Extraneural Metastases of Diffuse Midline Glioma, H3 K27M-Mutant at Diagnosis: Case Report, Review of the Literature, and Identifying Targetable Alterations.


Journal

Journal of pediatric hematology/oncology
ISSN: 1536-3678
Titre abrégé: J Pediatr Hematol Oncol
Pays: United States
ID NLM: 9505928

Informations de publication

Date de publication:
01 03 2022
Historique:
received: 25 01 2021
accepted: 25 03 2021
pubmed: 12 5 2021
medline: 27 4 2022
entrez: 11 5 2021
Statut: ppublish

Résumé

Extraneural metastases are rare in pediatric high-grade gliomas and little is known about the genomic profiles of tumors that disseminate beyond the central nervous system. We describe a pediatric patient with H3 K27M-mutant diffuse midline glioma of the brain and spine with biopsy-confirmed osseous metastases present at diagnosis and suspected metastatic parenchymal pulmonary disease. Several potentially clinically and/or therapeutically relevant genomic alterations were identified, including H3F3A and TP53 mutations as well as MET, CDK6, EMSY, and PIK3CG amplifications. Sequencing is critical to improve our understanding of the molecular drivers of distant metastases and discover therapeutic targets that penetrate all disease sites.

Identifiants

pubmed: 33974582
doi: 10.1097/MPH.0000000000002189
pii: 00043426-202203000-00079
doi:

Substances chimiques

Histones 0

Types de publication

Case Reports Journal Article Review

Langues

eng

Sous-ensembles de citation

IM

Pagination

e597-e604

Informations de copyright

Copyright © 2021 Wolters Kluwer Health, Inc. All rights reserved.

Déclaration de conflit d'intérêts

The authors declare no conflict of interest.

Références

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Auteurs

Margot A Lazow (MA)

Brain Tumor Center, Cancer and Blood Diseases Institute.

James L Leach (JL)

Department of Radiology and Medical Imaging, Cincinnati Children's Hospital Medical Center.
Departments of Radiology.
Pediatrics.

Andrew T Trout (AT)

Department of Radiology and Medical Imaging, Cincinnati Children's Hospital Medical Center.
Departments of Radiology.
Pediatrics.

John C Breneman (JC)

Pediatrics.
Radiation Oncology, University of Cincinnati College of Medicine, Cincinnati.

Maryam Fouladi (M)

Pediatric Neuro-Oncology Program, Nationwide Children's Hospital.
The Ohio State University College of Medicine, Columbus, OH.

Christine Fuller (C)

Department of Pathology, Upstate Medical University, Syracuse, NY.

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