MFN2-related Charcot-Marie-Tooth Disease with Atypical Ocular Manifestations.


Journal

Internal medicine (Tokyo, Japan)
ISSN: 1349-7235
Titre abrégé: Intern Med
Pays: Japan
ID NLM: 9204241

Informations de publication

Date de publication:
15 Dec 2021
Historique:
pubmed: 15 6 2021
medline: 18 12 2021
entrez: 14 6 2021
Statut: ppublish

Résumé

We herein describe a Charcot-Marie-Tooth disease (CMT) family with a MFN2 mutation with atypical ocular manifestations. The proband, his mother, his third daughter, and his deceased maternal grandfather all had symptoms of CMT and a visual impairment (either cataracts or severe astigmatism). On whole-exome sequencing for the proband having CMT and congenital cataracts, we identified a c.314C>T (p.Thr105Met) mutation in MFN2, but no mutation in the causative genes associated with cataracts. This missense mutation in MFN2 co-segregated with CMT and the atypical ocular manifestations in this family. The findings of this study might help to expand the clinical phenotype of heterogeneous MFN2-related CMT.

Identifiants

pubmed: 34121014
doi: 10.2169/internalmedicine.7463-21
pmc: PMC8758439
doi:

Substances chimiques

Mitochondrial Proteins 0
GTP Phosphohydrolases EC 3.6.1.-
MFN2 protein, human EC 3.6.1.-

Types de publication

Case Reports Journal Article

Langues

eng

Sous-ensembles de citation

IM

Pagination

3969-3974

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Auteurs

Haitian Nan (H)

Department of Neurology, University of Yamanashi, Japan.

Takanori Hata (T)

Department of Neurology, University of Yamanashi, Japan.

Toko Fukao (T)

Department of Neurology, University of Yamanashi, Japan.

Toshimichi Fukao (T)

Department of Pediatrics, University of Yamanashi, Japan.

Wanjing Chen (W)

Department of Ophthalmology, University of Yamanashi, Japan.

Takafumi Kurita (T)

Department of Neurology, University of Yamanashi, Japan.

Takahiro Natori (T)

Department of Neurology, University of Yamanashi, Japan.

Yoshihisa Takiyama (Y)

Department of Neurology, University of Yamanashi, Japan.

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Classifications MeSH