A Homozygous Deep Intronic Mutation Alters the Splicing of Nebulin Gene in a Patient With Nemaline Myopathy.

NEB alternative splicing nebulin nebulin isoforms nemalin myopathy neuromuscular disorder

Journal

Frontiers in neurology
ISSN: 1664-2295
Titre abrégé: Front Neurol
Pays: Switzerland
ID NLM: 101546899

Informations de publication

Date de publication:
2021
Historique:
received: 28 01 2021
accepted: 11 05 2021
entrez: 2 7 2021
pubmed: 3 7 2021
medline: 3 7 2021
Statut: epublish

Résumé

Nemaline myopathy is a rare disorder affecting the muscle sarcomere. Mutations in nebulin gene (

Identifiants

pubmed: 34211429
doi: 10.3389/fneur.2021.660113
pmc: PMC8239344
doi:

Types de publication

Journal Article

Langues

eng

Pagination

660113

Informations de copyright

Copyright © 2021 Laflamme, Lace, Thonta Setty, Rioux, Labrie, Droit, Chrestian and Rivest.

Déclaration de conflit d'intérêts

The authors declare that the research was conducted in the absence of any commercial or financial relationships that could be construed as a potential conflict of interest.

Références

Acta Neuropathol Commun. 2014 Apr 12;2:44
pubmed: 24725366
Muscle Nerve. 2012 Nov;46(5):730-7
pubmed: 22941678
Neuromuscul Disord. 1995 Mar;5(2):93-104
pubmed: 7767098
J Mol Biol. 1995 Apr 28;248(2):308-15
pubmed: 7739042
J Exp Biol. 2016 Jan;219(Pt 2):146-52
pubmed: 26792324
Genomics. 1988 Jan;2(1):1-7
pubmed: 2838409
J Neurol Sci. 1989 Jan;89(1):1-14
pubmed: 2926439
Eur J Hum Genet. 2004 Sep;12(9):744-51
pubmed: 15266303
Nature. 2015 Oct 1;526(7571):112-7
pubmed: 26367794
Phys Med Rehabil Clin N Am. 2012 Aug;23(3):609-31
pubmed: 22938878
Semin Pediatr Neurol. 2019 Apr;29:12-22
pubmed: 31060721
Nat Genet. 1995 Jan;9(1):75-9
pubmed: 7704029
Transcription. 2012 Jul-Aug;3(4):181-6
pubmed: 22771987
J Clin Invest. 2015 Jan;125(1):456-7
pubmed: 25654555
J Muscle Res Cell Motil. 2019 Jun;40(2):111-126
pubmed: 31228046
Nat Genet. 1999 Oct;23(2):208-12
pubmed: 10508519
Am J Hum Genet. 2000 Oct;67(4):814-21
pubmed: 10952871
Am J Hum Genet. 2013 Dec 5;93(6):1108-17
pubmed: 24268659
Genome Biol. 2016 Jun 06;17(1):122
pubmed: 27268795
Neuromuscul Disord. 2007 Jun;17(6):433-42
pubmed: 17434307
Bioinformatics. 2014 Aug 1;30(15):2114-20
pubmed: 24695404
J Child Neurol. 2008 Jun;23(6):609-13
pubmed: 18079309
J Biomed Biotechnol. 2010;2010:753675
pubmed: 20339475
Circ J. 2015;79(10):2081-7
pubmed: 26321576
Nucleic Acids Res. 2010 Sep;38(16):e164
pubmed: 20601685
Sci Rep. 2018 Oct 24;8(1):15728
pubmed: 30356055
J Cell Biol. 2006 Jun 19;173(6):905-16
pubmed: 16769824
J Struct Biol. 2010 May;170(2):325-33
pubmed: 20176113
Hum Mol Genet. 2019 May 15;28(10):1709-1725
pubmed: 30689900
Eur J Neurol. 2018 Jun;25(6):841-847
pubmed: 29498452
Arch Neurol. 2007 Sep;64(9):1334-8
pubmed: 17846275
Hum Mol Genet. 2009 Jul 1;18(13):2359-69
