Droplet digital PCR-based detection of circulating tumor DNA from pediatric high grade and diffuse midline glioma patients.

CSF DIPG HGG cfDNA ctDNA plasma

Journal

Neuro-oncology advances
ISSN: 2632-2498
Titre abrégé: Neurooncol Adv
Pays: England
ID NLM: 101755003

Informations de publication

Date de publication:
Historique:
entrez: 25 6 2021
pubmed: 26 6 2021
medline: 26 6 2021
Statut: epublish

Résumé

The use of liquid biopsy is of potential high importance for children with high grade (HGG) and diffuse midline gliomas (DMG), particularly where surgical procedures are limited, and invasive biopsy sampling not without risk. To date, however, the evidence that detection of cell-free DNA (cfDNA) or circulating tumor DNA (ctDNA) could provide useful information for these patients has been limited, or contradictory. We optimized droplet digital PCR (ddPCR) assays for the detection of common somatic mutations observed in pediatric HGG/DMG, and applied them to liquid biopsies from plasma, serum, cerebrospinal fluid (CSF), and cystic fluid collected from 32 patients. Although detectable in all biomaterial types, ctDNA presented at significantly higher levels in CSF compared to plasma and/or serum. When applied to a cohort of 127 plasma specimens from 41 patients collected from 2011 to 2018 as part of a randomized clinical trial in pediatric non-brainstem HGG/DMG, ctDNA profiling by ddPCR was of limited use due to the small volumes (mean = 0.49 mL) available. In anecdotal cases where sufficient material was available, cfDNA concentration correlated with disease progression in two examples each of poor response in Tumor-specific DNA alterations are more readily detected in CSF than plasma. Although we demonstrate the potential of the approach to assessing tumor burden, our results highlight the necessity for adequate sample collection and approach to improve detection if plasma samples are to be used.

Sections du résumé

BACKGROUND BACKGROUND
The use of liquid biopsy is of potential high importance for children with high grade (HGG) and diffuse midline gliomas (DMG), particularly where surgical procedures are limited, and invasive biopsy sampling not without risk. To date, however, the evidence that detection of cell-free DNA (cfDNA) or circulating tumor DNA (ctDNA) could provide useful information for these patients has been limited, or contradictory.
METHODS METHODS
We optimized droplet digital PCR (ddPCR) assays for the detection of common somatic mutations observed in pediatric HGG/DMG, and applied them to liquid biopsies from plasma, serum, cerebrospinal fluid (CSF), and cystic fluid collected from 32 patients.
RESULTS RESULTS
Although detectable in all biomaterial types, ctDNA presented at significantly higher levels in CSF compared to plasma and/or serum. When applied to a cohort of 127 plasma specimens from 41 patients collected from 2011 to 2018 as part of a randomized clinical trial in pediatric non-brainstem HGG/DMG, ctDNA profiling by ddPCR was of limited use due to the small volumes (mean = 0.49 mL) available. In anecdotal cases where sufficient material was available, cfDNA concentration correlated with disease progression in two examples each of poor response in
CONCLUSION CONCLUSIONS
Tumor-specific DNA alterations are more readily detected in CSF than plasma. Although we demonstrate the potential of the approach to assessing tumor burden, our results highlight the necessity for adequate sample collection and approach to improve detection if plasma samples are to be used.

Identifiants

pubmed: 34169282
doi: 10.1093/noajnl/vdab013
pii: vdab013
pmc: PMC8218704
doi:

Types de publication

Journal Article

Langues

eng

Pagination

vdab013

Informations de copyright

© The Author(s) 2021. Published by Oxford University Press, the Society for Neuro-Oncology and the European Association of Neuro-Oncology.

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Auteurs

Elisa Izquierdo (E)

Division of Molecular Pathology, Institute of Cancer Research, London, UK.

Paula Proszek (P)

Molecular Diagnostics, Royal Marsden Hospital NHS Trust, Sutton, UK.

Giulia Pericoli (G)

Department of Onco-haematology, Cell and Gene Therapy, Bambino Gesù Children's Hospital-IRCCS, Rome, Italy.

Sara Temelso (S)

Division of Molecular Pathology, Institute of Cancer Research, London, UK.

Matthew Clarke (M)

Division of Molecular Pathology, Institute of Cancer Research, London, UK.

Diana M Carvalho (DM)

Division of Molecular Pathology, Institute of Cancer Research, London, UK.

Alan Mackay (A)

Division of Molecular Pathology, Institute of Cancer Research, London, UK.

Lynley V Marshall (LV)

Division of Clinical Studies, The Institute of Cancer Research, London, UK.
Children & Young People's Unit, Royal Marsden Hospital NHS Trust, Sutton, UK.

Fernando Carceller (F)

Division of Clinical Studies, The Institute of Cancer Research, London, UK.
Children & Young People's Unit, Royal Marsden Hospital NHS Trust, Sutton, UK.

Darren Hargrave (D)

Department of Haematology and Oncology, UCL Great Ormond Street Institute for Child Health, London, UK.

Birgitta Lannering (B)

Department of Pediatrics, Institute of Clinical Sciences, Queen Silvia Children's Hospital, University of Gothenburg, Gothenburg, Sweden.

Zdenek Pavelka (Z)

Department of Pediatric Oncology, University Hospital Brno - Children's Hospital, Brno, Czechia.

Simon Bailey (S)

Department of Paediatric Oncology, Great North Children's Hospital, Newcastle University Center for Cancer, Newcastle upon Tyne, UK.

Natacha Entz-Werle (N)

Pediatric Onco-Hematology Department, University Hospital of Strasbourg, Strasbourg, France.
UMR CNRS 7021, Laboratory Bioimaging and Pathologies, Tumoral Signaling and Therapeutic Targets team, Faculty of Pharmacy, Illkirch, France.

Jacques Grill (J)

Pediatric and Adolescent Oncology and INSERM Unit U981, Team Genomics and Oncogenesis of Pediatric Brain Tumors, Gustave Roussy and Paris Saclay University, Villejuif, France.

Gilles Vassal (G)

Pediatric and Adolescent Oncology and INSERM Unit U981, Team Genomics and Oncogenesis of Pediatric Brain Tumors, Gustave Roussy and Paris Saclay University, Villejuif, France.

Daniel Rodriguez (D)

Medical Physics and Clinical Engineering, Nottingham University Hospital Trust Nottingham University Hospital Trust, Nottingham, UK.

Paul S Morgan (PS)

Medical Physics and Clinical Engineering, Nottingham University Hospital Trust Nottingham University Hospital Trust, Nottingham, UK.

Tim Jaspan (T)

Department of Radiology, Nottingham University Hospital Trust, Nottingham University Hospital Trust, Nottingham, UK.

Angela Mastronuzzi (A)

Department of Onco-haematology, Cell and Gene Therapy, Bambino Gesù Children's Hospital-IRCCS, Rome, Italy.

Mara Vinci (M)

Department of Onco-haematology, Cell and Gene Therapy, Bambino Gesù Children's Hospital-IRCCS, Rome, Italy.

Michael Hubank (M)

Molecular Diagnostics, Royal Marsden Hospital NHS Trust, Sutton, UK.

Chris Jones (C)

Division of Molecular Pathology, Institute of Cancer Research, London, UK.

Classifications MeSH