The histone demethylase PHF8 regulates astrocyte differentiation and function.


Journal

Development (Cambridge, England)
ISSN: 1477-9129
Titre abrégé: Development
Pays: England
ID NLM: 8701744

Informations de publication

Date de publication:
15 06 2021
Historique:
received: 17 07 2020
accepted: 15 04 2021
pubmed: 4 6 2021
medline: 3 8 2021
entrez: 3 6 2021
Statut: ppublish

Résumé

Epigenetic factors have been shown to play a crucial role in X-linked intellectual disability (XLID). Here, we investigate the contribution of the XLID-associated histone demethylase PHF8 to astrocyte differentiation and function. Using genome-wide analyses and biochemical assays in mouse astrocytic cultures, we reveal a regulatory crosstalk between PHF8 and the Notch signaling pathway that balances the expression of the master astrocytic gene Nfia. Moreover, PHF8 regulates key synaptic genes in astrocytes by maintaining low levels of H4K20me3. Accordingly, astrocytic-PHF8 depletion has a striking effect on neuronal synapse formation and maturation in vitro. These data reveal that PHF8 is crucial in astrocyte development to maintain chromatin homeostasis and limit heterochromatin formation at synaptogenic genes. Our studies provide insights into the involvement of epigenetics in intellectual disability.

Identifiants

pubmed: 34081130
pii: 268981
doi: 10.1242/dev.194951
pii:
doi:

Substances chimiques

Biomarkers 0
Histones 0
Transcription Factors 0
Histone Demethylases EC 1.14.11.-
PHF8 protein, mouse EC 1.14.11.27

Types de publication

Journal Article Research Support, Non-U.S. Gov't

Langues

eng

Sous-ensembles de citation

IM

Subventions

Organisme : Ministry of Economy
ID : PGC2018-096082-B-I00
Organisme : Ministerio de Economía, Industria y Competitividad, Gobierno de España
ID : BFU2015-69248-P
Organisme : Boehringer Ingelheim
Organisme : Ministerio de Ciencia e Innovación de España
ID : PID2019-111217RB-I00

Informations de copyright

© 2021. Published by The Company of Biologists Ltd.

Déclaration de conflit d'intérêts

Competing interests The authors declare no competing or financial interests.

Auteurs

Simona Iacobucci (S)

Department of Molecular Genomics, Instituto de Biología Molecular de Barcelona (IBMB), Consejo Superior de Investigaciones Científicas (CSIC), Barcelona 08028, Spain.

Natalia Padilla (N)

Research Unit in Clinical and Translational Bioinformatics, Vall d'Hebron Institute of Research (VHIR), Passeig de la Vall d'Hebron, 119; E-08035 Barcelona, Spain. Institut Català per la Recerca i Estudis Avançats (ICREA), Barcelona 08018, Spain.

Martina Gabrielli (M)

CNR Institute of Neuroscience, via Vanvitelli 32, 20129 Milan, Italy.

Claudia Navarro (C)

Department of Molecular Genomics, Instituto de Biología Molecular de Barcelona (IBMB), Consejo Superior de Investigaciones Científicas (CSIC), Barcelona 08028, Spain.

Marta Lombardi (M)

CNR Institute of Neuroscience, via Vanvitelli 32, 20129 Milan, Italy.

Marta Vicioso-Mantis (M)

Department of Molecular Genomics, Instituto de Biología Molecular de Barcelona (IBMB), Consejo Superior de Investigaciones Científicas (CSIC), Barcelona 08028, Spain.

Claudia Verderio (C)

CNR Institute of Neuroscience, via Vanvitelli 32, 20129 Milan, Italy.

Xavier de la Cruz (X)

Research Unit in Clinical and Translational Bioinformatics, Vall d'Hebron Institute of Research (VHIR), Passeig de la Vall d'Hebron, 119; E-08035 Barcelona, Spain. Institut Català per la Recerca i Estudis Avançats (ICREA), Barcelona 08018, Spain.

Marian A Martínez-Balbás (MA)

Department of Molecular Genomics, Instituto de Biología Molecular de Barcelona (IBMB), Consejo Superior de Investigaciones Científicas (CSIC), Barcelona 08028, Spain.

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Classifications MeSH