To Be or No B2: A Rare Cause of Stridor and Weakness in a Toddler.

SLC52A3 gene mutation muscle weakness riboflavin whole genome sequencing

Journal

Child neurology open
ISSN: 2329-048X
Titre abrégé: Child Neurol Open
Pays: United States
ID NLM: 101691975

Informations de publication

Date de publication:
Historique:
received: 25 03 2021
revised: 07 06 2021
accepted: 16 06 2021
entrez: 16 8 2021
pubmed: 17 8 2021
medline: 17 8 2021
Statut: epublish

Résumé

We present a case of a young child with a rare metabolic disorder whose clinical presentation resembled that of autoimmune myasthenia gravis. The differential diagnosis was expanded when autoantibody testing was negative and the patient did not respond to standard immunomodulatory therapies. Rapid whole genome sequencing identified 2 rare variants of uncertain significance in the

Identifiants

pubmed: 34395718
doi: 10.1177/2329048X211030723
pii: 10.1177_2329048X211030723
pmc: PMC8361551
doi:

Types de publication

Case Reports

Langues

eng

Pagination

2329048X211030723

Subventions

Organisme : NINDS NIH HHS
ID : R25 NS117367
Pays : United States

Informations de copyright

© The Author(s) 2021.

Déclaration de conflit d'intérêts

Declaration of Conflicting Interests: The authors declared no potential conflicts of interest with respect to the research, authorship, and/or publication of this article.

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Auteurs

Aliya L Frederick (AL)

Department of Neurosciences, University of California San Diego, CA, USA.
Rady Children's Hospital, San Diego, CA, USA.

Jennifer H Yang (JH)

Department of Neurosciences, University of California San Diego, CA, USA.
Rady Children's Hospital, San Diego, CA, USA.

Sarah Schneider (S)

Rady Children's Hospital, San Diego, CA, USA.
Department of Pediatrics, University of California San Diego, CA, USA.

Alexis Quade (A)

Rady Children's Hospital, San Diego, CA, USA.
Department of Pediatrics, University of California San Diego, CA, USA.
Department of Internal Medicine, University of California San Diego, CA, USA.

Lucia Guidugli (L)

Rady Children's Institute for Genomic Medicine, San Diego, CA, USA.

Kristen Wigby (K)

Rady Children's Hospital, San Diego, CA, USA.
Department of Genetics and Dysmorphology, University of California San Diego, CA, USA.

Melissa Cameron (M)

Rady Children's Hospital, San Diego, CA, USA.
Department of Pediatrics, University of California San Diego, CA, USA.

Classifications MeSH