Chilaiditi syndrome in pediatric patients - Symptomatic hepatodiaphragmatic interposition of colon: A case report and review of literature.

Abdominal pain Case report Colon Constipation Dyspnea Rare diseases Respiratory insufficiency

Journal

World journal of clinical pediatrics
ISSN: 2219-2808
Titre abrégé: World J Clin Pediatr
Pays: United States
ID NLM: 101627548

Informations de publication

Date de publication:
09 May 2021
Historique:
received: 05 01 2021
revised: 04 02 2021
accepted: 10 03 2021
entrez: 11 5 2021
pubmed: 12 5 2021
medline: 12 5 2021
Statut: epublish

Résumé

Chilaiditi syndrome is a rare disorder characterized by the hepatodiaphragmatic interposition of the intestine. Here we report a case of a 12-year-old male who was admitted to the pediatric intensive care unit secondary to abdominal pain and severe respiratory distress. He was treated conservatively but the symptoms persisted requiring a surgical approach. While there have been several cases of Chilaiditi syndrome reported in adults, there is a scarcity of cases reported in the pediatric population. Our review of the literature found only 30 pediatric cases, including our reported case, with Chilaiditi syndrome, 19 (63%) of which were male. The median age of diagnosis was 4.5 years old with an interquartile range of 2.0-10.0 years. In our review, we found that the most common predisposing factors in children are aerophagia (12/30 cases) and constipation (13/30 cases). Ninety percent of the cases presented with complete intestinal interposition, in 100% of which, the colon was involved. Three of the 30 cases were associated with volvulus. In the pediatric population, conservative (21/30 cases) and surgical (8/30 cases) treatment approaches have produced satisfactory outcomes for all the patients, regardless of approach.

Sections du résumé

BACKGROUND BACKGROUND
Chilaiditi syndrome is a rare disorder characterized by the hepatodiaphragmatic interposition of the intestine.
CASE SUMMARY METHODS
Here we report a case of a 12-year-old male who was admitted to the pediatric intensive care unit secondary to abdominal pain and severe respiratory distress. He was treated conservatively but the symptoms persisted requiring a surgical approach. While there have been several cases of Chilaiditi syndrome reported in adults, there is a scarcity of cases reported in the pediatric population. Our review of the literature found only 30 pediatric cases, including our reported case, with Chilaiditi syndrome, 19 (63%) of which were male. The median age of diagnosis was 4.5 years old with an interquartile range of 2.0-10.0 years. In our review, we found that the most common predisposing factors in children are aerophagia (12/30 cases) and constipation (13/30 cases). Ninety percent of the cases presented with complete intestinal interposition, in 100% of which, the colon was involved. Three of the 30 cases were associated with volvulus.
CONCLUSION CONCLUSIONS
In the pediatric population, conservative (21/30 cases) and surgical (8/30 cases) treatment approaches have produced satisfactory outcomes for all the patients, regardless of approach.

Identifiants

pubmed: 33972924
doi: 10.5409/wjcp.v10.i3.40
pmc: PMC8085720
doi:

Types de publication

Case Reports

Langues

eng

Pagination

40-47

Informations de copyright

©The Author(s) 2021. Published by Baishideng Publishing Group Inc. All rights reserved.

Déclaration de conflit d'intérêts

Conflict-of-interest statement: The authors declare that they have no conflict of interest.

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Auteurs

Luis Caicedo (L)

Division of Pediatric Gastroenterology, Hepatology, and Nutrition, Nicklaus Children's Hospital, Miami, FL 33155, United States.

Paul Wasuwanich (P)

Department of Medicine, University of Florida College of Medicine, Gainesville, FL 32610, United States.

Andrés Rivera (A)

Department of Pediatrics, Icahn School of Medicine at Mount Sinai, New York, NY 10092, United States.

Maria S Lopez (MS)

Department of Pediatrics, Nicklaus Children's Hospital, Miami, FL 33155, United States.

Wikrom Karnsakul (W)

Division of Pediatric Gastroenterology, Hepatology, and Nutrition, Department of Pediatrics, Johns Hopkins University School of Medicine, Baltimore, MD 21287, United States. wkarnsa1@jhmi.edu.

Classifications MeSH