K)

Institute of Pathology, University Hospital Essen, University Duisburg-Essen, 45122 Essen, Germany.

Bert Müller (B)

Department of Ophthalmology, Charité-Universitätsmedizin, 13353 Berlin, Germany.

Tatsiana Ryl (T)

Department of Pediatric Hematology and Oncology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Marc Schlamann (M)

Department of Neuroradiology, University Hospital Köln, 50937 Köln, Germany.

Sabrina Schlüter (S)

Department of Ophthalmology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Stefan Schönberger (S)

Department of Pediatric Hematology and Oncology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Johannes H Schulte (JH)

Department of Pediatric Hematology and Oncology, Charité-Universitätsmedizin, 13353 Berlin, Germany.

Selma Sirin (S)

Department of Diagnostic and Interventional Radiology and Neuroradiology, University Hospital Essen, 45122 Essen, Germany.

Daniela Süsskind (D)

Department of Ophthalmology, University Hospital Tübingen, 72076 Tübingen, Germany.

Beate Timmermann (B)

Clinic for Particle Therapy, West German Proton Therapy Centre Essen (WPE), University Hospital Essen, 45122 Essen, Germany.
German Consortium for Translational Cancer Research (DKTK), Standort Essen/Düsseldorf, 45122 Essen, Germany.

Saskia Ting (S)

Institute of Pathology, University Hospital Essen, University Duisburg-Essen, 45122 Essen, Germany.

Werner Wackernagel (W)

Department of Ophthalmology, Medical University of Graz, 8036 Graz, Austria.

Regina Wieland (R)

Department of Pediatric Hematology and Oncology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Martin Zenker (M)

Institute of Human Genetics, University Magdeburg, 39120 Magdeburg, Germany.

Michael Zeschnigk (M)

Institute of Human Genetics, Medical Faculty, University Duisburg-Essen, 45122 Essen, Germany.

Dirk Reinhardt (D)

Department of Pediatric Hematology and Oncology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Angelika Eggert (A)

Department of Pediatric Hematology and Oncology, Charité-Universitätsmedizin, 13353 Berlin, Germany.

Petra Ritter-Sovinz (P)

Division of Pediatric Hematology/Oncology, Department of Pediatrics and Adolescent Medicine, Medical University of Graz, 8036 Graz, Austria.

Dietmar R Lohmann (DR)

German Consortium for Translational Cancer Research (DKTK), Standort Essen/Düsseldorf, 45122 Essen, Germany.
Institute of Human Genetics, Medical Faculty, University Duisburg-Essen, 45122 Essen, Germany.

Norbert Bornfeld (N)

Department of Ophthalmology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.

Nikolaos Bechrakis (N)

Department of Ophthalmology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.
German Consortium for Translational Cancer Research (DKTK), Standort Essen/Düsseldorf, 45122 Essen, Germany.

Petra Ketteler (P)

Department of Pediatric Hematology and Oncology, University Hospital Essen, University Duisburg Essen, 45122 Essen, Germany.
German Consortium for Translational Cancer Research (DKTK), Standort Essen/Düsseldorf, 45122 Essen, Germany.
Institute of Human Genetics, Medical Faculty, University Duisburg-Essen, 45122 Essen, Germany.

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