pubmed: 19346529
J Clin Invest. 2014 Aug;124(8):3529-39
pubmed: 24960163
Hum Mutat. 2018 Mar;39(3):383-388
pubmed: 29266598
Annu Rev Genet. 2013;47:139-65
pubmed: 24274751
J Muscle Res Cell Motil. 2020 Mar;41(1):103-124
pubmed: 31982973
Nat Genet. 2014 Mar;46(3):310-5
pubmed: 24487276
Am J Hum Genet. 2017 Jan 5;100(1):169-178
pubmed: 28017374
Neuromuscul Disord. 2002 Feb;12(2):151-8
pubmed: 11738357
Hum Genet. 2017 Sep;136(9):1093-1111
pubmed: 28497172
Sci Rep. 2018 Jul 31;8(1):11490
pubmed: 30065346
Neuromuscul Disord. 2013 Dec;23(12):992-7
pubmed: 24095155
Dev Med Child Neurol. 2020 Mar;62(3):297-302
pubmed: 31578728
Neuropathol Appl Neurobiol. 2017 Feb;43(1):5-23
pubmed: 27976420
Ital J Pediatr. 2017 Nov 15;43(1):101
pubmed: 29141652
Skelet Muscle. 2014 Aug 01;4:15
pubmed: 25110572
Front Physiol. 2012 Feb 27;3:37
pubmed: 22375125
Proc Natl Acad Sci U S A. 1980 Jun;77(6):3254-8
pubmed: 6997874
Hum Genet. 2004 Aug;115(3):185-90
pubmed: 15221447
Am J Hum Genet. 2010 Dec 10;87(6):842-7
pubmed: 21109227
Neuromuscul Disord. 2019 Feb;29(2):97-107
pubmed: 30679003
Acta Neuropathol Commun. 2018 May 30;6(1):40
pubmed: 29848386
Neuromuscul Disord. 2009 Mar;19(3):179-81
pubmed: 19232495
Genet Med. 2019 Jul;21(7):1629-1638
pubmed: 30467404
Hum Mutat. 2014 Dec;35(12):1418-26
pubmed: 25205138
Am J Hum Genet. 2007 Jan;80(1):162-7
pubmed: 17160903
J Cell Biol. 1991 Oct;115(1):97-107
pubmed: 1717482
Hum Mutat. 2006 Sep;27(9):946-56
pubmed: 16917880
Mol Genet Genomics. 2017 Dec;292(6):1175-1195
pubmed: 28707092
Proc Natl Acad Sci U S A. 1999 Mar 2;96(5):2305-10
pubmed: 10051637
J Neuromuscul Dis. 2015 Sep 2;2(3):219-227
pubmed: 27858739
Curr Protoc Hum Genet. 2013 Jan;Chapter 7:Unit7.20
pubmed: 23315928
Nat Protoc. 2009;4(7):1073-81
pubmed: 19561590
Elife. 2017 Aug 09;6:
pubmed: 28826497
Hum Mol Genet. 2018 Sep 15;27(18):3272-3282
pubmed: 29931346
Genomics. 2006 Oct;88(4):489-95
pubmed: 16860535

Auteurs

Nathalie Laflamme (N)

Centre de recherche CHU de Québec- Laval University, Quebec City, QC, Canada.

Baiba Lace (B)

Department of Medical Genetics, Centre Mère Enfant Soleil, Laval University, Quebec City, QC, Canada.

Samarth Thonta Setty (S)

Centre de recherche CHU de Québec- Laval University, Quebec City, QC, Canada.

Nadie Rioux (N)

Centre de recherche CHU de Québec- Laval University, Quebec City, QC, Canada.

Yvan Labrie (Y)

Centre de recherche CHU de Québec- Laval University, Quebec City, QC, Canada.

Arnaud Droit (A)

Centre de recherche CHU de Québec- Laval University, Quebec City, QC, Canada.

Nicolas Chrestian (N)

Department of Pediatric Neurology, Pediatric Neuromuscular Disorder, Centre Mère Enfant Soleil, Laval University, Quebec City, QC, Canada.

Serge Rivest (S)

Centre de recherche CHU de Québec- Laval University, Quebec City, QC, Canada.

Classifications MeSH